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Herein, we report a male infant with non\u2010syndromic bilateral Type Vb ulnar longitudinal dysplasia with radiohumeral synostosis (apparent humeral bifurcation), and bilateral oligo\u2010ectro\u2010syndactyly who was born following an uncomplicated pregnancy, with no maternal use of prescription or illicit medication. Array CGH (60,000 probes) and chromosomal breakage analysis (DEB) were normal. Similar appearances have been reported in children exposed to thalidomide or cocaine, but sporadic patients have also been reported without a prior history of exposure to known teratogens.<\/jats:p><\/jats:sec>","DOI":"10.1002\/ajmg.a.38632","type":"journal-article","created":{"date-parts":[[2018,2,10]],"date-time":"2018-02-10T08:12:35Z","timestamp":1518250355000},"page":"1180-1183","source":"Crossref","is-referenced-by-count":1,"title":["Non\u2010syndromic bilateral ulnar aplasia with humero\u2010radial synostosis and oligo\u2010ectro\u2010dactyly"],"prefix":"10.1002","volume":"176","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-9201-9216","authenticated-orcid":false,"given":"Terri P.","family":"McVeigh","sequence":"first","affiliation":[{"name":"Department of Clinical Genetics Our Lady's Children's Hospital Crumlin Dublin Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Jonathan A.","family":"Soye","sequence":"additional","affiliation":[{"name":"Department of Radiology Our Lady of Lourdes Hospital Drogheda Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Emma","family":"Gordon","sequence":"additional","affiliation":[{"name":"Department of Paediatrics Our Lady of Lourdes Hospital Drogheda Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Sally A.","family":"Lynch","sequence":"additional","affiliation":[{"name":"Department of Clinical Genetics Our Lady's Children's Hospital Crumlin Dublin Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2018,2,10]]},"reference":[{"key":"e_1_2_5_2_1","doi-asserted-by":"publisher","DOI":"10.1002\/bdrc.21140"},{"key":"e_1_2_5_3_1","unstructured":"F\u00f6rster A. &Francis A. 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