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In this case report, we describe a male infant born to a diabetic mother who in addition to other typical congenital abnormalities was born with an impressive bifid tongue. Accompanying congenital anomalies include unilateral microphthalmia, bilateral microtia, cleft palate, micropenis with unilateral cryptorchidism, bilateral radial hypoplasia, unilateral pre\u2010axial polydactyly, and mid\u2010line central nervous system defects including arhinencephaly and pituitary hypoplasia. Review of the literature reveals an additional case of an infant with a bifid tongue born to a diabetic mother [Comess et al., <jats:ext-link xmlns:xlink=\"http:\/\/www.w3.org\/1999\/xlink\" xlink:href=\"#bib6\">1969<\/jats:ext-link>]. In conclusion, bifid tongue without oral hamartoma, a rare congenital anomaly, can be an associated finding in IDM. \u00a9 2007 Wiley\u2010Liss, Inc.<\/jats:p>","DOI":"10.1002\/ajmg.a.31877","type":"journal-article","created":{"date-parts":[[2007,7,30]],"date-time":"2007-07-30T23:46:36Z","timestamp":1185839196000},"page":"2035-2039","source":"Crossref","is-referenced-by-count":18,"title":["Bifid tongue: A rare feature associated with infants of diabetic mother syndrome"],"prefix":"10.1002","volume":"143A","author":[{"given":"Aaron 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