{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,10,16]],"date-time":"2026-10-16T13:18:49Z","timestamp":1792156729515,"version":"4.4.0"},"reference-count":35,"publisher":"Elsevier BV","license":[{"start":{"date-parts":[[2025,10,1]],"date-time":"2025-10-01T00:00:00Z","timestamp":1759276800000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"},{"start":{"date-parts":[[2025,10,1]],"date-time":"2025-10-01T00:00:00Z","timestamp":1759276800000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/legal\/tdmrep-license"}],"content-domain":{"domain":["clinicalkey.com","clinicalkey.com.au","clinicalkey.es","clinicalkey.fr","clinicalkey.jp","jprasurg.com","elsevier.com","sciencedirect.com"],"crossmark-restriction":true},"short-container-title":["Journal of Plastic, Reconstructive &amp; Aesthetic Surgery"],"published-print":{"date-parts":[[2025,10]]},"DOI":"10.1016\/j.bjps.2025.08.013","type":"journal-article","created":{"date-parts":[[2025,8,21]],"date-time":"2025-08-21T09:02:10Z","timestamp":1755766930000},"page":"137-143","update-policy":"https:\/\/doi.org\/10.1016\/elsevier_cm_policy","source":"Crossref","is-referenced-by-count":1,"special_numbering":"C","title":["Skeletal and endocrine manifestations of McCune-Albright syndrome in patients with fibrous dysplasia"],"prefix":"10.1016","volume":"109","author":[{"given":"Alexandre Meira","family":"Pazelli","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jainaha K.","family":"Srikumar","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0009-0004-4914-7369","authenticated-orcid":false,"given":"Aidin","family":"Gharavi","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Gregory J.","family":"Griepentrog","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Ethylin Wang","family":"Jabs","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Steven","family":"Moran","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-9950-3668","authenticated-orcid":false,"given":"Todd","family":"Milbrandt","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-6434-4676","authenticated-orcid":false,"given":"Samir","family":"Mardini","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Waleed","family":"Gibreel","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"78","reference":[{"issue":"17","key":"10.1016\/j.bjps.2025.08.013_bib1","doi-asserted-by":"crossref","first-page":"727","DOI":"10.1056\/NEJM193704292161701","article-title":"syndrome characterized by osteitis fibrosa disseminata, areas of pigmentation and endocrine dysfunction, with precocious puberty in females","volume":"216","author":"Albright","year":"1937","journal-title":"N Engl J Med"},{"issue":"4","key":"10.1016\/j.bjps.2025.08.013_bib2","doi-asserted-by":"crossref","first-page":"806","DOI":"10.1001\/archpedi.1937.01980040110009","article-title":"Osteodystrophia fibrosa: report of a case in which the condition was combined with precocious puberty, pathologic pigmentation of the skin and hyperthyroidism, with a review of the literature","volume":"54","author":"Mccune","year":"1937","journal-title":"Am J Dis Child"},{"issue":"2","key":"10.1016\/j.bjps.2025.08.013_bib3","doi-asserted-by":"crossref","first-page":"147","DOI":"10.1007\/s11914-023-00779-6","article-title":"Craniofacial fibrous dysplasia: clinical and therapeutic implications","volume":"21","author":"Szymczuk","year":"2023","journal-title":"Curr Osteoporos Rep"},{"issue":"24","key":"10.1016\/j.bjps.2025.08.013_bib4","doi-asserted-by":"crossref","first-page":"1688","DOI":"10.1056\/NEJM199112123252403","article-title":"Activating mutations of the stimulatory G protein in the McCune\u2013Albright syndrome","volume":"325","author":"Weinstein","year":"1991","journal-title":"N Engl J Med"},{"issue":"6","key":"10.1016\/j.bjps.2025.08.013_bib5","doi-asserted-by":"crossref","first-page":"1833","DOI":"10.1097\/PRS.0000000000002151","article-title":"Surgical management of polyostotic craniofacial fibrous dysplasia: long-term outcomes and predictors for postoperative regrowth","volume":"137","author":"Boyce","year":"2016","journal-title":"Plast Reconstr Surg"},{"issue":"11","key":"10.1016\/j.bjps.2025.08.013_bib6","doi-asserted-by":"crossref","first-page":"5152","DOI":"10.1073\/pnas.89.11.5152","article-title":"Identification of a mutation in the gene encoding the alpha subunit of the stimulatory G protein of adenylyl cyclase in McCune-Albright syndrome","volume":"89","author":"Schwindinger","year":"1992","journal-title":"Proc Natl Acad Sci"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib7","doi-asserted-by":"crossref","first-page":"50","DOI":"10.1186\/s13023-024-03036-w","article-title":"Diagnostic journey for individuals with fibrous dysplasia \/ McCune albright syndrome (FD\/MAS)","volume":"19","author":"Song","year":"2024","journal-title":"Orphanet J Rare Dis"},{"issue":"7","key":"10.1016\/j.bjps.2025.08.013_bib8","doi-asserted-by":"crossref","first-page":"1462","DOI":"10.1002\/jbmr.1603","article-title":"Denosumab treatment for fibrous dysplasia","volume":"27","author":"Boyce","year":"2012","journal-title":"J Bone Miner Res"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib9","doi-asserted-by":"crossref","first-page":"E126","DOI":"10.1210\/jc.2012-2111","article-title":"Optic neuropathy in McCune-Albright syndrome: effects of early diagnosis and treatment of growth hormone excess","volume":"98","author":"Boyce","year":"2013","journal-title":"J Clin Endocrinol Metab"},{"issue":"2","key":"10.1016\/j.bjps.2025.08.013_bib10","doi-asserted-by":"crossref","first-page":"65","DOI":"10.1007\/s11914-013-0144-5","article-title":"Fibrous dysplasia and fibroblast growth factor-23 regulation","volume":"11","author":"Boyce","year":"2013","journal-title":"Curr Osteoporos Rep"},{"issue":"6","key":"10.1016\/j.bjps.2025.08.013_bib11","doi-asserted-by":"crossref","first-page":"697","DOI":"10.1111\/odi.12563","article-title":"Fibrous dysplasia of bone: craniofacial and dental implications","volume":"23","author":"Burke","year":"2017","journal-title":"Oral Dis"},{"issue":"5","key":"10.1016\/j.bjps.2025.08.013_bib12","doi-asserted-by":"crossref","first-page":"403","DOI":"10.1016\/0197-0070(91)90056-R","article-title":"Exacerbation of fibrous dysplasia associated with an adolescent pregnancy","volume":"12","author":"Stevens-Simon","year":"1991","journal-title":"J Adolesc Health"},{"issue":"20","key":"10.1016\/j.bjps.2025.08.013_bib13","doi-asserted-by":"crossref","first-page":"1964","DOI":"10.1056\/NEJMc1808583","article-title":"Mosaic effects of growth hormone on fibrous dysplasia of bone","volume":"379","author":"Roszko","year":"2018","journal-title":"N Engl J Med"},{"issue":"11","key":"10.1016\/j.bjps.2025.08.013_bib14","doi-asserted-by":"crossref","first-page":"5104","DOI":"10.1210\/jc.2001-012022","article-title":"Characterization of gsp-mediated growth hormone excess in the context of McCune-Albright syndrome","volume":"87","author":"Akintoye","year":"2002","journal-title":"J Clin Endocrinol Metab"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib15","doi-asserted-by":"crossref","first-page":"139","DOI":"10.1186\/s13023-019-1102-9","article-title":"Best practice management guidelines for fibrous dysplasia\/McCune-Albright syndrome: a consensus statement from the FD\/MAS international consortium","volume":"14","author":"Javaid","year":"2019","journal-title":"Orphanet J Rare Dis"},{"key":"10.1016\/j.bjps.2025.08.013_bib16","series-title":"GeneReviews\u00ae [Internet]","article-title":"Fibrous Dysplasia \/ McCune-Albright Syndrome","author":"Szymczuk","year":"2015"},{"issue":"4","key":"10.1016\/j.bjps.2025.08.013_bib17","doi-asserted-by":"crossref","first-page":"949","DOI":"10.1016\/S0031-3955(05)70444-2","article-title":"Benign pediatric bone tumors","volume":"43","author":"Copley","year":"1996","journal-title":"Eval Treat Pedia Clin North Am"},{"issue":"6","key":"10.1016\/j.bjps.2025.08.013_bib18","doi-asserted-by":"crossref","first-page":"1806","DOI":"10.1097\/SCS.0000000000005498","article-title":"Surgical treatment of polyostotic craniomaxillofacial fibrous dysplasia associated with acromegalia: the McCune \u2013 Albright syndrome","volume":"30","author":"Franco","year":"2019","journal-title":"J Craniofacial Surg"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib19","doi-asserted-by":"crossref","first-page":"55","DOI":"10.1016\/j.berh.2007.11.004","article-title":"Fibrous dysplasia of bone and McCune\u2013Albright syndrome","volume":"22","author":"Chapurlat","year":"2008","journal-title":"Best Pract Res Clin Rheumatol"},{"issue":"4","key":"10.1016\/j.bjps.2025.08.013_bib20","doi-asserted-by":"crossref","first-page":"511","DOI":"10.1016\/j.jbspin.2019.01.010","article-title":"McCune-Albright syndrome and the shepherd crook deformity","volume":"86","author":"Freitas","year":"2019","journal-title":"Jt Bone Spine"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib21","doi-asserted-by":"crossref","first-page":"64","DOI":"10.1302\/1863-2548.11.170002","article-title":"Treatment of shepherd's crook deformity in patients with polyostotic fibrous dysplasia using a new type of custom made retrograde intramedullary nail: a technical note","volume":"11","author":"Hefti","year":"2017","journal-title":"J Child's Orthop"},{"issue":"7","key":"10.1016\/j.bjps.2025.08.013_bib22","article-title":"A Shepherd's crook deformity of proximal femur treated by valgus osteotomy and bone grafting","volume":"13","author":"Pathak","year":"2021","journal-title":"Cureus"},{"issue":"3","key":"10.1016\/j.bjps.2025.08.013_bib23","doi-asserted-by":"crossref","first-page":"187","DOI":"10.1007\/s11751-013-0174-7","article-title":"Fibrous dysplasia, shepherd's crook deformity and an intra-capsular femoral neck fracture","volume":"8","author":"Al-Mouazzen","year":"2013","journal-title":"Strateg Trauma Limb Reconstr"},{"issue":"5","key":"10.1016\/j.bjps.2025.08.013_bib24","doi-asserted-by":"crossref","first-page":"178","DOI":"10.1007\/s11914-016-0317-0","article-title":"Fibrous dysplasia\/McCune-Albright syndrome: clinical and translational perspectives","volume":"14","author":"Robinson","year":"2016","journal-title":"Curr Osteoporos Rep"},{"key":"10.1016\/j.bjps.2025.08.013_bib25","doi-asserted-by":"crossref","first-page":"192","DOI":"10.1016\/j.jor.2020.03.014","article-title":"Lower limb lengthening and deformity correction in polyostotic fibrous dysplasia using external fixation and flexible intramedullary nailing","volume":"21","author":"Popkov","year":"2020","journal-title":"J Orthop"},{"issue":"3","key":"10.1016\/j.bjps.2025.08.013_bib26","doi-asserted-by":"crossref","first-page":"329","DOI":"10.5312\/wjo.v13.i3.329","article-title":"Surgical treatment of femoral deformities in polyostotic fibrous dysplasia and McCune-Albright syndrome: a literature review","volume":"13","author":"Gorgolini","year":"2022","journal-title":"World J Orthop"},{"issue":"7","key":"10.1016\/j.bjps.2025.08.013_bib27","doi-asserted-by":"crossref","first-page":"968","DOI":"10.1002\/jbmr.4818","article-title":"Coxa vara deformity in fibrous Dysplasia\/McCune-Albright syndrome: prevalence, natural history and risk factors: a two-center study","volume":"38","author":"Meier","year":"2023","journal-title":"J Bone Miner Res"},{"issue":"2","key":"10.1016\/j.bjps.2025.08.013_bib28","doi-asserted-by":"crossref","first-page":"236","DOI":"10.1002\/jbmr.4463","article-title":"Long bone fractures in fibrous Dysplasia\/McCune-Albright syndrome: prevalence, natural history, and risk factors","volume":"37","author":"Geels","year":"2021","journal-title":"J Bone Miner Res"},{"issue":"8","key":"10.1016\/j.bjps.2025.08.013_bib29","first-page":"1848","article-title":"Fibrous dysplasia. Pathophysiology, evaluation, and treatment","volume":"87","author":"DiCaprio","year":"2005","journal-title":"J Bone Jt Surg Am"},{"issue":"1","key":"10.1016\/j.bjps.2025.08.013_bib30","doi-asserted-by":"crossref","first-page":"S1","DOI":"10.1186\/1750-1172-7-S1-S1","article-title":"The surgical management of fibrous dysplasia of bone","volume":"7","author":"Stanton","year":"2012","journal-title":"Orphanet J Rare Dis"},{"issue":"2","key":"10.1016\/j.bjps.2025.08.013_bib31","doi-asserted-by":"crossref","first-page":"345","DOI":"10.1210\/endrev\/bnz011","article-title":"Fibrous Dysplasia\/McCune-Albright syndrome: a rare, mosaic disease of g\u03b1\u200as activation","volume":"41","author":"Boyce","year":"2020","journal-title":"Endocr Rev"},{"issue":"5","key":"10.1016\/j.bjps.2025.08.013_bib32","doi-asserted-by":"crossref","first-page":"2107","DOI":"10.1210\/jc.2003-031225","article-title":"European collaborative study. Activating Gsalpha mutations: analysis of 113 patients with signs of McCune-Albright syndrome--a European Collaborative Study","volume":"89","author":"Lumbroso","year":"2004","journal-title":"J Clin Endocrinol Metab"},{"issue":"4","key":"10.1016\/j.bjps.2025.08.013_bib33","doi-asserted-by":"crossref","first-page":"439","DOI":"10.1007\/s00402-008-0669-8","article-title":"Secondary osteosarcoma arising in fibrous dysplasia, case report","volume":"129","author":"Doganavsargil","year":"2009","journal-title":"Arch Orthop Trauma Surg"},{"issue":"2","key":"10.1016\/j.bjps.2025.08.013_bib34","doi-asserted-by":"crossref","first-page":"318","DOI":"10.1016\/j.prp.2017.10.018","article-title":"Osteosarcoma arising in fibrous dysplasia, confirmed by mutational analysis of GNAS gene","volume":"214","author":"Sugiura","year":"2018","journal-title":"Pathol Res Pr"},{"issue":"11","key":"10.1016\/j.bjps.2025.08.013_bib35","doi-asserted-by":"crossref","first-page":"2229.e1","DOI":"10.1016\/j.joms.2016.06.174","article-title":"Osteosarcoma of the mandible arising in fibrous dysplasia\u2014a case report","volume":"74","author":"Pack","year":"2016","journal-title":"J Oral Maxillofac Surg"}],"container-title":["Journal of Plastic, Reconstructive &amp; Aesthetic Surgery"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S1748681525005005?httpAccept=text\/xml","content-type":"text\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S1748681525005005?httpAccept=text\/plain","content-type":"text\/plain","content-version":"vor","intended-application":"text-mining"}],"deposited":{"date-parts":[[2025,10,24]],"date-time":"2025-10-24T01:32:25Z","timestamp":1761269545000},"score":1,"resource":{"primary":{"URL":"https:\/\/linkinghub.elsevier.com\/retrieve\/pii\/S1748681525005005"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,10]]},"references-count":35,"alternative-id":["S1748681525005005"],"URL":"https:\/\/doi.org\/10.1016\/j.bjps.2025.08.013","relation":{},"ISSN":["1748-6815"],"issn-type":[{"value":"1748-6815","type":"print"}],"subject":[],"published":{"date-parts":[[2025,10]]},"assertion":[{"value":"Elsevier","name":"publisher","label":"This article is maintained by"},{"value":"Skeletal and endocrine manifestations of McCune-Albright syndrome in patients with fibrous dysplasia","name":"articletitle","label":"Article Title"},{"value":"Journal of Plastic, Reconstructive & Aesthetic Surgery","name":"journaltitle","label":"Journal Title"},{"value":"https:\/\/doi.org\/10.1016\/j.bjps.2025.08.013","name":"articlelink","label":"CrossRef DOI link to publisher maintained version"},{"value":"article","name":"content_type","label":"Content Type"},{"value":"\u00a9 2025 British Association of Plastic, Reconstructive and Aesthetic Surgeons. Published by Elsevier Ltd. All rights are reserved, including those for text and data mining, AI training, and similar technologies.","name":"copyright","label":"Copyright"}]}}