{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,21]],"date-time":"2026-09-21T12:09:17Z","timestamp":1789992557967,"version":"4.0.1"},"reference-count":36,"publisher":"Wiley","issue":"6","license":[{"start":{"date-parts":[[2015,6,1]],"date-time":"2015-06-01T00:00:00Z","timestamp":1433116800000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Muscle and Nerve"],"published-print":{"date-parts":[[2015,12]]},"abstract":"<jats:title>ABSTRACT<\/jats:title><jats:p><jats:italic>Introduction<\/jats:italic>: Camptocormia is the involuntary flexion of the thoracolumbar spine leading to an abnormal posture. <jats:italic>Methods<\/jats:italic>: We retrospectively identified patients with myopathy who manifested with camptocormia and were seen in our neuromuscular clinic. The diagnosis of myopathy was based on myopathic electromyographic changes, often accompanied by 1 or more of the following: elevated creatine kinase (CK); myopathic histopathological findings; and genetic confirmation. <jats:italic>Results<\/jats:italic>: Fifty\u2010two patients were identified; 35 had symptoms limited to camptocormia, but were found to have additional weakness of facial (8 patients), neck (11 patients), and limb muscles (17 patients). CK values were normal or mildly to moderately elevated. MRI\/CT of the spine showed paraspinal muscle atrophy and fat replacement. Facioscapulohumeral muscular dystrophy and sporadic inclusion body myositis were the most commonly identified myopathies in this cohort. <jats:italic>Conclusions<\/jats:italic>: Despite the difficulty in characterizing the myopathy in patients with camptocormia, a definitive diagnosis was possible in 54% of cases. The pattern of associated extra\u2010axial weakness may provide clues to the diagnosis. <jats:italic>Muscle Nerve<\/jats:italic> <jats:bold>52<\/jats:bold>: 1008\u20131012, 2015<\/jats:p>","DOI":"10.1002\/mus.24689","type":"journal-article","created":{"date-parts":[[2015,4,21]],"date-time":"2015-04-21T23:06:00Z","timestamp":1429657560000},"page":"1008-1012","source":"Crossref","is-referenced-by-count":36,"title":["Camptocormia as presenting manifestation of a spectrum of myopathic disorders"],"prefix":"10.1002","volume":"52","author":[{"given":"Partha S.","family":"Ghosh","sequence":"first","affiliation":[{"name":"Department of Neurology Boston Children's Hospital Boston Massachusetts USA"},{"name":"Department of Neurology Mayo Clinic 200 First Street SW Rochester Minnesota 55905 USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Margherita","family":"Milone","sequence":"additional","affiliation":[{"name":"Department of Neurology Mayo Clinic 200 First Street SW Rochester Minnesota 55905 USA"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2015,6]]},"reference":[{"key":"e_1_2_7_2_1","doi-asserted-by":"publisher","DOI":"10.1002\/mds.22780"},{"key":"e_1_2_7_3_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.clineuro.2005.07.004"},{"key":"e_1_2_7_4_1","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp.2006.087908"},{"key":"e_1_2_7_5_1","doi-asserted-by":"publisher","DOI":"10.1159\/000314897"},{"key":"e_1_2_7_6_1","doi-asserted-by":"publisher","DOI":"10.2340\/16501977-0252"},{"key":"e_1_2_7_7_1","first-page":"466","article-title":"Parkinsonism and camptocormia with focal spinal myopathy: case report and responsiveness to treatment","volume":"43","author":"Diaz\u2010Guzman J","year":"2006","journal-title":"Rev Neurol"},{"key":"e_1_2_7_8_1","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp.73.1.1"},{"key":"e_1_2_7_9_1","doi-asserted-by":"publisher","DOI":"10.1212\/01.wnl.0000171857.09079.9f"},{"key":"e_1_2_7_10_1","doi-asserted-by":"publisher","DOI":"10.1136\/bmj.2.3023.621"},{"key":"e_1_2_7_11_1","doi-asserted-by":"publisher","DOI":"10.3109\/17482960903426543"},{"key":"e_1_2_7_12_1","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp-2011-300311"},{"key":"e_1_2_7_13_1","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp.2008.155770"},{"key":"e_1_2_7_14_1","doi-asserted-by":"publisher","DOI":"10.1097\/CND.0b013e3182650718"},{"key":"e_1_2_7_15_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.jocn.2013.06.004"},{"key":"e_1_2_7_16_1","doi-asserted-by":"publisher","DOI":"10.1002\/mus.21403"},{"key":"e_1_2_7_17_1","doi-asserted-by":"publisher","DOI":"10.1016\/S0248-8663(01)00530-6"},{"key":"e_1_2_7_18_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.jbspin.2007.11.008"},{"key":"e_1_2_7_19_1","first-page":"1121","article-title":"An unrecognized cause of camptocormia: proximal myotonic myopathy","volume":"29","author":"Serratrice J","year":"2000","journal-title":"Presse Med"},{"key":"e_1_2_7_20_1","doi-asserted-by":"publisher","DOI":"10.1007\/s00586-009-1086-6"},{"key":"e_1_2_7_21_1","doi-asserted-by":"publisher","DOI":"10.1007\/s00415-010-5858-z"},{"key":"e_1_2_7_22_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.ajhg.2007.09.004"},{"key":"e_1_2_7_23_1","doi-asserted-by":"publisher","DOI":"10.1002\/mus.20910"},{"key":"e_1_2_7_24_1","doi-asserted-by":"publisher","DOI":"10.1002\/mus.23497"},{"key":"e_1_2_7_25_1","doi-asserted-by":"publisher","DOI":"10.1097\/CND.0b013e3182461a9c"},{"key":"e_1_2_7_26_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.nmd.2012.06.004"},{"key":"e_1_2_7_27_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.lpm.2012.11.007"},{"key":"e_1_2_7_28_1","doi-asserted-by":"publisher","DOI":"10.1001\/jamaneurol.2013.3209"},{"key":"e_1_2_7_29_1","doi-asserted-by":"publisher","DOI":"10.1097\/00007632-199505000-00007"},{"key":"e_1_2_7_30_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.jbspin.2010.05.012"},{"issue":"10","key":"e_1_2_7_31_1","article-title":"Myopathy as a cause of camptocormia: a prospective study","volume":"82","author":"Chanson JB","year":"2014","journal-title":"Neurology"},{"key":"e_1_2_7_32_1","doi-asserted-by":"publisher","DOI":"10.1093\/brain\/112.3.727"},{"key":"e_1_2_7_33_1","doi-asserted-by":"publisher","DOI":"10.1002\/mus.24060"},{"key":"e_1_2_7_34_1","doi-asserted-by":"publisher","DOI":"10.1002\/(SICI)1097-4598(199703)20:3<373::AID-MUS19>3.0.CO;2-1"},{"key":"e_1_2_7_35_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.ymgme.2013.08.005"},{"key":"e_1_2_7_36_1","doi-asserted-by":"publisher","DOI":"10.1007\/s11910-010-0092-8"},{"key":"e_1_2_7_37_1","doi-asserted-by":"publisher","DOI":"10.1136\/jnnp-2013-307447"}],"container-title":["Muscle &amp; 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