{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,10,30]],"date-time":"2025-10-30T11:32:07Z","timestamp":1761823927070,"version":"3.40.5"},"reference-count":55,"publisher":"Elsevier BV","license":[{"start":{"date-parts":[[2017,9,1]],"date-time":"2017-09-01T00:00:00Z","timestamp":1504224000000},"content-version":"tdm","delay-in-days":0,"URL":"https:\/\/www.elsevier.com\/tdm\/userlicense\/1.0\/"}],"content-domain":{"domain":["clinicalkey.jp","clinicalkey.com","worldneurosurgery.org","clinicalkey.es","clinicalkey.com.au","clinicalkey.fr","elsevier.com","sciencedirect.com"],"crossmark-restriction":true},"short-container-title":["World Neurosurgery"],"published-print":{"date-parts":[[2017,9]]},"DOI":"10.1016\/j.wneu.2017.06.123","type":"journal-article","created":{"date-parts":[[2017,6,23]],"date-time":"2017-06-23T20:31:01Z","timestamp":1498249861000},"page":"1039.e7-1039.e12","update-policy":"https:\/\/doi.org\/10.1016\/elsevier_cm_policy","source":"Crossref","is-referenced-by-count":9,"special_numbering":"C","title":["A Confirmed Case in the United Kingdom of Hirayama Disease in a Young White Male Presenting with Hand Weakness"],"prefix":"10.1016","volume":"105","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-6831-6990","authenticated-orcid":false,"given":"Daniel","family":"Lewis","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ankur","family":"Saxena","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Amit","family":"Herwadkar","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"John","family":"Leach","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"78","reference":[{"key":"10.1016\/j.wneu.2017.06.123_bib1","doi-asserted-by":"crossref","first-page":"38","DOI":"10.1080\/14660820500396877","article-title":"Nationwide survey of juvenile muscular atrophy of distal upper extremity (Hirayama disease) in Japan","volume":"7","author":"Tashiro","year":"2006","journal-title":"Amyotroph Lateral Scler"},{"key":"10.1016\/j.wneu.2017.06.123_bib2","doi-asserted-by":"crossref","first-page":"46","DOI":"10.1001\/archneur.1997.00550130032012","article-title":"Familial juvenile focal amyotrophy of the upper extremity (Hirayama disease)","volume":"54","author":"Robberecht","year":"1997","journal-title":"Arch Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib3","doi-asserted-by":"crossref","first-page":"297","DOI":"10.1001\/archneur.1980.00500540075011","article-title":"Juvenile muscular atrophy localized to arms","volume":"37","author":"Singh","year":"1980","journal-title":"Arch Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib4","doi-asserted-by":"crossref","first-page":"336","DOI":"10.1111\/j.1600-0404.1985.tb00880.x","article-title":"Non-familial, spinal segmental muscular atrophy in juvenile and young subjects","volume":"72","author":"Virmani","year":"1985","journal-title":"Acta Neurol Scand"},{"key":"10.1016\/j.wneu.2017.06.123_bib5","doi-asserted-by":"crossref","first-page":"73","DOI":"10.1016\/0924-980X(94)00246-4","article-title":"Central motor conduction in Hirayama disease","volume":"97","author":"Misra","year":"1995","journal-title":"Electroencephalogr Clin Neurophysiol"},{"key":"10.1016\/j.wneu.2017.06.123_bib6","doi-asserted-by":"crossref","first-page":"388","DOI":"10.1001\/archneur.1984.04050160050015","article-title":"Monomelic amyotrophy","volume":"41","author":"Gourie-Devi","year":"1984","journal-title":"Arch Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib7","doi-asserted-by":"crossref","first-page":"285","DOI":"10.1136\/jnnp.48.3.285","article-title":"Juvenile muscular atrophy of distal upper extremities","volume":"48","author":"Tan","year":"1985","journal-title":"J\u00a0Neurol Neurosurg Psychiatry"},{"key":"10.1016\/j.wneu.2017.06.123_bib8","doi-asserted-by":"crossref","first-page":"314","DOI":"10.1136\/jnnp.52.3.314","article-title":"Non familial juvenile distal spinal muscular atrophy of upper extremity","volume":"52","author":"Peiris","year":"1989","journal-title":"J\u00a0Neurol Neurosurg Psychiatry"},{"key":"10.1016\/j.wneu.2017.06.123_bib9","doi-asserted-by":"crossref","first-page":"165","DOI":"10.1136\/jnnp.54.2.165","article-title":"Juvenile distal spinal muscular atrophy of upper extremities in Chinese males: a single fibre electromyographic study of arms and legs","volume":"54","author":"Chan","year":"1991","journal-title":"J\u00a0Neurol Neurosurg Psychiatry"},{"key":"10.1016\/j.wneu.2017.06.123_bib10","doi-asserted-by":"crossref","first-page":"331","DOI":"10.1159\/000110335","article-title":"Juvenile lower cervical spinal muscular atrophy in Taiwan: report of 27 Chinese cases","volume":"12","author":"Kao","year":"1993","journal-title":"Neuroepidemiology"},{"key":"10.1016\/j.wneu.2017.06.123_bib11","first-page":"365","article-title":"Hirayama disease: MR diagnosis","volume":"19","author":"Chen","year":"1998","journal-title":"AJNR Am J Neuroradiol"},{"key":"10.1016\/j.wneu.2017.06.123_bib12","doi-asserted-by":"crossref","first-page":"768","DOI":"10.3346\/jkms.2004.19.5.768","article-title":"A\u00a0Korean case of juvenile muscular atrophy of distal upper extremity (hirayama disease) with dynamic cervical cord compression","volume":"19","author":"Kwon","year":"2004","journal-title":"J\u00a0Korean Med Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib13","doi-asserted-by":"crossref","first-page":"327","DOI":"10.3109\/17453676808989466","article-title":"Unilateral juvenile muscular atrophy of upper limbs","volume":"39","author":"Pilgaard","year":"1968","journal-title":"Acta Orthop Scand"},{"key":"10.1016\/j.wneu.2017.06.123_bib14","doi-asserted-by":"crossref","first-page":"237","DOI":"10.1159\/000114279","article-title":"A\u00a0case of juvenile muscular atrophy confined to one upper limb","volume":"10","author":"Compernolle","year":"2008","journal-title":"Eur Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib15","doi-asserted-by":"crossref","first-page":"351","DOI":"10.1016\/0022-510X(87)90169-9","article-title":"Benign juvenile focal muscular atrophy of upper extremities\u2013a familial case","volume":"80","author":"Schlegel","year":"1987","journal-title":"J\u00a0Neurol Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib16","first-page":"163","article-title":"[Chronic spinal amyotrophy involving the upper limbs in young adults (O'Sullivan and McLeod syndrome). MRI study of the cervical spinal cord]","volume":"145","author":"Gaio","year":"1989","journal-title":"Rev Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib17","first-page":"263","article-title":"MR imaging of the cervical cord in juvenile amyotrophy of distal upper extremity","volume":"10","author":"Biondi","year":"1989","journal-title":"Am J Neuroradiol"},{"key":"10.1016\/j.wneu.2017.06.123_bib18","first-page":"611","article-title":"Chronic distal juvenile unilateral amyotrophy localized to a superior limb (Hirayama type): a European case","volume":"143","author":"Leys","year":"1987","journal-title":"Rev Neurol (Paris)"},{"key":"10.1016\/j.wneu.2017.06.123_bib19","first-page":"759","article-title":"[Progressive muscular atrophy localized in the hand. Monomelic form of motor neuron disease?]","volume":"144","author":"Chaine","year":"1988","journal-title":"Rev Neurol (Paris)"},{"key":"10.1016\/j.wneu.2017.06.123_bib20","first-page":"943","article-title":"[Juvenile monomelic amyotrophy: Hirayama disease]","volume":"32","author":"Drozdowski","year":"1997","journal-title":"Neurol Neurochir Pol"},{"key":"10.1016\/j.wneu.2017.06.123_bib21","first-page":"1069","article-title":"MRI findings in Hirayama's disease: Flexion-induced cervical myelopathy or intrinsic motor neuron disease?","volume":"246","author":"Schr\u00f6der","year":"1999","journal-title":"J\u00a0Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib22","doi-asserted-by":"crossref","first-page":"319","DOI":"10.1016\/j.diii.2012.10.008","article-title":"Hirayama disease: three cases","volume":"94","author":"Dejobert","year":"2013","journal-title":"Diagn Interv Imaging"},{"key":"10.1016\/j.wneu.2017.06.123_bib23","doi-asserted-by":"crossref","first-page":"135","DOI":"10.1159\/000116249","article-title":"Electromyographic and computed tomographic findings in five patients with monomelic spinal muscular atrophy","volume":"28","author":"de Visser","year":"2008","journal-title":"Eur Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib24","first-page":"169","article-title":"Spinal monomelic amyotrophy","volume":"56","author":"Serratrice","year":"1991","journal-title":"Adv Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib25","doi-asserted-by":"crossref","first-page":"555","DOI":"10.1016\/S1130-1473(09)70134-4","article-title":"A\u00a0case of Hirayama disease treated with laminectomy and duraplasty without spinal fusion","volume":"20","author":"Arrese","year":"2009","journal-title":"Neurocirugia"},{"key":"10.1016\/j.wneu.2017.06.123_bib26","doi-asserted-by":"crossref","first-page":"191","DOI":"10.3171\/2013.10.SPINE13508","article-title":"A\u00a0severe case of Hirayama disease successfully treated by anterior cervical fusion","volume":"20","author":"Paredes","year":"2014","journal-title":"J\u00a0Neurosurg Spine"},{"key":"10.1016\/j.wneu.2017.06.123_bib27","doi-asserted-by":"crossref","first-page":"1264","DOI":"10.1007\/s00115-011-3320-9","article-title":"[Hirayama disease in Germany: case reports and review of the literature]","volume":"82","author":"Kang","year":"2011","journal-title":"Nervenarzt"},{"key":"10.1016\/j.wneu.2017.06.123_bib28","doi-asserted-by":"crossref","first-page":"503","DOI":"10.1016\/j.jbspin.2012.10.013","article-title":"Hirayama disease in Austria","volume":"80","author":"Finsterer","year":"2013","journal-title":"Joint Bone Spine"},{"key":"10.1016\/j.wneu.2017.06.123_bib29","doi-asserted-by":"crossref","first-page":"303","DOI":"10.1007\/s10072-008-0987-1","article-title":"Hirayama disease: three cases assessed by F wave, somatosensory and motor evoked potentials and magnetic resonance imaging not supporting flexion myelopathy","volume":"29","author":"Ammendola","year":"2008","journal-title":"Neurol Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib30","doi-asserted-by":"crossref","first-page":"1980","DOI":"10.1212\/01.WNL.0000068017.75780.44","article-title":"Cervical cord dysfunction during neck flexion in Hirayama's disease","volume":"60","author":"Restuccia","year":"2003","journal-title":"Neurology"},{"key":"10.1016\/j.wneu.2017.06.123_bib31","doi-asserted-by":"crossref","first-page":"364","DOI":"10.21037\/qims.2016.07.08","article-title":"Hirayama's disease: an Italian single center experience and review of the literature","volume":"6","author":"Vitale","year":"2016","journal-title":"Quant Imaging Med Surg"},{"key":"10.1016\/j.wneu.2017.06.123_bib32","doi-asserted-by":"crossref","first-page":"1049","DOI":"10.1007\/s10072-015-2080-x","article-title":"Hirayama disease: the importance of an early diagnosis","volume":"36","author":"Cortese","year":"2015","journal-title":"Neurol Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib33","doi-asserted-by":"crossref","first-page":"1129","DOI":"10.1002\/mus.880171002","article-title":"AAEM case report 28: monomelic amyotrophy","volume":"17","author":"Donofrio","year":"1994","journal-title":"Muscle Nerve"},{"key":"10.1016\/j.wneu.2017.06.123_bib34","doi-asserted-by":"crossref","first-page":"124","DOI":"10.1017\/S0317167100030316","article-title":"Monomelic atrophy","volume":"17","author":"Oryema","year":"1990","journal-title":"Can J Neurol Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib35","doi-asserted-by":"crossref","first-page":"451","DOI":"10.3174\/ajnr.A3277","article-title":"Cervical spine MR imaging findings of patients with Hirayama disease in North America: a multisite study","volume":"34","author":"Lehman","year":"2013","journal-title":"Am J Neuroradiol"},{"key":"10.1016\/j.wneu.2017.06.123_bib36","doi-asserted-by":"crossref","first-page":"191","DOI":"10.1097\/CND.0000000000000028","article-title":"Clinical improvement of monomelic amyotrophy after avoidance of sustained neck flexion","volume":"15","author":"Quinn","year":"2014","journal-title":"J\u00a0Clin Neuromuscul Dis"},{"key":"10.1016\/j.wneu.2017.06.123_bib37","doi-asserted-by":"crossref","first-page":"1695","DOI":"10.1007\/s10072-015-2222-1","article-title":"Hirayama disease: the importance of adequate flexion MRI for diagnosis","volume":"36","author":"Kontzialis","year":"2015","journal-title":"Neurol Sci"},{"key":"10.1016\/j.wneu.2017.06.123_bib38","doi-asserted-by":"crossref","first-page":"653","DOI":"10.1136\/jnnp.41.7.653","article-title":"Distal chronic spinal muscular atrophy involving the hands","volume":"41","author":"O'Sullivan","year":"1978","journal-title":"J\u00a0Neurol Neurosurg Psychiatry"},{"key":"10.1016\/j.wneu.2017.06.123_bib39","doi-asserted-by":"crossref","first-page":"1036","DOI":"10.1093\/brain\/awg117","article-title":"Sporadic lower motor neuron disease with adult onset: classification of subtypes","volume":"126","author":"Van den Berg-Vos","year":"2003","journal-title":"Brain"},{"key":"10.1016\/j.wneu.2017.06.123_bib40","doi-asserted-by":"crossref","first-page":"320","DOI":"10.1034\/j.1600-0404.2001.00074.x","article-title":"Juvenile asymmetric segmental spinal muscular atrophy (Hirayama's disease): three cases without evidence of \u201cflexion myelopathy\u201d","volume":"104","author":"Willeit","year":"2001","journal-title":"Acta Neurol Scand"},{"key":"10.1016\/j.wneu.2017.06.123_bib41","doi-asserted-by":"crossref","first-page":"362","DOI":"10.1111\/j.1474-7766.2004.00265.x","article-title":"Neurological rarities","volume":"4","author":"Talbot","year":"2004","journal-title":"Pract Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib42","doi-asserted-by":"crossref","first-page":"2078","DOI":"10.1007\/s00415-011-6046-5","article-title":"Waterskier's Hirayama syndrome","volume":"258","author":"Bede","year":"2011","journal-title":"J Neurol"},{"key":"10.1016\/j.wneu.2017.06.123_bib43","doi-asserted-by":"crossref","DOI":"10.1136\/bcr-2013-200645","article-title":"A Portuguese case of Hirayama disease","volume":"2013","author":"Correia de Sa","year":"2013","journal-title":"BMJ Case Rep"},{"issue":"suppl 4","key":"10.1016\/j.wneu.2017.06.123_bib44","doi-asserted-by":"crossref","first-page":"S91","DOI":"10.1046\/j.1440-1789.2000.00305.x","article-title":"Juvenile muscular atrophy of distal upper extremity (Hirayama disease): focal cervical ischemic poliomyelopathy","volume":"20","author":"Hirayama","year":"2000","journal-title":"Neuropathology"},{"key":"10.1016\/j.wneu.2017.06.123_bib45","doi-asserted-by":"crossref","first-page":"133","DOI":"10.3109\/17482960902912407","article-title":"Clinical features of Hirayama disease in mainland China","volume":"11","author":"Zhou","year":"2010","journal-title":"Amyotroph Lateral Scler"},{"key":"10.1016\/j.wneu.2017.06.123_bib46","first-page":"173","article-title":"Improved motor function in hands","volume":"41","author":"Tokumaru","year":"2001","journal-title":"Rinsho Shinkeigaku"},{"key":"10.1016\/j.wneu.2017.06.123_bib47","doi-asserted-by":"crossref","first-page":"629","DOI":"10.3171\/2009.12.SPINE09431","article-title":"Hirayama disease","volume":"12","author":"Lin","year":"2010","journal-title":"J\u00a0Neurosurg Spine"},{"issue":"1 suppl","key":"10.1016\/j.wneu.2017.06.123_bib48","doi-asserted-by":"crossref","first-page":"33","DOI":"10.3171\/spi.1999.91.1.0033","article-title":"Surgical treatment for patients with cervical flexion myelopathy","volume":"91","author":"Kohno","year":"1999","journal-title":"J\u00a0Neurosurg"},{"key":"10.1016\/j.wneu.2017.06.123_bib49","doi-asserted-by":"crossref","first-page":"486","DOI":"10.1097\/00007632-199703010-00004","article-title":"Juvenile amyotrophy of the distal upper extremity: pathologic findings of the dura mater and surgical management","volume":"22","author":"Konno","year":"1997","journal-title":"Spine"},{"key":"10.1016\/j.wneu.2017.06.123_bib50","first-page":"625","article-title":"[A case of flexion myelopathy presenting juvenile segmental muscular atrophy of upper extremities--a successful treatment by cervical spine immobilization]","volume":"30","author":"Masaki","year":"1990","journal-title":"Rinsho Shinkeigaku"},{"key":"10.1016\/j.wneu.2017.06.123_bib51","doi-asserted-by":"crossref","first-page":"86","DOI":"10.3171\/spi.2005.3.2.0086","article-title":"Anterior spinal decompression and fusion for cervical flexion myelopathy in young patients","volume":"3","author":"Watanabe","year":"2005","journal-title":"J\u00a0Neurosurg Spine"},{"key":"10.1016\/j.wneu.2017.06.123_bib52","doi-asserted-by":"crossref","first-page":"1196","DOI":"10.1227\/01.NEU.0000345951.24132.7F","article-title":"Lack of epidural pressure change with neck flexion in a patient with Hirayama disease: case report","volume":"64","author":"Patel","year":"2009","journal-title":"Neurosurgery"},{"key":"10.1016\/j.wneu.2017.06.123_bib53","doi-asserted-by":"crossref","first-page":"276","DOI":"10.1007\/s005860100344","article-title":"Pathophysiology and treatment for cervical flexion myelopathy","volume":"11","author":"Fujimoto","year":"2002","journal-title":"Eur Spine J"},{"key":"10.1016\/j.wneu.2017.06.123_bib54","doi-asserted-by":"crossref","first-page":"743","DOI":"10.3171\/2014.7.SPINE13955","article-title":"Cervical duraplasty with tenting sutures via laminoplasty for\u00a0cervical flexion myelopathy in patients with Hirayama disease: successful decompression of a \u2018tight dural canal in flexion\u2019 without spinal fusion","volume":"21","author":"Ito","year":"2014","journal-title":"J Neurosurg Spine"},{"key":"10.1016\/j.wneu.2017.06.123_bib55","first-page":"173","article-title":"[Cervical collar therapy for juvenile muscular atrophy of distal upper extremity (Hirayama disease): results from 38 cases]","volume":"41","author":"Tokumaru","year":"2000","journal-title":"Rinsho Shinkeigaku"}],"container-title":["World Neurosurgery"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S1878875017310185?httpAccept=text\/xml","content-type":"text\/xml","content-version":"vor","intended-application":"text-mining"},{"URL":"https:\/\/api.elsevier.com\/content\/article\/PII:S1878875017310185?httpAccept=text\/plain","content-type":"text\/plain","content-version":"vor","intended-application":"text-mining"}],"deposited":{"date-parts":[[2018,8,31]],"date-time":"2018-08-31T08:52:08Z","timestamp":1535705528000},"score":1,"resource":{"primary":{"URL":"https:\/\/linkinghub.elsevier.com\/retrieve\/pii\/S1878875017310185"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2017,9]]},"references-count":55,"alternative-id":["S1878875017310185"],"URL":"https:\/\/doi.org\/10.1016\/j.wneu.2017.06.123","relation":{},"ISSN":["1878-8750"],"issn-type":[{"type":"print","value":"1878-8750"}],"subject":[],"published":{"date-parts":[[2017,9]]},"assertion":[{"value":"Elsevier","name":"publisher","label":"This article is maintained by"},{"value":"A Confirmed Case in the United Kingdom of Hirayama Disease in a Young White Male Presenting with Hand Weakness","name":"articletitle","label":"Article Title"},{"value":"World Neurosurgery","name":"journaltitle","label":"Journal Title"},{"value":"https:\/\/doi.org\/10.1016\/j.wneu.2017.06.123","name":"articlelink","label":"CrossRef DOI link to publisher maintained version"},{"value":"article","name":"content_type","label":"Content Type"},{"value":"Crown Copyright \u00a9 2017 Published by Elsevier Inc. All rights reserved.","name":"copyright","label":"Copyright"}]}}