{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,9,21]],"date-time":"2025-09-21T08:46:54Z","timestamp":1758444414948,"version":"3.44.0"},"reference-count":43,"publisher":"Elsevier BV","license":[{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/legal\/tdmrep-license"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-017"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-037"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-012"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-029"},{"start":{"date-parts":[[2023,8,1]],"date-time":"2023-08-01T00:00:00Z","timestamp":1690848000000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-004"}],"funder":[{"DOI":"10.13039\/501100020265","name":"Stan Perron Charitable Foundation","doi-asserted-by":"publisher","id":[{"id":"10.13039\/501100020265","id-type":"DOI","asserted-by":"publisher"}]},{"DOI":"10.13039\/501100000925","name":"National Health and Medical Research Council","doi-asserted-by":"publisher","award":["APP1117105"],"award-info":[{"award-number":["APP1117105"]}],"id":[{"id":"10.13039\/501100000925","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["clinicalkey.com","clinicalkey.com.au","clinicalkey.es","clinicalkey.fr","clinicalkey.jp","jpeds.com","elsevier.com","sciencedirect.com"],"crossmark-restriction":true},"short-container-title":["The Journal of Pediatrics"],"published-print":{"date-parts":[[2023,8]]},"DOI":"10.1016\/j.jpeds.2023.113418","type":"journal-article","created":{"date-parts":[[2023,4,6]],"date-time":"2023-04-06T20:53:47Z","timestamp":1680814427000},"page":"113418","update-policy":"https:\/\/doi.org\/10.1016\/elsevier_cm_policy","source":"Crossref","is-referenced-by-count":0,"special_numbering":"C","title":["Hospitalizations from Birth to 28\u00a0Years in a Population Cohort of Individuals Born with Five Rare Craniofacial Anomalies in Western Australia"],"prefix":"10.1016","volume":"259","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-2027-4231","authenticated-orcid":false,"given":"Mohammed","family":"Junaid","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Linda","family":"Slack-Smith","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kingsley","family":"Wong","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Timothy","family":"Hewitt","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Emma","family":"Glasson","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Jenny","family":"Bourke","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Gareth","family":"Baynam","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hanny","family":"Calache","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Helen","family":"Leonard","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"78","reference":[{"key":"10.1016\/j.jpeds.2023.113418_bib1","doi-asserted-by":"crossref","first-page":"207","DOI":"10.1016\/j.cps.2018.12.001","article-title":"Craniofacial microsomia","volume":"46","author":"Birgfeld","year":"2019","journal-title":"Clin Plast Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib2","doi-asserted-by":"crossref","first-page":"83","DOI":"10.1055\/s-0032-1320066","article-title":"Treacher Collins syndrome","volume":"26","author":"Chang","year":"2012","journal-title":"Semin Plast Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib3","doi-asserted-by":"crossref","first-page":"249","DOI":"10.1016\/j.cps.2018.11.010","article-title":"Pierre Robin sequence","volume":"46","author":"Hsieh","year":"2019","journal-title":"Clin Plast Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib4","doi-asserted-by":"crossref","first-page":"291","DOI":"10.1136\/jmg.23.4.291","article-title":"The Van der Woude syndrome (dominantly inherited lip pits and clefts)","volume":"23","author":"Schinzel","year":"1986","journal-title":"J Med Genet"},{"key":"10.1016\/j.jpeds.2023.113418_bib5","doi-asserted-by":"crossref","first-page":"312","DOI":"10.1159\/000450533","article-title":"Frontonasal dysplasia: towards an understanding of molecular and developmental aetiology","volume":"7","author":"Farlie","year":"2016","journal-title":"Mol Syndromol"},{"key":"10.1016\/j.jpeds.2023.113418_bib6","doi-asserted-by":"crossref","first-page":"271","DOI":"10.1002\/ajmg.c.31373","article-title":"Clinical care in craniofacial microsomia: a review of current management recommendations and opportunities to advance research","volume":"163","author":"Heike","year":"2013","journal-title":"Am J Med Genet C Semin Med Genet"},{"key":"10.1016\/j.jpeds.2023.113418_bib7","doi-asserted-by":"crossref","first-page":"191","DOI":"10.1097\/PRS.0000000000001896","article-title":"Treacher Collins syndrome: a systematic review of evidence-based treatment and recommendations","volume":"137","author":"Plomp","year":"2016","journal-title":"Plast Reconstr Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib8","doi-asserted-by":"crossref","first-page":"581","DOI":"10.1016\/j.bjoms.2014.02.007","article-title":"The surgical management of Treacher Collins syndrome","volume":"52","author":"Cobb","year":"2014","journal-title":"Br J Oral Maxillofac Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib9","doi-asserted-by":"crossref","first-page":"1040","DOI":"10.1002\/ppul.24038","article-title":"Epidemiology of Robin sequence with cleft palate in the East of Scotland between 2004 and 2013","volume":"53","author":"Wright","year":"2018","journal-title":"Pediatr Pulmonol"},{"key":"10.1016\/j.jpeds.2023.113418_bib10","series-title":"Craniofacial microsomia and Treacher Collins syndrome: comprehensive treatment of associated facial deformities","article-title":"Orthodontic considerations in the craniofacial microsomia patients","author":"Da Silveira","year":"2022"},{"key":"10.1016\/j.jpeds.2023.113418_bib11","doi-asserted-by":"crossref","first-page":"605","DOI":"10.1177\/000348940511400805","article-title":"Anomalies of the ear in the Pierre Robin triad","volume":"114","author":"Gruen","year":"2005","journal-title":"Ann Otol Rhinol Laryngol"},{"key":"10.1016\/j.jpeds.2023.113418_bib12","doi-asserted-by":"crossref","first-page":"37","DOI":"10.1038\/sj.bdj.2017.581","article-title":"Are people with an orofacial cleft at a higher risk of dental caries? A systematic review and meta-analysis","volume":"223","author":"Worth","year":"2017","journal-title":"Br Dent J"},{"key":"10.1016\/j.jpeds.2023.113418_bib13","doi-asserted-by":"crossref","first-page":"1277","DOI":"10.1097\/SCS.0000000000001551","article-title":"Unilateral craniofacial microsomia: unrecognized cause of pediatric obstructive sleep apnea","volume":"26","author":"Szpalski","year":"2015","journal-title":"J Craniofac Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib14","doi-asserted-by":"crossref","first-page":"480","DOI":"10.1097\/PRS.0000000000004581","article-title":"Surgical management and outcomes of Pierre Robin sequence: a comparison of mandibular distraction osteogenesis and tongue\u2013lip adhesion","volume":"142","author":"Zhang","year":"2018","journal-title":"Plast Reconstr Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib15","doi-asserted-by":"crossref","first-page":"1217","DOI":"10.1016\/j.ijom.2013.07.161","article-title":"Management and treatment protocol for hemifacial microsomia","volume":"42","author":"Uribe","year":"2013","journal-title":"Int J Oral Maxillofac Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib16","doi-asserted-by":"crossref","first-page":"2818","DOI":"10.1002\/lary.24782","article-title":"Regional variations in the presentation and surgical management of Pierre Robin sequence","volume":"124","author":"Scott","year":"2014","journal-title":"Laryngoscope"},{"key":"10.1016\/j.jpeds.2023.113418_bib17","doi-asserted-by":"crossref","first-page":"1167","DOI":"10.1177\/10556656211036618","article-title":"Description of total population hospital admissions for Treacher Collins syndrome in Australia","volume":"59","author":"Junaid","year":"2022","journal-title":"Cleft Palate Craniofac J"},{"key":"10.1016\/j.jpeds.2023.113418_bib18","doi-asserted-by":"crossref","first-page":"766","DOI":"10.1071\/AH080766","article-title":"A decade of data linkage in Western Australia: strategic design, applications and benefits of the WA data linkage system","volume":"32","author":"Holman","year":"2008","journal-title":"Aust Health Rev"},{"year":"2015","series-title":"Western Australian register of developmental anomalies 1980-2014","author":"Newborn Health Service Department of Health Western Australia","key":"10.1016\/j.jpeds.2023.113418_bib19"},{"key":"10.1016\/j.jpeds.2023.113418_bib21","doi-asserted-by":"crossref","first-page":"453","DOI":"10.1111\/j.1467-842X.1999.tb01297.x","article-title":"Population-based linkage of health records in Western Australia: development of a health services research linked database","volume":"23","author":"Holman","year":"1999","journal-title":"Aust N Z J Public Health"},{"key":"10.1016\/j.jpeds.2023.113418_bib23","doi-asserted-by":"crossref","first-page":"1795","DOI":"10.1038\/s41390-022-02024-9","article-title":"Association between craniofacial anomalies, intellectual disability and autism spectrum disorder: Western Australian population-based study","volume":"92","author":"Junaid","year":"2022","journal-title":"Pediatr Res"},{"key":"10.1016\/j.jpeds.2023.113418_bib24","doi-asserted-by":"crossref","first-page":"990","DOI":"10.1002\/bdra.23059","article-title":"Evaluation of ICD-9-CM codes for craniofacial microsomia","volume":"94","author":"Luquetti","year":"2012","journal-title":"Birth Defects Res A Clin Mol Teratol"},{"year":"2017","author":"Falster","key":"10.1016\/j.jpeds.2023.113418_bib25"},{"key":"10.1016\/j.jpeds.2023.113418_bib26","doi-asserted-by":"crossref","first-page":"E11","DOI":"10.3171\/2015.9.FOCUS15383","article-title":"Complications after craniosynostosis surgery: comparison of the 2012 Kids\u2019 inpatient database and pediatric NSQIP database","volume":"39","author":"Lin","year":"2015","journal-title":"Neurosurg Focus"},{"key":"10.1016\/j.jpeds.2023.113418_bib27","doi-asserted-by":"crossref","first-page":"32","DOI":"10.1186\/1471-2431-9-32","article-title":"A retrospective population-based study of childhood hospital admissions with record linkage to a birth defects registry","volume":"9","author":"Colvin","year":"2009","journal-title":"BMC Pediatr"},{"key":"10.1016\/j.jpeds.2023.113418_bib30","doi-asserted-by":"crossref","first-page":"103","DOI":"10.1093\/aje\/kwm245","article-title":"Relation between intrauterine growth and subsequent intellectual disability in a ten-year population cohort of children in Western Australia","volume":"167","author":"Leonard","year":"2008","journal-title":"Am J Epidemiol"},{"key":"10.1016\/j.jpeds.2023.113418_bib31","doi-asserted-by":"crossref","first-page":"e89","DOI":"10.1097\/MPG.0000000000002042","article-title":"Evolving trends of gastrostomy insertion within a pediatric population","volume":"67","author":"Glasson","year":"2018","journal-title":"J Pediatr Gastroenterol Nutr"},{"key":"10.1016\/j.jpeds.2023.113418_bib32","doi-asserted-by":"crossref","first-page":"441","DOI":"10.1111\/jpc.13024","article-title":"Hospitalisations up to adulthood for children born with orofacial clefts","volume":"52","author":"Bell","year":"2016","journal-title":"J Paediatr Child Health"},{"key":"10.1016\/j.jpeds.2023.113418_bib33","doi-asserted-by":"crossref","first-page":"162","DOI":"10.1016\/j.jpeds.2021.09.060","article-title":"Epidemiology of rare craniofacial anomalies: retrospective Western Australian population data linkage study","volume":"241","author":"Junaid","year":"2022","journal-title":"J Pediatr"},{"key":"10.1016\/j.jpeds.2023.113418_bib34","doi-asserted-by":"crossref","first-page":"90","DOI":"10.1111\/j.1600-0528.2012.00726.x","article-title":"How population-level data linkage might impact on dental research","volume":"40","author":"Slack-Smith","year":"2012","journal-title":"Community Dent Oral Epidemiol"},{"key":"10.1016\/j.jpeds.2023.113418_bib36","first-page":"90","article-title":"Epidemiology of hospital admissions for craniosynostosis in Australia: a population-based study","volume":"40","author":"Junaid","year":"2023","journal-title":"Cleft Palate Craniofac J"},{"key":"10.1016\/j.jpeds.2023.113418_bib37","doi-asserted-by":"crossref","first-page":"536","DOI":"10.1016\/S0007-1226(97)91303-5","article-title":"Current concepts in the understanding and management of hemifacial microsomia","volume":"50","author":"Cousley","year":"1997","journal-title":"Br J Plast Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib38","doi-asserted-by":"crossref","first-page":"695","DOI":"10.1016\/j.otc.2012.03.007","article-title":"Pierre Robin sequence: evaluation, management, indications for surgery, and pitfalls","volume":"45","author":"Scott","year":"2012","journal-title":"Otolaryngol Clin North Am"},{"key":"10.1016\/j.jpeds.2023.113418_bib39","doi-asserted-by":"crossref","first-page":"885","DOI":"10.1016\/S0022-3468(96)90403-0","article-title":"Experience with frontonasal dysplasia of varying severity","volume":"31","author":"Qureshi","year":"1996","journal-title":"J Pediatr Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib40","doi-asserted-by":"crossref","first-page":"31","DOI":"10.5694\/mja2.51088","article-title":"Potentially preventable hospitalisations of people with intellectual disability in New South Wales","volume":"215","author":"Weise","year":"2021","journal-title":"Med J Aust"},{"key":"10.1016\/j.jpeds.2023.113418_bib41","doi-asserted-by":"crossref","first-page":"116","DOI":"10.1071\/AH09674","article-title":"Recognising potential for preventing hospitalisation","volume":"34","author":"Banham","year":"2010","journal-title":"Aust Health Rev"},{"key":"10.1016\/j.jpeds.2023.113418_bib42","doi-asserted-by":"crossref","first-page":"74","DOI":"10.1186\/1472-6963-6-74","article-title":"The effects of socioeconomic status, accessibility to services and patient type on hospital use in Western Australia: a retrospective cohort study of patients with homogenous health status","volume":"6","author":"Moorin","year":"2006","journal-title":"BMC Health Serv Res"},{"key":"10.1016\/j.jpeds.2023.113418_bib43","series-title":"Oral and maxillofacial surgery for the clinician","article-title":"Modern management of craniosynostosis","author":"Koppel","year":"2021"},{"key":"10.1016\/j.jpeds.2023.113418_bib44","doi-asserted-by":"crossref","first-page":"691","DOI":"10.1071\/AH080691","article-title":"Acute upper respiratory infections in Western Australian emergency departments, 2000-2003","volume":"32","author":"Ingarfield","year":"2008","journal-title":"Aus Health Rev"},{"key":"10.1016\/j.jpeds.2023.113418_bib45","doi-asserted-by":"crossref","first-page":"797","DOI":"10.1093\/ije\/26.4.797","article-title":"Hospitalization of aboriginal and non-aboriginal patients for respiratory tract diseases in Western Australia, 1988-1993","volume":"26","author":"Williams","year":"1997","journal-title":"Int J Epidemiol"},{"key":"10.1016\/j.jpeds.2023.113418_bib46","doi-asserted-by":"crossref","first-page":"25","DOI":"10.4103\/1817-1737.197770","article-title":"Polysomnographic findings in infants with Pierre Robin sequence","volume":"12","author":"Khayat","year":"2017","journal-title":"Ann Thorac Med"},{"key":"10.1016\/j.jpeds.2023.113418_bib47","doi-asserted-by":"crossref","first-page":"1330","DOI":"10.1016\/j.ijom.2017.05.020","article-title":"Obstructive sleep apnoea in craniofacial microsomia: analysis of 755 patients","volume":"46","author":"Caron","year":"2017","journal-title":"Int J Oral Maxillofac Surg"},{"key":"10.1016\/j.jpeds.2023.113418_bib49","doi-asserted-by":"crossref","first-page":"1296","DOI":"10.1016\/j.ijom.2022.01.005","article-title":"Hearing impairment and ear anomalies in craniofacial microsomia: a systematic review","volume":"51","author":"Rooijers","year":"2022","journal-title":"Int J Oral Maxillofac Surg"}],"container-title":["The Journal of Pediatrics"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S0022347623002457?httpAccept=text\/xml","content-type":"text\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S0022347623002457?httpAccept=text\/plain","content-type":"text\/plain","content-version":"vor","intended-application":"text-mining"}],"deposited":{"date-parts":[[2025,9,20]],"date-time":"2025-09-20T09:17:32Z","timestamp":1758359852000},"score":1,"resource":{"primary":{"URL":"https:\/\/linkinghub.elsevier.com\/retrieve\/pii\/S0022347623002457"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2023,8]]},"references-count":43,"alternative-id":["S0022347623002457"],"URL":"https:\/\/doi.org\/10.1016\/j.jpeds.2023.113418","relation":{},"ISSN":["0022-3476"],"issn-type":[{"type":"print","value":"0022-3476"}],"subject":[],"published":{"date-parts":[[2023,8]]},"assertion":[{"value":"Elsevier","name":"publisher","label":"This article is maintained by"},{"value":"Hospitalizations from Birth to 28\u00a0Years in a Population Cohort of Individuals Born with Five Rare Craniofacial Anomalies in Western Australia","name":"articletitle","label":"Article Title"},{"value":"The Journal of Pediatrics","name":"journaltitle","label":"Journal Title"},{"value":"https:\/\/doi.org\/10.1016\/j.jpeds.2023.113418","name":"articlelink","label":"CrossRef DOI link to publisher maintained version"},{"value":"article","name":"content_type","label":"Content Type"},{"value":"\u00a9 2023 Elsevier Inc. All rights reserved.","name":"copyright","label":"Copyright"}],"article-number":"113418"}}