{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,4,11]],"date-time":"2026-04-11T08:06:32Z","timestamp":1775894792714,"version":"3.50.1"},"reference-count":37,"publisher":"Elsevier BV","issue":"10","license":[{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/legal\/tdmrep-license"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-017"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-037"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-012"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-029"},{"start":{"date-parts":[[2023,10,1]],"date-time":"2023-10-01T00:00:00Z","timestamp":1696118400000},"content-version":"stm-asf","delay-in-days":0,"URL":"https:\/\/doi.org\/10.15223\/policy-004"}],"funder":[{"DOI":"10.13039\/501100010275","name":"Deutsche Gesellschaft f\u00fcr Muskelkranke","doi-asserted-by":"publisher","id":[{"id":"10.13039\/501100010275","id-type":"DOI","asserted-by":"publisher"}]}],"content-domain":{"domain":["clinicalkey.com","clinicalkey.com.au","clinicalkey.es","clinicalkey.fr","clinicalkey.jp","nmd-journal.com","elsevier.com","sciencedirect.com"],"crossmark-restriction":true},"short-container-title":["Neuromuscular Disorders"],"published-print":{"date-parts":[[2023,10]]},"DOI":"10.1016\/j.nmd.2023.08.012","type":"journal-article","created":{"date-parts":[[2023,8,25]],"date-time":"2023-08-25T20:46:56Z","timestamp":1692996416000},"page":"754-761","update-policy":"https:\/\/doi.org\/10.1016\/elsevier_cm_policy","source":"Crossref","is-referenced-by-count":4,"title":["Suitability of the Respicheck questionnaire and Epworth sleepiness scale for therapy monitoring in myotonic dystrophy type 1"],"prefix":"10.1016","volume":"33","author":[{"given":"Eva","family":"Heidsieck","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-9891-5919","authenticated-orcid":false,"given":"Kristina","family":"Gutschmidt","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Benedikt","family":"Schoser","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-8407-3642","authenticated-orcid":false,"given":"Stephan","family":"Wenninger","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"78","reference":[{"key":"10.1016\/j.nmd.2023.08.012_bib0001","series-title":"Myotonic dystrophy","first-page":"331","author":"Harper","year":"1979"},{"key":"10.1016\/j.nmd.2023.08.012_bib0002","series-title":"Gene reviews ((R))","article-title":"Myotonic dystrophy type 1","author":"Bird","year":"1993"},{"key":"10.1016\/j.nmd.2023.08.012_bib0003","doi-asserted-by":"crossref","first-page":"303","DOI":"10.3389\/fneur.2018.00303","article-title":"Core clinical phenotypes in myotonic dystrophies","volume":"9","author":"Wenninger","year":"2018","journal-title":"Front Neurol"},{"issue":"10","key":"10.1016\/j.nmd.2023.08.012_bib0004","doi-asserted-by":"crossref","first-page":"572","DOI":"10.1016\/j.neurol.2016.08.003","article-title":"Unravelling the myotonic dystrophy type 1 clinical spectrum: a systematic registry-based study with implications for disease classification","volume":"172","author":"De Antonio","year":"2016","journal-title":"Rev Neurol"},{"issue":"1","key":"10.1016\/j.nmd.2023.08.012_bib0005","doi-asserted-by":"crossref","first-page":"17","DOI":"10.1016\/j.nmd.2019.10.011","article-title":"Characteristics of respiratory muscle involvement in myotonic dystrophy type 1","volume":"30","author":"Henke","year":"2020","journal-title":"Neuromuscul Disord"},{"issue":"5","key":"10.1016\/j.nmd.2023.08.012_bib0006","doi-asserted-by":"crossref","first-page":"432","DOI":"10.1016\/j.nmd.2015.01.011","article-title":"Participants of the 207th EW. 207th ENMC Workshop on chronic respiratory insufficiency in myotonic dystrophies: management and implications for research, 27-29 June 2014, Naarden, The Netherlands","volume":"25","author":"Sansone","year":"2015","journal-title":"Neuromuscul Disord"},{"issue":"4","key":"10.1016\/j.nmd.2023.08.012_bib0007","doi-asserted-by":"crossref","first-page":"302","DOI":"10.1016\/j.nmd.2019.02.006","article-title":"Sleep-disordered breathing and effects of non-invasive ventilation on objective sleep and nocturnal respiration in patients with myotonic dystrophy type I","volume":"29","author":"Spiesshoefer","year":"2019","journal-title":"Neuromuscul Disord"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0008","doi-asserted-by":"crossref","first-page":"198","DOI":"10.1016\/j.nmd.2018.12.002","article-title":"Respiratory dysfunction in myotonic dystrophy type 1: a systematic review","volume":"29","author":"Hawkins","year":"2019","journal-title":"Neuromuscul Disord"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0009","doi-asserted-by":"crossref","first-page":"579","DOI":"10.1007\/s11325-013-0921-5","article-title":"Prevalence and clinical correlates of sleep disordered breathing in myotonic dystrophy types 1 and 2","volume":"18","author":"Bianchi","year":"2014","journal-title":"Sleep Breath"},{"issue":"4","key":"10.1016\/j.nmd.2023.08.012_bib0010","doi-asserted-by":"crossref","first-page":"529","DOI":"10.3233\/JND-160191","article-title":"Sleepiness and sleep-related breathing disorders in myotonic dystrophy and responses to treatment: a prospective cohort study","volume":"3","author":"West","year":"2016","journal-title":"J Neuromuscul Dis"},{"key":"10.1016\/j.nmd.2023.08.012_bib0011","doi-asserted-by":"crossref","first-page":"92","DOI":"10.1016\/j.sleep.2016.12.005","article-title":"Quality of life and excessive daytime sleepiness in children and adolescents with myotonic dystrophy type 1","volume":"32","author":"Ho","year":"2017","journal-title":"Sleep Med"},{"key":"10.1016\/j.nmd.2023.08.012_bib0012","doi-asserted-by":"crossref","first-page":"118","DOI":"10.1016\/j.jns.2019.02.012","article-title":"Prevalence and predictor factors of respiratory impairment in a large cohort of patients with Myotonic Dystrophy type 1 (DM1): a retrospective, cross sectional study","volume":"399","author":"Rossi","year":"2019","journal-title":"J Neurol Sci"},{"issue":"4","key":"10.1016\/j.nmd.2023.08.012_bib0013","doi-asserted-by":"crossref","first-page":"301","DOI":"10.1016\/j.nmd.2020.02.014","article-title":"Screening for early symptoms of respiratory involvement in myotonic dystrophy type 1 using the Respicheck questionnaire","volume":"30","author":"De Mattia","year":"2020","journal-title":"Neuromuscul Disord"},{"issue":"9","key":"10.1016\/j.nmd.2023.08.012_bib0014","doi-asserted-by":"crossref","first-page":"750","DOI":"10.1016\/j.nmd.2020.07.003","article-title":"Expiratory muscle strength training improves measures of pressure generation and cough strength in a patient with myotonic dystrophy type 1","volume":"30","author":"Allen","year":"2020","journal-title":"Neuromuscul Disord"},{"issue":"6","key":"10.1016\/j.nmd.2023.08.012_bib0015","doi-asserted-by":"crossref","first-page":"573","DOI":"10.1177\/0269215513512215","article-title":"Effects of respiratory muscle training on pulmonary functions in patients with slowly progressive neuromuscular disease: a randomized controlled trial","volume":"28","author":"Aslan","year":"2014","journal-title":"Clin Rehabil"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0016","first-page":"349","article-title":"Inspiratory muscle training in patients with amyotrophic lateral sclerosis: a systematic review","volume":"35","author":"Eidenberger","year":"2014","journal-title":"Neuro Rehabil"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0017","doi-asserted-by":"crossref","first-page":"221","DOI":"10.1016\/j.physio.2016.01.002","article-title":"Respiratory training improved ventilatory function and respiratory muscle strength in patients with multiple sclerosis and lateral amyotrophic sclerosis: systematic review and meta-analysis","volume":"102","author":"Ferreira","year":"2016","journal-title":"Physiotherapy"},{"issue":"1","key":"10.1016\/j.nmd.2023.08.012_bib0018","doi-asserted-by":"crossref","first-page":"1577","DOI":"10.4102\/sajp.v77i1.1577","article-title":"Inspiratory muscle training in children and adolescents living with neuromuscular diseases: a pre-experimental study","volume":"77","author":"Human","year":"2021","journal-title":"S Afr J Physiother"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0019","first-page":"255","article-title":"Effects of respiratory muscle training (RMT) in children with infantile-onset Pompe disease and respiratory muscle weakness","volume":"7","author":"Jones","year":"2014","journal-title":"J Pediatr Rehabil Med"},{"issue":"2","key":"10.1016\/j.nmd.2023.08.012_bib0020","doi-asserted-by":"crossref","first-page":"120","DOI":"10.1016\/j.ymgme.2015.09.003","article-title":"Respiratory muscle training (RMT) in late-onset Pompe disease (LOPD): effects of training and detraining","volume":"117","author":"Jones","year":"2016","journal-title":"Mol Genet Metab"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0021","doi-asserted-by":"crossref","first-page":"314","DOI":"10.1111\/j.1469-8749.1986.tb03879.x","article-title":"Respiratory muscle training in Duchenne muscular dystrophy","volume":"28","author":"Martin","year":"1986","journal-title":"Dev Med Child Neurol"},{"issue":"1","key":"10.1016\/j.nmd.2023.08.012_bib0022","doi-asserted-by":"crossref","first-page":"133","DOI":"10.1007\/s00415-018-9112-4","article-title":"Safety and efficacy of short- and long-term inspiratory muscle training in late-onset Pompe disease (LOPD): a pilot study","volume":"266","author":"Wenninger","year":"2019","journal-title":"J Neurol"},{"issue":"6","key":"10.1016\/j.nmd.2023.08.012_bib0023","doi-asserted-by":"crossref","first-page":"540","DOI":"10.1093\/sleep\/14.6.540","article-title":"A new method for measuring daytime sleepiness: the Epworth sleepiness scale","volume":"14","author":"Johns","year":"1991","journal-title":"Sleep"},{"key":"10.1016\/j.nmd.2023.08.012_bib0024","series-title":"The clinical assessment of daytime sleepiness in patients with obstructive sleep apnea. Surgery for snoring and obstructive sleep apnea","first-page":"283","author":"Johns","year":"2003"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0025","doi-asserted-by":"crossref","first-page":"768","DOI":"10.1542\/peds.2004-0730","article-title":"Daytime sleepiness and hyperactivity in children with suspected sleep-disordered breathing","volume":"114","author":"Melendres","year":"2004","journal-title":"Pediatrics"},{"issue":"10","key":"10.1016\/j.nmd.2023.08.012_bib0026","first-page":"1348","article-title":"The assessment of maximal respiratory mouth pressures in adults","volume":"54","author":"Evans","year":"2009","journal-title":"Respir Care"},{"issue":"Suppl 16","key":"10.1016\/j.nmd.2023.08.012_bib0027","doi-asserted-by":"crossref","first-page":"5","DOI":"10.1183\/09041950.005s1693","article-title":"Lung volumes and forced ventilatory flows","volume":"6","author":"Quanjer","year":"1993","journal-title":"Eur Respir J"},{"issue":"6","key":"10.1016\/j.nmd.2023.08.012_bib0028","doi-asserted-by":"crossref","first-page":"906","DOI":"10.1002\/mus.24097","article-title":"Myotonic Dystrophy Health Index: initial evaluation of a disease-specific outcome measure","volume":"49","author":"Heatwole","year":"2014","journal-title":"Muscle Nerve"},{"issue":"5","key":"10.1016\/j.nmd.2023.08.012_bib0029","doi-asserted-by":"crossref","first-page":"310","DOI":"10.1016\/j.nmd.2010.03.010","article-title":"Rasch-built myotonic dystrophy type 1 activity and participation scale (DM1-Activ)","volume":"20","author":"Hermans","year":"2010","journal-title":"Neuromuscular Disorders: NMD"},{"issue":"1","key":"10.1016\/j.nmd.2023.08.012_bib0030","doi-asserted-by":"crossref","first-page":"52","DOI":"10.1186\/s13023-017-0598-0","article-title":"Maximum inspiratory pressure as a clinically meaningful trial endpoint for neuromuscular diseases: a comprehensive review of the literature","volume":"12","author":"Schoser","year":"2017","journal-title":"Orphanet J Rare Dis"},{"issue":"3","key":"10.1016\/j.nmd.2023.08.012_bib0031","doi-asserted-by":"crossref","first-page":"5","DOI":"10.1097\/01823246-200920030-00002","article-title":"Inspiratory muscle training in patients with chronic obstructive pulmonary disease: the state of the evidence","volume":"20","author":"Shoemaker","year":"2009","journal-title":"Cardiopulm Phys Ther J"},{"key":"10.1016\/j.nmd.2023.08.012_bib0032","article-title":"Safety and efficacy of short- and long-term inspiratory muscle training in late-onset Pompe disease (LOPD): a pilot study","author":"Wenninger","year":"2018","journal-title":"J Neurol"},{"key":"10.1016\/j.nmd.2023.08.012_bib0033","first-page":"67","article-title":"Respiratory muscle training with enzyme replacement therapy improves muscle strength in late\u2013onset Pompe disease","volume":"5","author":"Jevnikar","year":"2015","journal-title":"Mol Genet Metab Rep"},{"key":"10.1016\/j.nmd.2023.08.012_bib0034","doi-asserted-by":"crossref","DOI":"10.1016\/j.nmd.2017.03.009","article-title":"Inspiratory muscle training for children and adolescents with neuromuscular diseases: a systematic review","author":"Human","year":"2017","journal-title":"Neuromuscular disorders: NMD"},{"key":"10.1016\/j.nmd.2023.08.012_bib0035","doi-asserted-by":"crossref","DOI":"10.1016\/j.ymgme.2011.05.006","article-title":"Increased inspiratory and expiratory muscle strength following respiratory muscle strength training (RMST) in two patients with late-onset Pompe disease","author":"Jones","year":"2011","journal-title":"Mol Genet Metab"},{"issue":"4","key":"10.1016\/j.nmd.2023.08.012_bib0036","doi-asserted-by":"crossref","first-page":"555","DOI":"10.1007\/s00408-016-9881-4","article-title":"Inspiratory muscle training in late-onset pompe disease: the effects on pulmonary function tests, quality of life, and sleep quality","volume":"194","author":"Aslan","year":"2016","journal-title":"Lung"},{"issue":"11","key":"10.1016\/j.nmd.2023.08.012_bib0037","doi-asserted-by":"crossref","first-page":"904","DOI":"10.1016\/j.nmd.2020.09.023","article-title":"Respiratory muscle training in late-onset Pompe disease: results of a sham-controlled clinical trial","volume":"30","author":"Jones","year":"2020","journal-title":"Neuromuscul Disord"}],"container-title":["Neuromuscular Disorders"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S0960896623007071?httpAccept=text\/xml","content-type":"text\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S0960896623007071?httpAccept=text\/plain","content-type":"text\/plain","content-version":"vor","intended-application":"text-mining"}],"deposited":{"date-parts":[[2025,10,18]],"date-time":"2025-10-18T08:14:55Z","timestamp":1760775295000},"score":1,"resource":{"primary":{"URL":"https:\/\/linkinghub.elsevier.com\/retrieve\/pii\/S0960896623007071"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2023,10]]},"references-count":37,"journal-issue":{"issue":"10","published-print":{"date-parts":[[2023,10]]}},"alternative-id":["S0960896623007071"],"URL":"https:\/\/doi.org\/10.1016\/j.nmd.2023.08.012","relation":{},"ISSN":["0960-8966"],"issn-type":[{"value":"0960-8966","type":"print"}],"subject":[],"published":{"date-parts":[[2023,10]]},"assertion":[{"value":"Elsevier","name":"publisher","label":"This article is maintained by"},{"value":"Suitability of the Respicheck questionnaire and Epworth sleepiness scale for therapy monitoring in myotonic dystrophy type 1","name":"articletitle","label":"Article Title"},{"value":"Neuromuscular Disorders","name":"journaltitle","label":"Journal Title"},{"value":"https:\/\/doi.org\/10.1016\/j.nmd.2023.08.012","name":"articlelink","label":"CrossRef DOI link to publisher maintained version"},{"value":"article","name":"content_type","label":"Content Type"},{"value":"\u00a9 2023 Elsevier B.V. All rights reserved.","name":"copyright","label":"Copyright"}]}}