{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,17]],"date-time":"2026-08-17T14:30:57Z","timestamp":1786977057150,"version":"build-2736575974"},"reference-count":17,"publisher":"Wiley","issue":"3","license":[{"start":{"date-parts":[[2015,12,12]],"date-time":"2015-12-12T00:00:00Z","timestamp":1449878400000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"funder":[{"name":"Bob and Nancy Edwards Scholarship, University of Sydney"},{"name":"National Health and Medical Research Council (NHMRC) Career Development Fellowship","award":["1067066"],"award-info":[{"award-number":["1067066"]}]},{"name":"NHMRC Principal Research Fellowship","award":["634341"],"award-info":[{"award-number":["634341"]}]},{"name":"NHMRC Career Development Fellowship","award":["1087062"],"award-info":[{"award-number":["1087062"]}]},{"name":"Developmental Pathways in WA Children Project","award":["LP100200507"],"award-info":[{"award-number":["LP100200507"]}]}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Birth Defects Research"],"published-print":{"date-parts":[[2016,3]]},"abstract":"<jats:sec>\n                    <jats:title>BACKGROUND<\/jats:title>\n                    <jats:p>Only two population\u2010based studies have reported survival beyond 15 years for individuals with orofacial clefts (OFC), and only for individuals with isolated OFC. Compared with the general population, long\u2010term survival was similar for individuals with cleft lip only, and lower for individuals with cleft palate only. Results for those born with isolated cleft lip and cleft palate were inconsistent.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>METHODS<\/jats:title>\n                    <jats:p>Using linked population\u2010based health data, including a congenital anomaly register with active surveillance and diagnoses up to 6 years, we compared survival at 1, 5, and 20 years for infants born 1980 to 2010 with, and without OFC.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>RESULTS<\/jats:title>\n                    <jats:p>Of the 8112 live born infants in the cohort, 186 died before 20 years; most (81%) died during infancy. Compared with infants without OFC, infants born with all types of isolated OFC \u00b1 additional minor anomalies had similar infant survival (around 99%), but we found lower survival for infants with all cleft types and an additional major anomaly (66\u201384%). From 1 to 5 years, only infants with cleft palate only and an additional major anomaly had lower survival (97%) compared with children without OFC (99.9%). From 5 to 20 years, children with all cleft types, with or without additional major anomalies had similar survival to children without OFC (98\u2013100%).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>CONCLUSION<\/jats:title>\n                    <jats:p>Parents with a child diagnosed with an OFC \u00b1 additional minor anomalies only can be reassured that the OFC does not influence survival rates in infancy, or long\u2010term. Infant survival was lower only for children with OFC and additional major anomalies. Birth Defects Research (Part A) 106:172\u2013177, 2016. \u00a9 2015 Wiley Periodicals, Inc.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1002\/bdra.23473","type":"journal-article","created":{"date-parts":[[2015,12,12]],"date-time":"2015-12-12T10:15:26Z","timestamp":1449915326000},"page":"172-177","source":"Crossref","is-referenced-by-count":7,"title":["Long\u2010term survival for infants born with orofacial clefts in Western Australia"],"prefix":"10.1002","volume":"106","author":[{"given":"Jane C.","family":"Bell","sequence":"first","affiliation":[{"name":"Sydney School of Public Health University of Sydney New South Wales"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Natasha","family":"Nassar","sequence":"additional","affiliation":[{"name":"Population Perinatal Health Research, Kolling Institute for Medical Research University of Sydney  New South Wales"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Carol","family":"Bower","sequence":"additional","affiliation":[{"name":"Western Australian Register of Developmental Anomalies King Edward Memorial Hospital Subiaco Western Australia"},{"name":"Telethon Institute for Child Health Research, Centre for Child Health Research University of Western Australia Western Australia"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Robin M.","family":"Turner","sequence":"additional","affiliation":[{"name":"School of Public Health and Community Medicine University of New South Wales New South Wales"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Camille","family":"Raynes\u2010Greenow","sequence":"additional","affiliation":[{"name":"Sydney School of Public Health University of Sydney New South Wales"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2015,12,12]]},"reference":[{"key":"e_1_2_6_2_1","doi-asserted-by":"publisher","DOI":"10.1002\/bdra.20218"},{"key":"e_1_2_6_3_1","volume-title":"Australian Demographic Statistics \u2010 3101.0","author":"Australian Bureau of Statistics","year":"2014"},{"key":"e_1_2_6_4_1","doi-asserted-by":"publisher","DOI":"10.1002\/bdra.23110"},{"key":"e_1_2_6_5_1","doi-asserted-by":"publisher","DOI":"10.1111\/j.1365-3016.2005.00666.x"},{"key":"e_1_2_6_6_1","doi-asserted-by":"publisher","DOI":"10.1111\/j.1753-6405.1990.tb00627.x"},{"key":"e_1_2_6_7_1","volume-title":"Report of the Western Australian Register of Developmental Anomalies 1980\u20132011","author":"Bower C","year":"2012"},{"key":"e_1_2_6_8_1","doi-asserted-by":"publisher","DOI":"10.1136\/bmj.38106.559120.7C"},{"key":"e_1_2_6_9_1","doi-asserted-by":"publisher","DOI":"10.1136\/adc.88.5.391"},{"key":"e_1_2_6_10_1","doi-asserted-by":"publisher","DOI":"10.1597\/1545-1569(1996)033<0400:FYOLMA>2.3.CO;2"},{"key":"e_1_2_6_11_1","doi-asserted-by":"publisher","DOI":"10.1002\/tera.1420070308"},{"key":"e_1_2_6_12_1","doi-asserted-by":"publisher","DOI":"10.1071\/AH080766"},{"key":"e_1_2_6_13_1","doi-asserted-by":"publisher","DOI":"10.1597\/1545-1569(1992)029<0451:FYMAIW>2.3.CO;2"},{"key":"e_1_2_6_14_1","doi-asserted-by":"publisher","DOI":"10.1002\/tera.1073"},{"key":"e_1_2_6_15_1","volume-title":"SAS 9.3","author":"SAS Institute Inc","year":"2012"},{"key":"e_1_2_6_16_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0140-6736(09)61922-X"},{"key":"e_1_2_6_17_1","doi-asserted-by":"publisher","DOI":"10.1597\/02-076"},{"key":"e_1_2_6_18_1","doi-asserted-by":"publisher","DOI":"10.1597\/05-123"}],"container-title":["Birth Defects Research Part A: Clinical and Molecular Teratology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.wiley.com\/onlinelibrary\/tdm\/v1\/articles\/10.1002%2Fbdra.23473","content-type":"unspecified","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/pdf\/10.1002\/bdra.23473","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,9,26]],"date-time":"2023-09-26T00:16:15Z","timestamp":1695687375000},"score":1,"resource":{"primary":{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/10.1002\/bdra.23473"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2015,12,12]]},"references-count":17,"journal-issue":{"issue":"3","published-print":{"date-parts":[[2016,3]]}},"alternative-id":["10.1002\/bdra.23473"],"URL":"https:\/\/doi.org\/10.1002\/bdra.23473","archive":["Portico"],"relation":{},"ISSN":["1542-0752","1542-0760"],"issn-type":[{"value":"1542-0752","type":"print"},{"value":"1542-0760","type":"electronic"}],"subject":[],"published":{"date-parts":[[2015,12,12]]}}}