{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,30]],"date-time":"2026-06-30T05:07:23Z","timestamp":1782796043469,"version":"3.54.5"},"reference-count":37,"publisher":"Wiley","issue":"3","license":[{"start":{"date-parts":[[2022,2,6]],"date-time":"2022-02-06T00:00:00Z","timestamp":1644105600000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Musculoskeletal Care"],"published-print":{"date-parts":[[2022,9]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:sec><jats:title>Purpose<\/jats:title><jats:p>Fatigue is an overlooked symptom for musculoskeletal diseases, including rare conditions like systemic sclerosis (SSc). The purpose of this study were the following: (1) to adapt the content and delivery method of an existing fatigue intervention, and (2) to determine the feasibility of Fatigue and Activity Management Education in Systemic Sclerosis (FAME\u2010iSS).<\/jats:p><\/jats:sec><jats:sec><jats:title>Methods<\/jats:title><jats:p>In Phase 1 adaptations were recorded using the Framework for Modification and Adaptations. In Phase 2, participants completed the 6\u2010week FAME\u2010iSS intervention and baseline, post\u2010intervention, and 3\u2010month follow\u2010up assessments measuring fatigue levels, fatigue impact, mental health, self\u2010efficacy, and use of energy conservation strategies. Qualitative data included a post\u2010intervention focus group and 3\u2010month follow\u2010up interviews.<\/jats:p><\/jats:sec><jats:sec><jats:title>Results<\/jats:title><jats:p>Three main changes were made to the original intervention: (1) the content was adapted from management of Lupus\u2010related fatigue to management of SSc\u2010related fatigue, (2) context for delivery from Ireland to United States, and (3) in\u2010person to online format. Participants (<jats:italic>n<\/jats:italic>\u00a0=\u00a04) were 51.8\u00a0\u00b1\u00a012.1\u00a0years old, had been diagnosed with SSc for 12.0\u00a0\u00b1\u00a08.0\u00a0years, were receiving disability support, and had college degrees. All participants had 100% attendance and completed all study activities. Participants had positive comments about the programme format, content, and implementation. Post\u2010intervention, improvements were observed in most measures. Moderate effect sizes were noted in fatigue and self\u2010efficacy scores.<\/jats:p><\/jats:sec><jats:sec><jats:title>Conclusion<\/jats:title><jats:p>Participants' positive responses supported the need for FAME\u2010iSS for people with SSc. Even with the small sample, FAME\u2010iSS led to improvements in fatigue and use of energy conservation strategies. The online format allowed for participation and sharing of ideas, especially during the global pandemic.<\/jats:p><\/jats:sec>","DOI":"10.1002\/msc.1617","type":"journal-article","created":{"date-parts":[[2022,2,6]],"date-time":"2022-02-06T09:08:20Z","timestamp":1644138500000},"page":"593-604","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":14,"title":["Fatigue and activity management education for individuals with systemic sclerosis: Adaptation and feasibility study of an intervention for a rare disease"],"prefix":"10.1002","volume":"20","author":[{"given":"Kristine","family":"Carandang","sequence":"first","affiliation":[{"name":"Child and Adolescent Services Research Center  San Diego California USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Janet","family":"Poole","sequence":"additional","affiliation":[{"name":"Occupational Therapy Graduate Program University of New Mexico  Albuquerque New Mexico USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-8539-8123","authenticated-orcid":false,"given":"Deirdre","family":"Connolly","sequence":"additional","affiliation":[{"name":"Discipline of Occupational Therapy School of Medicine Trinity College Dublin  Dublin Ireland"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2022,2,6]]},"reference":[{"key":"e_1_2_11_2_1","doi-asserted-by":"publisher","DOI":"10.1371\/journal.pone.0026061"},{"key":"e_1_2_11_3_1","doi-asserted-by":"publisher","DOI":"10.1080\/09638288.2017.1323023"},{"key":"e_1_2_11_4_1","doi-asserted-by":"publisher","DOI":"10.1037\/0033-295X.84.2.191"},{"issue":"4","key":"e_1_2_11_5_1","first-page":"150","article-title":"Fatigue in systemic sclerosis: A systematic review","volume":"36","author":"Basta F.","year":"2018","journal-title":"Clinical and Experimental Rheumatology"},{"issue":"4","key":"e_1_2_11_6_1","first-page":"639","article-title":"Comparison of self\u2010reported fatigue in rheumatoid arthritis and controls","volume":"22","author":"Belza B. 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