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A 17\u2010year\u2010old patient with severe haemoptysis who was diagnosed with right pulmonary artery agenesis, associated with hypertrophy of the homolateral bronchial arteries and numerous systemic collaterals. Despite three embolisation procedures, a high\u2010risk of recurrence required pneumonectomy. A 45\u2010year\u2010old patient with tetralogy of Fallot and a known left pulmonary artery agenesis presented with 300\u2009mL haemoptysis. The attempt of embolisation and closure of a communication between the circumflex artery and the bronchial arterial network failed, leading to left pneumonectomy. Every case of haemoptysis requires a chest CT scan, among other reasons, in order to identify potential UPAA. Management must be multidisciplinary, often involving surgery.<\/jats:p>","DOI":"10.1002\/rcr2.70196","type":"journal-article","created":{"date-parts":[[2025,4,25]],"date-time":"2025-04-25T10:27:18Z","timestamp":1745576838000},"update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":0,"title":["Severe Haemoptysis due to Pulmonary Artery Agenesis, About Two Rare but Threatening Case Reports"],"prefix":"10.1002","volume":"13","author":[{"ORCID":"https:\/\/orcid.org\/0009-0007-7719-7453","authenticated-orcid":false,"given":"Marina","family":"Gue\u00e7amburu","sequence":"first","affiliation":[{"name":"Service Des Maladies Respiratoires, H\u00f4pital Haut Leveque CHU de Bordeaux  Pessac France"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Anne\u2010Claire","family":"Toublanc","sequence":"additional","affiliation":[{"name":"Service Des Maladies Respiratoires, H\u00f4pital Haut Leveque CHU de Bordeaux  Pessac 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