{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,28]],"date-time":"2026-07-28T21:12:31Z","timestamp":1785273151216,"version":"3.55.0"},"reference-count":12,"publisher":"Springer Science and Business Media LLC","issue":"9","license":[{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"vor","delay-in-days":0,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0"}],"funder":[{"DOI":"10.13039\/501100004047","name":"Karolinska Institute","doi-asserted-by":"crossref","id":[{"id":"10.13039\/501100004047","id-type":"DOI","asserted-by":"crossref"}]}],"content-domain":{"domain":["link.springer.com"],"crossmark-restriction":false},"short-container-title":["Acta Neurochir"],"abstract":"<jats:title>Abstract<\/jats:title><jats:p>Spinal arachnoid cysts (SACs) arise either intra- or extradurally and are usually solitary, while cases of multiple SACs have been scarcely reported in the literature. Herein, we report on a rare case of multiple and recurring intradural spinal arachnoid cysts (SACs) causing severe spinal cord compression and neuropathic radicular pain, in a 35-year-old female with a 10-year follow-up. Two separate attempts at surgery were performed but only provided temporary relief since the cysts recurred and new ones formed along the entirety of the spinal cord. Finally, a conservative approach with physiotherapy and a combination of analgesic medications was pursued.<\/jats:p>","DOI":"10.1007\/s00701-023-05732-1","type":"journal-article","created":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T05:02:01Z","timestamp":1690866121000},"page":"2699-2705","update-policy":"https:\/\/doi.org\/10.1007\/springer_crossmark_policy","source":"Crossref","is-referenced-by-count":3,"title":["An unusual cause of chronic neuropathic pain: report of a case of multiple intradural spinal arachnoid cysts and review of the literature"],"prefix":"10.1007","volume":"165","author":[{"given":"Victor Gabriel","family":"El-Hajj","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Erik","family":"Edstr\u00f6m","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3776-6136","authenticated-orcid":false,"given":"Adrian","family":"Elmi-Terander","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Alexander","family":"Fletcher-Sandersj\u00f6\u00f6","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"297","published-online":{"date-parts":[[2023,8,1]]},"reference":[{"key":"5732_CR1","doi-asserted-by":"publisher","first-page":"e298","DOI":"10.1016\/j.wneu.2021.10.173","volume":"158","author":"A Baig Mirza","year":"2022","unstructured":"Baig Mirza A, Bartram J, Vastani A, Gebreyohanes A, Al Banna Q, Lavrador JP, Vasan AK, Grahovac G (2022) Systematic review of surgical management of spinal intradural arachnoid cysts. World Neurosurg 158:e298\u2013e309","journal-title":"World Neurosurg"},{"key":"5732_CR2","doi-asserted-by":"publisher","DOI":"10.1186\/1757-1626-2-7531","author":"MA Bitaraf","year":"2009","unstructured":"Bitaraf MA, Zeinalizadeh M, Meybodi AT, Meybodi KT, Habibi Z (2009) Multiple extradural spinal arachnoid cysts: a case report and review of the literature. Cases J. https:\/\/doi.org\/10.1186\/1757-1626-2-7531","journal-title":"Cases J"},{"key":"5732_CR3","doi-asserted-by":"crossref","unstructured":"El-Hajj VG, Singh A, Pham K, Edstr\u00f6m E, Elmi-Terander A, Fletcher-Sandersj\u00f6\u00f6 A (2023) Long-term outcomes following surgical treatment of spinal arachnoid cysts: a population-based consecutive cohort study. [Unpublished manuscript]","DOI":"10.1016\/j.spinee.2023.08.011"},{"issue":"4","key":"5732_CR4","doi-asserted-by":"publisher","first-page":"657","DOI":"10.1007\/s00381-012-1990-7","volume":"29","author":"P Evangelou","year":"2013","unstructured":"Evangelou P, Meixensberger J, Bernhard M, Hirsch W, Kiess W, Merkenschlager A, Nestler U, Preuss M (2013) Operative management of idiopathic spinal intradural arachnoid cysts in children: a systematic review. Childs Nerv Syst 29(4):657\u2013664","journal-title":"Childs Nerv Syst"},{"issue":"4","key":"5732_CR5","doi-asserted-by":"publisher","first-page":"535","DOI":"10.1177\/197140091102400407","volume":"24","author":"ER G\u00f3mez","year":"2011","unstructured":"G\u00f3mez ER, Quiles AM, Pedraza S (2011) Spinal arachnoid cyst as an infrequent cause of spinal cord compression. 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Br J Neurosurg 5(1):77\u201382","journal-title":"Br J Neurosurg"},{"key":"5732_CR8","doi-asserted-by":"publisher","DOI":"10.1016\/j.bas.2022.100904","volume":"2","author":"P Kalsi","year":"2022","unstructured":"Kalsi P, Hejrati N, Charalampidis A, Wu PH, Schneider M, Wilson JRF, Gao AF, Massicotte EM, Fehlings MG (2022) Spinal arachnoid cysts: a case series & systematic review of the literature. Brain Spine 2:100904","journal-title":"Brain Spine"},{"issue":"2","key":"5732_CR9","doi-asserted-by":"publisher","first-page":"94","DOI":"10.1007\/BF01138190","volume":"20","author":"K Osuka","year":"1997","unstructured":"Osuka K, Takayasu M, Tanazawa T, Ichihara K, Itoh Y (1997) Multiple communicating intradural arachnoid cysts: usefulness of myelography and myelo-computed tomography using both lumbar and cervical punctures. Case report. 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Surg Neurol Int 7(18):S473\u2013S474","journal-title":"Surg Neurol Int"}],"container-title":["Acta Neurochirurgica"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/link.springer.com\/content\/pdf\/10.1007\/s00701-023-05732-1.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/link.springer.com\/article\/10.1007\/s00701-023-05732-1\/fulltext.html","content-type":"text\/html","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/link.springer.com\/content\/pdf\/10.1007\/s00701-023-05732-1.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,9,4]],"date-time":"2023-09-04T08:19:57Z","timestamp":1693815597000},"score":1,"resource":{"primary":{"URL":"https:\/\/link.springer.com\/10.1007\/s00701-023-05732-1"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2023,8,1]]},"references-count":12,"journal-issue":{"issue":"9","published-online":{"date-parts":[[2023,9]]}},"alternative-id":["5732"],"URL":"https:\/\/doi.org\/10.1007\/s00701-023-05732-1","relation":{},"ISSN":["0942-0940"],"issn-type":[{"value":"0942-0940","type":"electronic"}],"subject":[],"published":{"date-parts":[[2023,8,1]]},"assertion":[{"value":"22 June 2023","order":1,"name":"received","label":"Received","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"22 July 2023","order":2,"name":"accepted","label":"Accepted","group":{"name":"ArticleHistory","label":"Article History"}},{"value":"1 August 2023","order":3,"name":"first_online","label":"First Online","group":{"name":"ArticleHistory","label":"Article History"}},{"order":1,"name":"Ethics","group":{"name":"EthicsHeading","label":"Declarations"}},{"value":"This report is in accordance with all ethical guidelines and was approved by the regional ethical committee (Dnr: 2016\/1708\u201331\/4).","order":2,"name":"Ethics","group":{"name":"EthicsHeading","label":"Ethics approval"}},{"value":"Written informed consent was obtained from the patient for publication of this case report and accompanying images.","order":3,"name":"Ethics","group":{"name":"EthicsHeading","label":"Consent to participate"}},{"value":"The authors declare no competing interests.","order":4,"name":"Ethics","group":{"name":"EthicsHeading","label":"Conflict of interest"}}]}}