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This observation seems to indicate that bilateral pulmonary agenesis is a severe expression of a developmental field defect that usually is represented by abnormal lung lobation or hypoplasia. The previously reported cases are discussed from the perspective of the developmental field concept.<\/jats:p>","DOI":"10.1002\/ajmg.1320210114","type":"journal-article","created":{"date-parts":[[2005,6,12]],"date-time":"2005-06-12T00:47:57Z","timestamp":1118537277000},"page":"93-103","source":"Crossref","is-referenced-by-count":41,"title":["Bilateral pulmonary agenesis: Association with the hydrolethalus syndrome and review of the literature from a developmental field perspective"],"prefix":"10.1002","volume":"21","author":[{"given":"Helga V.","family":"Toriello","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Stephen C.","family":"Bauserman","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"John M.","family":"Opitz","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"James F.","family":"Reynolds","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2005,6,3]]},"reference":[{"key":"e_1_2_1_2_1","first-page":"375","article-title":"Congenital absence of both lungs","volume":"41","author":"Allen","year":"1925","journal-title":"Surg Gynecol Obstet"},{"key":"e_1_2_1_3_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.1320090209"},{"key":"e_1_2_1_4_1","doi-asserted-by":"publisher","DOI":"10.1136\/adc.33.170.364"},{"key":"e_1_2_1_5_1","doi-asserted-by":"publisher","DOI":"10.1136\/thx.28.4.526"},{"key":"e_1_2_1_6_1","doi-asserted-by":"publisher","DOI":"10.1111\/j.1651-2227.1966.tb15215.x"},{"key":"e_1_2_1_7_1","first-page":"80","article-title":"Tracheal agenesis and associated malformations: A comparison with the tracheoesophageal fistula and the VACTERL association","volume":"3","author":"Evans JA","year":"1984","journal-title":"Proc Greenwood Genet Center"},{"key":"e_1_2_1_8_1","doi-asserted-by":"crossref","first-page":"993","DOI":"10.1542\/peds.28.6.993","article-title":"Congenital abnormalites of pulmonary vessels and their relations to malformations of the lung","volume":"23","author":"Ferencz C","year":"1961","journal-title":"Pediatrics"},{"key":"e_1_2_1_9_1","first-page":"496","volume-title":"Genetic disorders of the respiratory system","author":"Gilbert EF","year":"1979"},{"key":"e_1_2_1_10_1","volume-title":"Embryology for Surgeons","author":"Gray SW","year":"1972"},{"key":"e_1_2_1_11_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.1320140304"},{"key":"e_1_2_1_12_1","first-page":"30","volume-title":"Tracheo\u2010bronchial anomalies in children","author":"Landing BH","year":"1973"},{"key":"e_1_2_1_13_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.1320140305"},{"key":"e_1_2_1_14_1","first-page":"83","article-title":"A teratologic model for associations","volume":"3","author":"Lubinsky M","year":"1984","journal-title":"Proc Greenwood Genet Center"},{"key":"e_1_2_1_15_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.1320140309"},{"key":"e_1_2_1_16_1","first-page":"175","article-title":"Agenesis of the lung Presentation of eight new cases and review of the literature","volume":"42","author":"Maltz DM","year":"1968","journal-title":"Pediatrics"},{"key":"e_1_2_1_17_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0022-3476(82)80337-5"},{"key":"e_1_2_1_18_1","volume-title":"The Clinical Delineation of Birth Defects. 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