{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,7,30]],"date-time":"2025-07-30T10:09:46Z","timestamp":1753870186837,"version":"3.41.2"},"reference-count":7,"publisher":"Wiley","issue":"2","license":[{"start":{"date-parts":[[2018,11,28]],"date-time":"2018-11-28T00:00:00Z","timestamp":1543363200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Respirology Case Reports"],"published-print":{"date-parts":[[2019,2]]},"abstract":"<jats:p>A 45\u2010year\u2010old lady presented acutely with pleuritic chest pain, haemoptysis, and dyspnoea. Her background was significant for a 1.4 cm renal angiomyolipoma, and she was an ex\u2010smoker without any relevant family history. A computed tomography (CT) pulmonary angiogram was negative for a pulmonary embolism but demonstrated diffuse cystic change throughout both lungs. A bronchoscopy confirmed a normal endobronchial tree, and pulmonary function tests demonstrated moderate airways obstruction, with reversibility and a normal diffusion capacity for carbon monoxide (DLCO). A video\u2010assisted thoracoscopic surgery (VATS) lung biopsy showed non\u2010caseating granulomas, and serum angiotensin converting enzyme (ACE) was elevated consistent with a diagnosis of pulmonary sarcoidosis. Further sectioning indicated focal areas that stained positive for Human Melanoma Black 45 (HMB\u201045), confirming lymphangioleiomyomatosis (LAM). A diagnosis of cystic lung disease secondary to coexistent sarcoidosis and LAM was made.<\/jats:p>","DOI":"10.1002\/rcr2.389","type":"journal-article","created":{"date-parts":[[2018,11,29]],"date-time":"2018-11-29T03:09:35Z","timestamp":1543460975000},"update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":0,"title":["Coexistent sarcoidosis and lymphangioleiomyomatosis in a patient with cystic lung disease"],"prefix":"10.1002","volume":"7","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-4831-2268","authenticated-orcid":false,"given":"Sarah","family":"Cullivan","sequence":"first","affiliation":[{"name":"Department of Respiratory Medicine Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Peter","family":"De La Harpe Golden","sequence":"additional","affiliation":[{"name":"Department of Pathology Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Deirdre","family":"Doyle","sequence":"additional","affiliation":[{"name":"Department of Radiology Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kishore Kumar","family":"Doddakula","sequence":"additional","affiliation":[{"name":"Department of Cardiothoracic Surgery Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Louise","family":"Burke","sequence":"additional","affiliation":[{"name":"Department of Pathology Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Desmond Michael","family":"Murphy","sequence":"additional","affiliation":[{"name":"Department of Respiratory Medicine Cork University Hospital  Ireland"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2018,11,28]]},"reference":[{"key":"e_1_2_6_2_1","doi-asserted-by":"publisher","DOI":"10.2147\/TCRM.S50784"},{"key":"e_1_2_6_3_1","doi-asserted-by":"publisher","DOI":"10.1148\/rg.306105512"},{"key":"e_1_2_6_4_1","doi-asserted-by":"publisher","DOI":"10.1164\/rccm.201607-1384ST"},{"key":"e_1_2_6_5_1","doi-asserted-by":"publisher","DOI":"10.1378\/chest.100.6.1726"},{"key":"e_1_2_6_6_1","doi-asserted-by":"publisher","DOI":"10.1177\/1066896915617028"},{"key":"e_1_2_6_7_1","doi-asserted-by":"publisher","DOI":"10.1186\/s12890-017-0447-x"},{"key":"e_1_2_6_8_1","doi-asserted-by":"publisher","DOI":"10.1038\/ni.3655"}],"container-title":["Respirology Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.wiley.com\/onlinelibrary\/tdm\/v1\/articles\/10.1002%2Frcr2.389","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/pdf\/10.1002\/rcr2.389","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,9,15]],"date-time":"2023-09-15T13:00:50Z","timestamp":1694782850000},"score":1,"resource":{"primary":{"URL":"https:\/\/onlinelibrary.wiley.com\/doi\/10.1002\/rcr2.389"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2018,11,28]]},"references-count":7,"journal-issue":{"issue":"2","published-print":{"date-parts":[[2019,2]]}},"alternative-id":["10.1002\/rcr2.389"],"URL":"https:\/\/doi.org\/10.1002\/rcr2.389","archive":["Portico"],"relation":{},"ISSN":["2051-3380","2051-3380"],"issn-type":[{"type":"print","value":"2051-3380"},{"type":"electronic","value":"2051-3380"}],"subject":[],"published":{"date-parts":[[2018,11,28]]},"assertion":[{"value":"2018-09-30","order":0,"name":"received","label":"Received","group":{"name":"publication_history","label":"Publication History"}},{"value":"2018-10-31","order":1,"name":"accepted","label":"Accepted","group":{"name":"publication_history","label":"Publication History"}},{"value":"2018-11-28","order":2,"name":"published","label":"Published","group":{"name":"publication_history","label":"Publication History"}}],"article-number":"e00389"}}