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In two cases, yellow-tan nodules were grossly visible in the myocardium; in the third case, no gross lesions were identified. Microscopic examination in all three cases revealed multiple, scattered clusters of histiocytoid myocytes which on ultrastructural examination were filled with abnormal mitochondria, scattered lipid droplets, and scanty myofibrils. These pathologic findings are similar to those previously described. The pathogenesis of this entity remains controversial. It was recently proposed that this disorder is X-linked dominant with the associated gene located in the region of Xp22. <\/jats:p>","DOI":"10.1007\/s100249900007","type":"journal-article","created":{"date-parts":[[2002,7,25]],"date-time":"2002-07-25T06:40:57Z","timestamp":1027579257000},"page":"56-69","source":"Crossref","is-referenced-by-count":65,"title":["Histiocytoid Cardiomyopathy: Three New Cases and a Review of the Literature"],"prefix":"10.1177","volume":"1","author":[{"given":"Bahig M.","family":"Shehata","sequence":"first","affiliation":[{"name":"Department of Pathology, Children's Medical Center of Northwest Ohio, 2142 North Cove Boulevard, Toledo, OH 43606, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kathleen","family":"Patterson","sequence":"additional","affiliation":[{"name":"Department of Pathology, Children's Hospital and Medical Center, 4800 Sandpoint Way NE, Seattle, WA 98105, USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Jean E.","family":"Thomas","sequence":"additional","affiliation":[{"name":"Medical College of Ohio, 3000 Arlington Avenue, P.O. 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