{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,13]],"date-time":"2026-07-13T09:06:22Z","timestamp":1783933582619,"version":"3.55.0"},"reference-count":7,"publisher":"Elsevier BV","license":[{"start":{"date-parts":[[2026,1,1]],"date-time":"2026-01-01T00:00:00Z","timestamp":1767225600000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"},{"start":{"date-parts":[[2026,1,1]],"date-time":"2026-01-01T00:00:00Z","timestamp":1767225600000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/legal\/tdmrep-license"},{"start":{"date-parts":[[2026,2,8]],"date-time":"2026-02-08T00:00:00Z","timestamp":1770508800000},"content-version":"vor","delay-in-days":38,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":["clinicalkey.com","clinicalkey.com.au","clinicalkey.es","clinicalkey.fr","clinicalkey.jp","elsevier.com","sciencedirect.com"],"crossmark-restriction":true},"short-container-title":["Clinical Parkinsonism &amp; Related Disorders"],"published-print":{"date-parts":[[2026]]},"DOI":"10.1016\/j.prdoa.2026.100428","type":"journal-article","created":{"date-parts":[[2026,2,19]],"date-time":"2026-02-19T08:21:46Z","timestamp":1771489306000},"page":"100428","update-policy":"https:\/\/doi.org\/10.1016\/elsevier_cm_policy","source":"Crossref","is-referenced-by-count":0,"special_numbering":"C","title":["An unusual case of Pisa syndrome secondary to anti-IgLon 5 disease"],"prefix":"10.1016","volume":"14","author":[{"ORCID":"https:\/\/orcid.org\/0009-0004-7272-5454","authenticated-orcid":false,"given":"Sindhu V.","family":"Nambiar","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Thomas","family":"Mathew","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Vishal Chandra","family":"Sharma","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Arjun","family":"Jayaprakash","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Shagun","family":"Bhardwaj","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Anita","family":"Mahadevanan","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"78","reference":[{"issue":"6","key":"10.1016\/j.prdoa.2026.100428_b0020","doi-asserted-by":"crossref","first-page":"708","DOI":"10.1002\/mdc3.13016","article-title":"Unusual head movements in anti-IgLON5 disease","volume":"7","author":"Peeters","year":"2020","journal-title":"Mov. Disord. Clin. Pract."},{"issue":"1","key":"10.1016\/j.prdoa.2026.100428_b0025","doi-asserted-by":"crossref","first-page":"135","DOI":"10.1002\/mdc3.13575","article-title":"Head drop and trunk flexion as an early manifestation of anti-IgLON5 disease","volume":"10","author":"Soman Pillai","year":"2022","journal-title":"Mov. Disord. Clin. Pract."},{"issue":"5","key":"10.1016\/j.prdoa.2026.100428_b0030","doi-asserted-by":"crossref","first-page":"575","DOI":"10.1002\/mdc3.14012","article-title":"Unusual head drops, neck and truncal dystonia and sleep orthopnea with a favorable treatment response in IgLon5 antibody disease","volume":"11","author":"Bavdhankar","year":"2024","journal-title":"Movement Disord Clin Pract."},{"key":"10.1016\/j.prdoa.2026.100428_b0005","doi-asserted-by":"crossref","unstructured":"K. Ekbom, H. Lindholm, L. Ljungberg, New dystonic syndrome associated with butyrophenone therapy, Z. Neurol. 202(2) (1972) 94\u2013103. 2. Sabater L, Gaig C, Gelpi E, et al. A novel non-rapid-Ekbom K, Lindholm H, Ljungberg L. New dystonic syndrome associated with butyrophenone therapy. Z Neurol. 1972; 202(2):94\u2013103.","DOI":"10.1007\/BF00316159"},{"issue":"1","key":"10.1016\/j.prdoa.2026.100428_bib31","doi-asserted-by":"crossref","first-page":"038","DOI":"10.29328\/journal.jnnd.1001033","article-title":"PISA Syndrome-Orthopedic manifestation of a neurological disease?","volume":"4","author":"Dutta","year":"2020","journal-title":"Journal of Neuroscience and Neurological Disorders"},{"key":"10.1016\/j.prdoa.2026.100428_b0010","doi-asserted-by":"crossref","first-page":"575","DOI":"10.1016\/S1474-4422(14)70051-1","article-title":"A novel non-rapid-eye movement and rapid-eye-movement parasomnia with sleep breathing disorder associated with antibodies to IgLON5: a case series, characterisation of the antigen, and post-mortem study","volume":"13","author":"Sabater","year":"2014","journal-title":"Lancet Neurol."},{"issue":"3","key":"10.1016\/j.prdoa.2026.100428_b0015","doi-asserted-by":"crossref","first-page":"440","DOI":"10.4103\/aian.aian_1073_24","article-title":"The expanding spectrum of AntiIgLON5 disease: a case series from an Indian Cohort","volume":"28","author":"Ganapule","year":"2025","journal-title":"Ann. Indian Acad. Neurol."}],"container-title":["Clinical Parkinsonism &amp; Related Disorders"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S2590112526000083?httpAccept=text\/xml","content-type":"text\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S2590112526000083?httpAccept=text\/plain","content-type":"text\/plain","content-version":"vor","intended-application":"text-mining"}],"deposited":{"date-parts":[[2026,7,13]],"date-time":"2026-07-13T08:20:18Z","timestamp":1783930818000},"score":1,"resource":{"primary":{"URL":"https:\/\/linkinghub.elsevier.com\/retrieve\/pii\/S2590112526000083"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026]]},"references-count":7,"alternative-id":["S2590112526000083"],"URL":"https:\/\/doi.org\/10.1016\/j.prdoa.2026.100428","relation":{},"ISSN":["2590-1125"],"issn-type":[{"value":"2590-1125","type":"print"}],"subject":[],"published":{"date-parts":[[2026]]},"assertion":[{"value":"Elsevier","name":"publisher","label":"This article is maintained by"},{"value":"An unusual case of Pisa syndrome secondary to anti-IgLon 5 disease","name":"articletitle","label":"Article Title"},{"value":"Clinical Parkinsonism & Related Disorders","name":"journaltitle","label":"Journal Title"},{"value":"https:\/\/doi.org\/10.1016\/j.prdoa.2026.100428","name":"articlelink","label":"CrossRef DOI link to publisher maintained version"},{"value":"simple-article","name":"content_type","label":"Content Type"},{"value":"\u00a9 2026 The Author(s). Published by Elsevier Ltd.","name":"copyright","label":"Copyright"}],"article-number":"100428"}}