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The aims of this scoping review were to describe the pain experiences of children and adults with AMC, to identify pain assessment tools and management techniques, and document the impact of pain on participation in everyday activities among children and adults with AMC. A search of the literature was conducted in four search engines and identified a total of 89 articles. Once study eligibility was reviewed, 21 studies met the selection criteria and were included in this review. Pain appears to be more commonly experienced in adults with AMC compared with children with AMC, with individuals having undergone multiple corrective procedures self\u2010reporting pain more often. In adult populations, musculoskeletal chronic pain is a significant problem, resulting in restrictions in activities of daily living, mobility, and participation. Researchers and clinicians must agree on the use of validated measures appropriate for evaluating pain in AMC and the use of appropriate pain management techniques to relieve pain. Pediatric studies should focus on determining how commonly pain is experienced in infants, children, and adolescents with AMC. Pain in adults with AMC should be acknowledged to offer proper client\u2010centered interventions throughout the lifespan.<\/jats:p>","DOI":"10.1002\/ajmg.c.31725","type":"journal-article","created":{"date-parts":[[2019,7,26]],"date-time":"2019-07-26T03:03:49Z","timestamp":1564110229000},"page":"436-453","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":28,"title":["Pain among children and adults living with arthrogryposis multiplex congenita: A scoping review"],"prefix":"10.1002","volume":"181","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-6330-623X","authenticated-orcid":false,"given":"Alexa","family":"Cirillo","sequence":"first","affiliation":[{"name":"Shriners Hospital for Children\u2010Canada  Montreal Canada"},{"name":"School of Physical and Occupational Therapy, Faculty of Medicine McGill University  Montreal Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0186-8309","authenticated-orcid":false,"given":"Jessica","family":"Collins","sequence":"additional","affiliation":[{"name":"Shriners Hospital for Children\u2010Canada  Montreal Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-8901-2301","authenticated-orcid":false,"given":"Bonita","family":"Sawatzky","sequence":"additional","affiliation":[{"name":"University of British Columbia, Department of Orthopedics  Vancouver Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-0664-2843","authenticated-orcid":false,"given":"Reggie","family":"Hamdy","sequence":"additional","affiliation":[{"name":"Shriners Hospital for Children\u2010Canada  Montreal Canada"},{"name":"Department of Orthopedics, Faculty of Medicine McGill University  Montreal Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-8567-7173","authenticated-orcid":false,"given":"No\u00e9mi","family":"Dahan\u2010Oliel","sequence":"additional","affiliation":[{"name":"Shriners Hospital for Children\u2010Canada  Montreal Canada"},{"name":"School of Physical and Occupational Therapy, Faculty of Medicine McGill University  Montreal Canada"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2019,7,26]]},"reference":[{"key":"e_1_2_8_2_1","doi-asserted-by":"publisher","DOI":"10.1097\/scs.0b013e318068ff1a"},{"key":"e_1_2_8_3_1","doi-asserted-by":"publisher","DOI":"10.1097\/BPO.0b013e31820cad93"},{"key":"e_1_2_8_4_1","doi-asserted-by":"publisher","DOI":"10.1080\/1364557032000119616"},{"key":"e_1_2_8_5_1","doi-asserted-by":"publisher","DOI":"10.1097\/PEP.0000000000000148"},{"key":"e_1_2_8_6_1","doi-asserted-by":"publisher","DOI":"10.1542\/peds.108.2.482"},{"key":"e_1_2_8_7_1","doi-asserted-by":"publisher","DOI":"10.5435\/00124635-200211000-00006"},{"key":"e_1_2_8_8_1","doi-asserted-by":"publisher","DOI":"10.1100\/tsw.2007.254"},{"key":"e_1_2_8_9_1","doi-asserted-by":"publisher","DOI":"10.1177\/204946371100500306"},{"key":"e_1_2_8_10_1","doi-asserted-by":"publisher","DOI":"10.1177\/112070000901906s08"},{"key":"e_1_2_8_11_1","doi-asserted-by":"publisher","DOI":"10.1097\/01241398-200009000-00020"},{"issue":"8","key":"e_1_2_8_12_1","first-page":"S38","article-title":"Results of primary talectomy for clubfoot in infants and toddlers with arthrogryposis multiplex congenita","volume":"98","author":"Chotigavanichaya C.","year":"2015","journal-title":"Journal of the Medical Association of Thailand"},{"key":"e_1_2_8_13_1","doi-asserted-by":"publisher","DOI":"10.1111\/j.1469-8749.2005.tb01036.x"},{"key":"e_1_2_8_14_1","unstructured":"Dahan\u2010Oliel N. 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