{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,18]],"date-time":"2026-06-18T14:56:03Z","timestamp":1781794563632,"version":"3.54.5"},"reference-count":11,"publisher":"Springer Science and Business Media LLC","issue":"1","license":[{"start":{"date-parts":[[2026,6,18]],"date-time":"2026-06-18T00:00:00Z","timestamp":1781740800000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"},{"start":{"date-parts":[[2026,6,18]],"date-time":"2026-06-18T00:00:00Z","timestamp":1781740800000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"}],"funder":[{"DOI":"10.13039\/501100006451","name":"Hospices Civils de Lyon","doi-asserted-by":"crossref","id":[{"id":"10.13039\/501100006451","id-type":"DOI","asserted-by":"crossref"}]}],"content-domain":{"domain":["link.springer.com"],"crossmark-restriction":false},"short-container-title":["Childs Nerv Syst"],"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Purpose<\/jats:title>\n                    <jats:p>Supernumerary breasts (polymastia) and supernumerary nipples (polythelia) are congenital anomalies resulting from incomplete regression of the embryonic mammary ridge. They most frequently occur along the embryologic milk line extending from the axilla to the groin. Ectopic localization outside this line is rare, and dorsal presentations are exceptional. In such cases, an association with underlying spinal dysraphism has occasionally been reported.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Methods<\/jats:title>\n                    <jats:p>We report the case of an 11-year-old girl presenting with a congenital dorsal midline swelling initially diagnosed as a lipoma. Progressive enlargement and the appearance of a central pigmented structure prompted further evaluation. Clinical examination confirmed a dorsal midline areola-nipple complex with underlying tumefaction. Spinal MRI demonstrated an intradural lipoma at the T4 level associated with a fibrous tract extending toward the cutaneous lesion, resulting in a tethered cord configuration.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>The patient underwent combined resection of the ectopic mammary tissue and neurosurgical detethering with partial lipoma resection. Postoperative recovery was uneventful with no neurological deficit.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion<\/jats:title>\n                    <jats:p>Dorsal midline ectopic mammary tissue is extremely rare and may represent a cutaneous marker underlying spinal dysraphism. Careful clinical examination and spinal imaging should therefore be considered in such atypical presentations.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1007\/s00381-026-07350-5","type":"journal-article","created":{"date-parts":[[2026,6,18]],"date-time":"2026-06-18T14:38:51Z","timestamp":1781793531000},"update-policy":"https:\/\/doi.org\/10.1007\/springer_crossmark_policy","source":"Crossref","is-referenced-by-count":0,"title":["Dorsal midline ectopic mammary tissue as a cutaneous marker of spinal dysraphism: intradural lipoma and tethered cord in a child with literature review"],"prefix":"10.1007","volume":"42","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-2276-5376","authenticated-orcid":false,"given":"Paula","family":"Alcazar","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"H\u00e9l\u00e8ne","family":"Person","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Federico","family":"Di Rocco","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Lisa","family":"Boudy","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Camilla","family":"de Laurentis","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"C\u00e9cile","family":"Picard","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Alexandre","family":"Vasiljevic","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Alexandru","family":"Szathmari","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Pierre-Aur\u00e9lien","family":"Beuriat","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"297","published-online":{"date-parts":[[2026,6,18]]},"reference":[{"key":"7350_CR1","volume-title":"Langman\u2019s medical embryology","author":"TW Sadler","year":"2012","unstructured":"Sadler TW (2012) Langman\u2019s medical embryology, 12th ed. Lippincott Williams & Wilkins, Philadelphia","edition":"12th ed"},{"key":"7350_CR2","doi-asserted-by":"crossref","unstructured":"Grossl NA (2000) Supernumerary breast tissue: historical perspectives and clinical features. South Med J 93(1):29\u201332","DOI":"10.1097\/00007611-200001000-00004"},{"key":"7350_CR3","doi-asserted-by":"crossref","unstructured":"Loukas M, Clarke P, Tubbs RS (2007) Accessory breasts: a historical and current perspective. Am Surg 73(5):525\u2013528","DOI":"10.1177\/000313480707300522"},{"issue":"10","key":"7350_CR4","doi-asserted-by":"publisher","first-page":"821","DOI":"10.1007\/s004310050944","volume":"157","author":"H Schmidt","year":"1998","unstructured":"Schmidt H (1998) Supernumerary nipples: prevalence, size, sex and side predilection \u2014 a prospective clinical study. Eur J Pediatr 157(10):821\u20133. https:\/\/doi.org\/10.1007\/s004310050944","journal-title":"Eur J Pediatr"},{"issue":"9","key":"7350_CR5","doi-asserted-by":"publisher","first-page":"903","DOI":"10.1097\/00007611-199509000-00002","volume":"88","author":"V Velanovich","year":"1995","unstructured":"Velanovich V (1995) Ectopic breast tissue, supernumerary breasts, and supernumerary nipples. South Med J 88(9):903\u20136. https:\/\/doi.org\/10.1097\/00007611-199509000-00002","journal-title":"South Med J"},{"issue":"7","key":"7350_CR6","doi-asserted-by":"publisher","DOI":"10.1093\/jscr\/rjae441","volume":"2024","author":"M Ismail","year":"2024","unstructured":"Ismail M, Thet MS, Khan KU, Ullah N (2024) Dorsal ectopic breast-a cutaneous marker of occult spinal dysraphism. J Surg Case Rep 2024(7):rjae441. https:\/\/doi.org\/10.1093\/jscr\/rjae441","journal-title":"J Surg Case Rep"},{"key":"7350_CR7","doi-asserted-by":"publisher","unstructured":"Hertzler DA 2nd, DePowell JJ, Stevenson CB, Mangano FT (2010) Tethered cord syndrome: a review of the literature from embryology to adult presentation. Neurosurg Focus 29(1):E1. https:\/\/doi.org\/10.3171\/2010.3.FOCUS1079","DOI":"10.3171\/2010.3.FOCUS1079"},{"issue":"1","key":"7350_CR8","doi-asserted-by":"publisher","first-page":"1","DOI":"10.3171\/foc.2001.10.1.2","volume":"10","author":"DE Warder","year":"2001","unstructured":"Warder DE (2001) Tethered cord syndrome and occult spinal dysraphism. Neurosurg Focus 10(1):1\u20139. https:\/\/doi.org\/10.3171\/foc.2001.10.1.2","journal-title":"Neurosurg Focus"},{"issue":"3","key":"7350_CR9","doi-asserted-by":"publisher","first-page":"392","DOI":"10.4103\/0028-3886.158220","volume":"63","author":"VK Gupta","year":"2015","unstructured":"Gupta VK, Kapoor I, Punia RS, Attri AK (2015) Dorsal ectopic breast in a case of spinal dysraphism: a rare entity. Neurol India 63(3):392\u20134. https:\/\/doi.org\/10.4103\/0028-3886.158220","journal-title":"Neurol India"},{"key":"7350_CR10","doi-asserted-by":"publisher","unstructured":"Gandhoke CS, Syal SK, Singh H, Singh D, Saran RK (2018) Dorsal accessory ectopic breast with polythelia - a marker of occult spinal dysraphism. Surg Neurol Int 24(9):143.\u00a0https:\/\/doi.org\/10.4103\/sni.sni_34_18","DOI":"10.4103\/sni.sni_34_18"},{"issue":"7","key":"7350_CR11","doi-asserted-by":"publisher","first-page":"471","DOI":"10.1007\/s002340000325","volume":"42","author":"P Tortori-Donati","year":"2000","unstructured":"Tortori-Donati P, Rossi A, Cama A (2000) Spinal dysraphism: a review of neuroradiological features with embryological correlations and proposal for a new classification. Neuroradiology 42(7):471\u201391. https:\/\/doi.org\/10.1007\/s002340000325","journal-title":"Neuroradiology"}],"container-title":["Child's Nervous System"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/link.springer.com\/content\/pdf\/10.1007\/s00381-026-07350-5.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/link.springer.com\/article\/10.1007\/s00381-026-07350-5","content-type":"text\/html","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/link.springer.com\/content\/pdf\/10.1007\/s00381-026-07350-5.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,6,18]],"date-time":"2026-06-18T14:38:54Z","timestamp":1781793534000},"score":1,"resource":{"primary":{"URL":"https:\/\/link.springer.com\/10.1007\/s00381-026-07350-5"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,6,18]]},"references-count":11,"journal-issue":{"issue":"1","published-online":{"date-parts":[[2026,12]]}},"alternative-id":["7350"],"URL":"https:\/\/doi.org\/10.1007\/s00381-026-07350-5","relation":{},"ISSN":["1433-0350"],"issn-type":[{"value":"1433-0350","type":"electronic"}],"subject":[],"published":{"date-parts":[[2026,6,18]]},"assertion":[{"value":"15 April 2026","order":1,"name":"received","label":"Received","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"10 June 2026","order":2,"name":"accepted","label":"Accepted","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"18 June 2026","order":3,"name":"first_online","label":"First Online","group":{"name":"ArticleHistory","label":"Article History"}},{"order":1,"name":"Ethics","group":{"name":"EthicsHeading","label":"Declarations"}},{"value":"The patient\u2019s medical records were reviewed in accordance with our institution\u2019s confidentiality and data protection protocols. Written informed consent was obtained from the patient and her legal guardians for the use of clinical information and the publication of accompanying images.","order":2,"name":"Ethics","group":{"name":"EthicsHeading","label":"Ethical approval"}},{"value":"The authors declare no competing interests.","order":3,"name":"Ethics","group":{"name":"EthicsHeading","label":"Competing interest"}}],"article-number":"255"}}