{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,3,25]],"date-time":"2026-03-25T13:07:49Z","timestamp":1774444069108,"version":"3.50.1"},"reference-count":13,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"C","license":[{"start":{"date-parts":[[2024,5,1]],"date-time":"2024-05-01T00:00:00Z","timestamp":1714521600000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"},{"start":{"date-parts":[[2024,5,1]],"date-time":"2024-05-01T00:00:00Z","timestamp":1714521600000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/legal\/tdmrep-license"},{"start":{"date-parts":[[2024,4,22]],"date-time":"2024-04-22T00:00:00Z","timestamp":1713744000000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"funder":[{"DOI":"10.13039\/501100015690","name":"Universitas Padjadjaran","doi-asserted-by":"publisher","id":[{"id":"10.13039\/501100015690","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["lww.com","ovid.com"],"crossmark-restriction":true},"short-container-title":[],"published-print":{"date-parts":[[2024,5]]},"abstract":"<jats:title>ABSTRACT<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Introduction:<\/jats:title>\n                    <jats:p>Neural fibrolipoma, also known as fibrolipomatous hamartoma (FLH), is a rare benign tumor that usually affects the upper limb and tends to develop near the n. median. FLH is a rare birth defect defined by the noncancerous growth of fibroadipose tissue around nerve bundles. These conditions are associated with abnormal bone growth, resulting in macrodactyly in about one-third of cases. The illness is medically referred to as macrodystrophia lipomatosa (MDL).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Case presentation:<\/jats:title>\n                    <jats:p>A-4 years old girl presents with the index finger and thumb larger than the surrounding fingers and has been present since birth. Over time, the index finger and thumb continue to enlarge. This enlargement is accompanied by pain, a tingling sensation, and occasional bluish discoloration, especially at night. The patient is the third child out of four siblings, with a history of normal birth and no abnormalities in other parts of the body. The patient can grip objects in daily activities, but there is noticeable stiffness in the right hand.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Discussion:<\/jats:title>\n                    <jats:p>FLH with macrodactyly is an uncommon abnormality that can manifest as either a minor lesion or a big mass affecting the entire extremity. Clinically, it is challenging to challenging to diagnose FLH in patient with macrodactyly.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusion:<\/jats:title>\n                    <jats:p>It is crucial to possess a thorough understanding of the distinctive histology and radiological findings in order to accurately diagnose and treat the condition.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Highlights<\/jats:title>\n                  <\/jats:sec>","DOI":"10.1016\/j.ijscr.2024.109680","type":"journal-article","created":{"date-parts":[[2024,4,24]],"date-time":"2024-04-24T12:45:44Z","timestamp":1713962744000},"update-policy":"https:\/\/doi.org\/10.1097\/lww.0000000000001000","source":"Crossref","is-referenced-by-count":1,"title":["Fibrolipomatous hamartroma with macrodactyly in a 4 years old female patient: A case report"],"prefix":"10.1097","volume":"118","author":[{"given":"Hardisiswo","family":"Soedjana","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Betha Egih","family":"Riestiano","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Lisa Y.","family":"Hasibuan","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Valdi Muharam","family":"Kusumadiningrat","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"276","reference":[{"issue":"6","key":"R1-78-20260325","doi-asserted-by":"crossref","first-page":"766","DOI":"10.4103\/0019-5154.91851","article-title":"Multiple neural fibrolipomas with macrodactyly","volume":"56","author":"Gupta,","year":"2011","journal-title":"Indian J. Dermatol."},{"key":"R2-78-20260325","doi-asserted-by":"crossref","DOI":"10.7759\/cureus.2293","article-title":"Fibrolipomatous hamartoma of the median nerve with Macrodystrophia Lipomatosa","author":"Azeemuddin,","year":"2018","journal-title":"Cureus"},{"issue":"9","key":"R3-78-20260325","doi-asserted-by":"crossref","first-page":"499","DOI":"10.1016\/S1726-4901(10)70107-6","article-title":"MRI diagnosis of Fibrolipomatous hamartoma of the median nerve and associated Macrodystrophia Lipomatosa","volume":"73","author":"Chiang,","year":"2010","journal-title":"J. Chin. Med. 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Hand Surg."},{"issue":"5","key":"R7-78-20260325","doi-asserted-by":"crossref","first-page":"1136","DOI":"10.1097\/JS9.0000000000000373","article-title":"The SCARE 2023 guideline: updating consensus surgical CAse REport (SCARE) guidelines","volume":"109","author":"Sohrabi,","year":"2023","journal-title":"Int J Surg Lond Engl."},{"issue":"1","key":"R8-78-20260325","article-title":"A unique case of a fibrolipomatous hamartoma of the fingeral nerve of the great toe, a case report","volume":"2","author":"Liette,","year":"2022","journal-title":"Foot & Ankle Surgery: Techniques, Reports & Cases."},{"issue":"4","key":"R9-78-20260325","doi-asserted-by":"crossref","first-page":"1286","DOI":"10.3171\/2018.12.JNS183050","article-title":"Strengthening the association of lipomatosis of nerve and nerve-territory overgrowth: a systematic review","volume":"132","author":"Marek,","year":"2019","journal-title":"J. Neurosurg."},{"key":"R10-78-20260325","doi-asserted-by":"crossref","first-page":"736","DOI":"10.1016\/j.jaad.2013.10.002","article-title":"Fibrolipomatous hamartoma of the nerve: a clinicopathologic report of 13 cases","volume":"70","author":"Plaza,","year":"2014","journal-title":"J. Am. Acad. Dermatol."},{"issue":"10","key":"R11-78-20260325","doi-asserted-by":"crossref","first-page":"2055","DOI":"10.1016\/j.jhsa.2013.03.022","article-title":"Lipofibromatous hamartoma of the median nerve: a comprehensive review and systematic approach to evaluation, diagnosis, and treatment","volume":"38","author":"Tahiri,","year":"2013","journal-title":"J. Hand Surg. 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