{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,29]],"date-time":"2026-08-29T01:26:38Z","timestamp":1787966798195,"version":"build-2784847793"},"reference-count":17,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2023,4,17]],"date-time":"2023-04-17T00:00:00Z","timestamp":1681689600000},"content-version":"vor","delay-in-days":75,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Epileptic Disorders"],"published-print":{"date-parts":[[2023,2]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>Sturge\u2013Weber Syndrome (SWS) is a rare neurocutaneous disorder caused by focal vascular dysplasia. It is associated with facial angiomas, ocular abnormalities, epilepsy, intellectual disability, and leptomeningeal angiomas. There is a paucity of literature regarding the management of epilepsy and pregnancy in women with SWS. The effects of pregnancy on this syndrome therefore remain largely undefined. Consensus on management is needed;\u00a0as pregnancy has widespread effects on the vascular system and therefore may pose risk in women with SWS. This is a comprehensive review of the existing literature and case report of a woman with SWS, refractory epilepsy, and a successful pregnancy and delivery. Fifteen cases were found and, in addition to our case, 14 cases were reviewed, 11 of which discuss labor and delivery. Neurological complications were described in four cases and successful delivery without complication occurred in seven patient cases.<\/jats:p>","DOI":"10.1002\/epd2.20058","type":"journal-article","created":{"date-parts":[[2023,4,10]],"date-time":"2023-04-10T05:34:18Z","timestamp":1681104858000},"page":"87-93","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":2,"title":["Pregnancy and refractory epilepsy in Sturge\u2013Weber syndrome: Challenges and outcomes"],"prefix":"10.1002","volume":"25","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-5439-9016","authenticated-orcid":false,"given":"Jennifer","family":"Olson","sequence":"first","affiliation":[{"name":"Neurology University of Cincinnati Medical Center  Cincinnati Ohio USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Heather","family":"McKee","sequence":"additional","affiliation":[{"name":"Neurology University of Cincinnati Medical Center  Cincinnati Ohio USA"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2023,4,17]]},"reference":[{"key":"e_1_2_6_2_1","doi-asserted-by":"publisher","DOI":"10.1212\/WNL.0b013e3182604548"},{"key":"e_1_2_6_3_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0031-3955(16)38367-5"},{"issue":"12","key":"e_1_2_6_4_1","first-page":"353","article-title":"Sturge\u2013Weber\u2013Thoma syndrome, a case report","volume":"72","author":"Benedek E","year":"1979","journal-title":"Fogorv Sz"},{"key":"e_1_2_6_5_1","first-page":"17","article-title":"Sturge\u2013Weber syndrome: apropos of an anatomo\u2010clinical case report with prepapillary glial proliferation","volume":"243","author":"Kallay O","year":"1992","journal-title":"Bull Soc Belge Ophtalmol"},{"key":"e_1_2_6_6_1","doi-asserted-by":"publisher","DOI":"10.1016\/0002-9378(95)90383-6"},{"issue":"8","key":"e_1_2_6_7_1","first-page":"536","article-title":"Sturge\u2013Weber angiomatosis responsible for hemiplegia without cerebral infarction in term pregnancy","volume":"152","author":"Chabriat H","year":"1996","journal-title":"Rev Neurol (Paris)"},{"key":"e_1_2_6_8_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.ijoa.2010.11.011"},{"issue":"2","key":"e_1_2_6_9_1","first-page":"19","article-title":"Pregnancy with Sturge Weber syndrome presenting as status epilepticus","volume":"2","author":"Gupta M","year":"2013","journal-title":"Indian J Med Case Rep"},{"key":"e_1_2_6_10_1","doi-asserted-by":"publisher","DOI":"10.1016\/S1701-2163(15)30814-8"},{"key":"e_1_2_6_11_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.ejogrb.2006.11.010"},{"key":"e_1_2_6_12_1","doi-asserted-by":"publisher","DOI":"10.18203\/2320-1770.ijrcog20150112"},{"key":"e_1_2_6_13_1","doi-asserted-by":"publisher","DOI":"10.1177\/0300060520913708"},{"issue":"16","key":"e_1_2_6_14_1","first-page":"2","article-title":"Sturge Weber syndrome's angioma electively occurring during pregnancy: case report","volume":"88","author":"Radji F","year":"2017","journal-title":"Neurology"},{"key":"e_1_2_6_15_1","doi-asserted-by":"publisher","DOI":"10.1038\/sj.eye.6701474"},{"key":"e_1_2_6_16_1","doi-asserted-by":"publisher","DOI":"10.4103\/psychiatry.IndianJPsychiatry_560_18"},{"key":"e_1_2_6_17_1","doi-asserted-by":"publisher","DOI":"10.1080\/01443615.2022.2027895"},{"key":"e_1_2_6_18_1","doi-asserted-by":"publisher","DOI":"10.1097\/01.wco.0000218226.27937.57"}],"container-title":["Epileptic Disorders"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/pdf\/10.1002\/epd2.20058","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2024,3,18]],"date-time":"2024-03-18T16:04:53Z","timestamp":1710777893000},"score":1,"resource":{"primary":{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/10.1002\/epd2.20058"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2023,2]]},"references-count":17,"journal-issue":{"issue":"1","published-print":{"date-parts":[[2023,2]]}},"alternative-id":["10.1002\/epd2.20058"],"URL":"https:\/\/doi.org\/10.1002\/epd2.20058","archive":["Portico"],"relation":{},"ISSN":["1294-9361","1950-6945"],"issn-type":[{"value":"1294-9361","type":"print"},{"value":"1950-6945","type":"electronic"}],"subject":[],"published":{"date-parts":[[2023,2]]},"assertion":[{"value":"2022-10-31","order":0,"name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2023-03-30","order":1,"name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}},{"value":"2023-04-17","order":2,"name":"published","label":"Published","group":{"name":"publication_history","label":"Publication History"}}]}}