{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,12,8]],"date-time":"2025-12-08T22:15:54Z","timestamp":1765232154089},"reference-count":14,"publisher":"Wiley","issue":"2","license":[{"start":{"date-parts":[[2014,7,30]],"date-time":"2014-07-30T00:00:00Z","timestamp":1406678400000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["The Laryngoscope"],"published-print":{"date-parts":[[2015,2]]},"abstract":"<jats:sec><jats:title>Objectives\/Hypothesis<\/jats:title><jats:p>This study aimed to investigate the diagnosis and management of a distinct developmental deformity syndrome characterized by congenital cheek fistula, ectopic accessory parotid gland, and preauricular appendage.<\/jats:p><\/jats:sec><jats:sec><jats:title>Study Design<\/jats:title><jats:p>Retrospective study.<\/jats:p><\/jats:sec><jats:sec><jats:title>Methods<\/jats:title><jats:p>We analyzed the medical records, radiologic and histopathologic findings, and follow\u2010up data for seven patients (four males) with a congenital cheek salivary fistula. Computed tomography, fistulography, and sialography had been performed for diagnosis. Surgical treatment effect was evaluated.<\/jats:p><\/jats:sec><jats:sec><jats:title>Results<\/jats:title><jats:p>The mean age of the patients was 8.1 years (range, 2\u201316 years). The distinctive clinical feature was a congenital skin orifice lateral to the commissure with saliva discharge during eating. The cheek fistulae were accompanied by ipsilateral preauricular appendages in all seven patients. The skin orifice connected to an ectopic gland anterior to the masseter and inferior to Stensen's duct. Parotid sialography demonstrated an intact Stensen's duct in all cases. Hypoplasia of the ipsilateral mandible could be observed in five cases. Excision of the ectopic gland, skin orifice, and fistula was performed in five cases resulting in optimal treatment outcomes with no recurrent or adverse events.<\/jats:p><\/jats:sec><jats:sec><jats:title>Conclusions<\/jats:title><jats:p>A congenital saliva\u2010discharging fistula with an ectopic accessory parotid gland, ipsilateral preauricular appendage, and mandibular hypoplasia constitutes a rare developmental syndrome. Surgical excision can effectively treat congenital cheek salivary fistula.<\/jats:p><\/jats:sec><jats:sec><jats:title>Level of Evidence<\/jats:title><jats:p>4.<jats:italic>Laryngoscope<\/jats:italic>, 125:360\u2013364, 2015<\/jats:p><\/jats:sec>","DOI":"10.1002\/lary.24859","type":"journal-article","created":{"date-parts":[[2014,7,30]],"date-time":"2014-07-30T09:19:03Z","timestamp":1406711943000},"page":"360-364","source":"Crossref","is-referenced-by-count":12,"title":["Cheek fistula from the ectopic salivary gland: A variant of the oculo\u2010auriculo\u2010vertebral spectrum"],"prefix":"10.1002","volume":"125","author":[{"given":"Zhi\u2010Peng","family":"Sun","sequence":"first","affiliation":[{"name":"Department of Oral and Maxillofacial Radiology Peking University School and Hospital of Stomatology Beijing China"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Xia","family":"Hong","sequence":"additional","affiliation":[{"name":"Department of Oral and Maxillofacial Surgery Peking University School and Hospital of Stomatology Beijing China"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Xu\u2010Chen","family":"Ma","sequence":"additional","affiliation":[{"name":"Department of Oral and Maxillofacial Radiology Peking University School and Hospital of Stomatology Beijing China"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Zu\u2010Yan","family":"Zhang","sequence":"additional","affiliation":[{"name":"Department of Oral and Maxillofacial Radiology Peking University School and Hospital of Stomatology Beijing China"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Guang\u2010Yan","family":"Yu","sequence":"additional","affiliation":[{"name":"Department of Oral and Maxillofacial Surgery Peking University School and Hospital of Stomatology Beijing China"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2014,7,30]]},"reference":[{"key":"e_1_2_6_2_1","first-page":"7","article-title":"Accessory parotid gland with ectopic fistulous duct\u2014diagnosis by ultrasonography, digital fistulography, digital sialography and CT fistulography. A case report and review of current literature","volume":"5","author":"Kulkarni CD","year":"2011","journal-title":"J Radiol Case Rep"},{"key":"e_1_2_6_3_1","doi-asserted-by":"publisher","DOI":"10.1017\/S0022215111002945"},{"key":"e_1_2_6_4_1","doi-asserted-by":"crossref","first-page":"34","DOI":"10.1177\/014556131209100111","article-title":"A case of congenital fistula from an accessory parotid gland: diagnosis and treatment","volume":"91","author":"Pinto FR","year":"2012","journal-title":"Ear Nose Throat J"},{"key":"e_1_2_6_5_1","doi-asserted-by":"publisher","DOI":"10.3342\/ceo.2008.1.2.113"},{"key":"e_1_2_6_6_1","first-page":"997","article-title":"Congenital fistula from ectopic accessory parotid gland: diagnosis with CT sialography and CT fistulography","volume":"16","author":"Moon WK","year":"1995","journal-title":"AJNR Am J Neuroradiol"},{"key":"e_1_2_6_7_1","doi-asserted-by":"publisher","DOI":"10.1017\/S0022215107001417"},{"key":"e_1_2_6_8_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0300-9785(86)80045-X"},{"key":"e_1_2_6_9_1","doi-asserted-by":"publisher","DOI":"10.1016\/0278-2391(92)90113-E"},{"key":"e_1_2_6_10_1","first-page":"130","article-title":"Congenital external fistula of the accessory parotid gland: a case report","volume":"11","author":"He JQ","year":"2008","journal-title":"Chin J Dent Res"},{"key":"e_1_2_6_11_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.a.32950"},{"key":"e_1_2_6_12_1","doi-asserted-by":"crossref","first-page":"790","DOI":"10.1093\/oso\/9780195118612.003.0019","volume-title":"Syndromes of the Head and Neck","author":"Gorlin RJ","year":"2001"},{"key":"e_1_2_6_13_1","doi-asserted-by":"publisher","DOI":"10.1016\/0030-4220(77)90049-4"},{"key":"e_1_2_6_14_1","first-page":"106","volume-title":"Surgery of the Auricle: Tumors\u2010Trauma\u2010Defects\u2010Abnormalities","author":"Hilko W","year":"2007"},{"key":"e_1_2_6_15_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.oooo.2011.08.015"}],"container-title":["The Laryngoscope"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.wiley.com\/onlinelibrary\/tdm\/v1\/articles\/10.1002%2Flary.24859","content-type":"unspecified","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/pdf\/10.1002\/lary.24859","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2024,5,31]],"date-time":"2024-05-31T16:59:47Z","timestamp":1717174787000},"score":1,"resource":{"primary":{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/10.1002\/lary.24859"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2014,7,30]]},"references-count":14,"journal-issue":{"issue":"2","published-print":{"date-parts":[[2015,2]]}},"alternative-id":["10.1002\/lary.24859"],"URL":"https:\/\/doi.org\/10.1002\/lary.24859","archive":["Portico"],"relation":{},"ISSN":["0023-852X","1531-4995"],"issn-type":[{"value":"0023-852X","type":"print"},{"value":"1531-4995","type":"electronic"}],"subject":[],"published":{"date-parts":[[2014,7,30]]}}}