{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,26]],"date-time":"2026-09-26T10:54:29Z","timestamp":1790420069442,"version":"4.1.0"},"reference-count":42,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2023,3,27]],"date-time":"2023-03-27T00:00:00Z","timestamp":1679875200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"funder":[{"DOI":"10.13039\/501100002915","name":"Fondation pour la Recherche M\u00e9dicale","doi-asserted-by":"publisher","award":["MND202004011718"],"award-info":[{"award-number":["MND202004011718"]}],"id":[{"id":"10.13039\/501100002915","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Annals of Neurology"],"published-print":{"date-parts":[[2023,7]]},"abstract":"<jats:sec>\n                    <jats:title>Objective<\/jats:title>\n                    <jats:p>\n                      Survival of patients with monogenic Parkinson's disease may depend on the causative genes associated with the disease. In this study, we compare survival of patients with Parkinson's disease according to the presence of\n                      <jats:italic>SNCA<\/jats:italic>\n                      ,\n                      <jats:italic>PRKN<\/jats:italic>\n                      ,\n                      <jats:italic>LRRK2<\/jats:italic>\n                      , or\n                      <jats:italic>GBA<\/jats:italic>\n                      mutations.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Methods<\/jats:title>\n                    <jats:p>\n                      Data from the French Parkinson Disease Genetics national multicenter cohort study were used. Patients with sporadic and familial Parkinson's disease were recruited between 1990 and 2021. Patients were genotyped for the presence of mutations in the\n                      <jats:italic>SNCA<\/jats:italic>\n                      ,\n                      <jats:italic>PRKN<\/jats:italic>\n                      ,\n                      <jats:italic>LRRK2<\/jats:italic>\n                      , or\n                      <jats:italic>GBA<\/jats:italic>\n                      genes. Vital status was collected from the National death register for participants born in France. Hazard ratios (HRs) and 95% confidence intervals (CIs) were computed using multivariable Cox proportional hazards regression.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>\n                      Of the 2,037 patients with Parkinson's disease, 889 had died after a follow\u2010up of up to 30\u2009years. Patients with\n                      <jats:italic>PRKN<\/jats:italic>\n                      (n\u00a0=\u00a0100, HR\u00a0=\u00a00.41;\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0=\u00a00.001) and\n                      <jats:italic>LRRK2<\/jats:italic>\n                      mutations (n\u00a0=\u00a051, HR\u00a0=\u00a00.49;\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0=\u00a00.023) had longer survival than those without any mutation, whereas patients with\n                      <jats:italic>SNCA<\/jats:italic>\n                      (n\u00a0=\u00a020, HR\u00a0=\u00a09.88;\n                      <jats:italic>p<\/jats:italic>\n                      \u2009&lt;\u20090.001) or\n                      <jats:italic>GBA<\/jats:italic>\n                      mutations (n\u00a0=\u00a0173, HR\u00a0=\u00a01.33;\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0=\u00a00.048) had shorter survival.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Interpretation<\/jats:title>\n                    <jats:p>\n                      Survival differs across genetic forms of Parkinson's disease, with higher mortality for patients with\n                      <jats:italic>SNCA<\/jats:italic>\n                      or\n                      <jats:italic>GBA<\/jats:italic>\n                      mutations, and lower mortality for those with\n                      <jats:italic>PRKN<\/jats:italic>\n                      or\n                      <jats:italic>LRRK2<\/jats:italic>\n                      mutations. Differences in severity and disease progression among monogenic forms of Parkinson's disease likely explain these findings, which has important consequences for genetic counselling and choice of end points for future clinical trials for targeted therapies. ANN NEUROL 2023;94:123\u2013132\n                    <\/jats:p>\n                  <\/jats:sec>","DOI":"10.1002\/ana.26636","type":"journal-article","created":{"date-parts":[[2023,3,11]],"date-time":"2023-03-11T02:29:11Z","timestamp":1678501751000},"page":"123-132","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":24,"title":["Differences in Survival across Monogenic Forms of Parkinson's Disease"],"prefix":"10.1002","volume":"94","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-8251-3410","authenticated-orcid":false,"given":"Aymeric","family":"Lanore","sequence":"first","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Neurology, CIC Neurosciences H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Fanny","family":"Casse","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Christelle","family":"Tesson","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Thomas","family":"Courtin","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Genetics H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Poornima Jayadev","family":"Menon","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Neurology, CIC Neurosciences H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"},{"name":"School of Postgraduate Studies Royal College of Surgeons in Ireland  Dublin Ireland"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-5027-497X","authenticated-orcid":false,"given":"Sara","family":"Sambin","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Neurology, CIC Neurosciences H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Graziella","family":"Mangone","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Neurology, CIC Neurosciences H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"},{"name":"Department of Neurology, Movement Disorder Division Rush University Medical Center  Chicago IL"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Louise\u2010Laure","family":"Mariani","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Neurology, CIC Neurosciences H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Suzanne","family":"Lesage","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Alexis","family":"Brice","sequence":"additional","affiliation":[{"name":"Sorbonne Universit\u00e9, Institut du Cerveau\u2014Paris Brain Institute\u2014ICM, Inserm, CNRS  Paris France"},{"name":"Assistance Publique H\u00f4pitaux de Paris, Department of Genetics H\u00f4pital Piti\u00e9\u2010Salp\u00eatri\u00e8re  Paris France"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-9724-5490","authenticated-orcid":false,"given":"Alexis","family":"Elbaz","sequence":"additional","affiliation":[{"name":"Universit\u00e9 Paris\u2010Saclay, UVSQ, Univ. 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