{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,28]],"date-time":"2026-09-28T03:36:32Z","timestamp":1790566592867,"version":"4.1.0"},"reference-count":38,"publisher":"EDP Sciences","license":[{"start":{"date-parts":[[2019,9,27]],"date-time":"2019-09-27T00:00:00Z","timestamp":1569542400000},"content-version":"vor","delay-in-days":269,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["SICOT-J"],"accepted":{"date-parts":[[2019,7,7]]},"published-print":{"date-parts":[[2019]]},"abstract":"<jats:p>We report the case of a 30-year-old woman with histologically proven monostotic fibrous dysplasia of C2 revealed by a pathological fracture of the odontoid process. Radiological investigations showed a ground-glass mineralization of the vertebral body, a centimetric lytic area with poorly defined margins involving the inferior part of the vertebral body and inferior endplate and a fracture through an osteolytic area in the base of the odontoid process.<\/jats:p>\n<jats:p>Owing to the vertebral instability, a surgical procedure combining C0\u2013C5 fixation and posterior bone grafting was performed. The surgical biopsy was inconclusive and pathological confirmation was finally obtained through a percutaneous needle biopsy under fluoroscopic guidance. At 26-month follow-up, the patient still experienced mild persistent cervical posterior neck pain and stiffness possibly related to a C5\u20136 laxity below the intervertebral fixation.<\/jats:p>\n<jats:p>This case combines three radiological findings, which are unusual in fibrous dysplasia: monostotic presentation involving the spine, some aggressive radiographic features, and a pathological fracture.<\/jats:p>","DOI":"10.1051\/sicotj\/2019024","type":"journal-article","created":{"date-parts":[[2019,9,27]],"date-time":"2019-09-27T08:12:01Z","timestamp":1569571921000},"page":"34","source":"Crossref","is-referenced-by-count":4,"title":["Locally aggressive monostotic fibrous dysplasia of the cervical spine mimicking malignancy: a case report and literature review"],"prefix":"10.1051","volume":"5","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-2903-1428","authenticated-orcid":false,"given":"Audrey","family":"Milon","sequence":"first","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Marc","family":"Polivka","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Fr\u00e9derique","family":"Larousserie","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Guillaume","family":"Lot","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jean-Marc","family":"Ziza","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jean-Denis","family":"Laredo","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"250","published-online":{"date-parts":[[2019,9,27]]},"reference":[{"issue":"5","key":"R1","doi-asserted-by":"crossref","first-page":"874","DOI":"10.1001\/archsurg.1938.01190230153012","volume":"36","author":"Lichtenstein","year":"1938","journal-title":"Arch Surg"},{"issue":"2","key":"R2","doi-asserted-by":"crossref","first-page":"207","DOI":"10.2106\/00004623-196244020-00001","volume":"44","author":"Harris","year":"1962","journal-title":"J Bone Jt Surg"},{"key":"R3","unstructured":"Dahlin DC, Unni KK. 1986. Bone tumors: general aspects and data on 8,547 cases, 4th edn. Thomas, USA. Available from https:\/\/www.osti.gov\/scitech\/biblio\/5518830."},{"issue":"11","key":"R4","doi-asserted-by":"crossref","first-page":"5152","DOI":"10.1073\/pnas.89.11.5152","volume":"89","author":"Schwindinger","year":"1992","journal-title":"Proc Natl Acad Sci"},{"issue":"517","key":"R5","doi-asserted-by":"crossref","first-page":"1","DOI":"10.1259\/0007-1285-44-517-1","volume":"44","author":"Gibson","year":"1971","journal-title":"Br J Radiol"},{"issue":"24","key":"R6","doi-asserted-by":"crossref","first-page":"E933","DOI":"10.1097\/BRS.0b013e318186b31a","volume":"33","author":"Arantes","year":"2008","journal-title":"Spine"},{"issue":"8","key":"R7","doi-asserted-by":"crossref","first-page":"977","DOI":"10.1097\/00007632-199208000-00020","volume":"17","author":"Ehara","year":"1992","journal-title":"Spine"},{"issue":"4","key":"R8","doi-asserted-by":"crossref","first-page":"984","DOI":"10.2106\/JBJS.I.00727","volume":"92","author":"Schoenfeld","year":"2010","journal-title":"J Bone Jt Surg Am"},{"issue":"5","key":"R9","doi-asserted-by":"crossref","first-page":"781","DOI":"10.2106\/00004623-199072050-00023","volume":"72","author":"Hu","year":"1990","journal-title":"JBJS"},{"key":"R10","first-page":"107","volume":"27","author":"Ohki","year":"1990","journal-title":"J West Pacif Orthop Assoc"},{"issue":"5","key":"R11","first-page":"429","volume":"36","author":"Iwasaki","year":"2008","journal-title":"No Shinkei Geka Neurol Surg"},{"issue":"2","key":"R12","doi-asserted-by":"crossref","first-page":"243","DOI":"10.1097\/00007632-198902000-00020","volume":"14","author":"Stirrat","year":"1989","journal-title":"Spine"},{"issue":"5","key":"R13","doi-asserted-by":"crossref","first-page":"527","DOI":"10.1080\/02688690400012525","volume":"18","author":"Marshman","year":"2004","journal-title":"Br J Neurosurg"},{"key":"R14","first-page":"504","volume":"99","author":"Schlumberger","year":"1946","journal-title":"Mil Surg"},{"issue":"6","key":"R15","first-page":"490","volume":"111","author":"Rosendahl-Jensen","year":"1956","journal-title":"Acta Chir Scand"},{"issue":"2","key":"R16","doi-asserted-by":"crossref","first-page":"75","DOI":"10.1007\/s00402-006-0231-5","volume":"127","author":"Proschek","year":"2007","journal-title":"Arch Orthop Trauma Surg"},{"issue":"2","key":"R17","doi-asserted-by":"crossref","first-page":"137","DOI":"10.1007\/BF00300941","volume":"1","author":"Villas","year":"1992","journal-title":"Eur Spine J"},{"issue":"4","key":"R18","doi-asserted-by":"crossref","first-page":"497","DOI":"10.4103\/0028-3886.44810","volume":"56","author":"Sambasivan","year":"2008","journal-title":"Neurol India"},{"issue":"1","key":"R19","doi-asserted-by":"crossref","first-page":"49","DOI":"10.1148\/radiology.151.1.6701333","volume":"151","author":"Resnik","year":"1984","journal-title":"Radiology"},{"issue":"23","key":"R20","doi-asserted-by":"crossref","first-page":"2016","DOI":"10.1097\/BRS.0b013e3182a8cc05","volume":"38","author":"Wu","year":"2013","journal-title":"Spine"},{"issue":"1015","key":"R21","doi-asserted-by":"crossref","first-page":"996","DOI":"10.1259\/bjr\/81329736","volume":"85","author":"Park","year":"2012","journal-title":"Br J Radiol"},{"issue":"7\u20138","key":"R22","doi-asserted-by":"crossref","first-page":"460","DOI":"10.1007\/PL00013774","volume":"120","author":"Chow","year":"2000","journal-title":"Arch Orthop Trauma Surg"},{"issue":"2","key":"R23","doi-asserted-by":"crossref","first-page":"75","DOI":"10.1007\/s00402-006-0231-5","volume":"127","author":"Proschek","year":"2007","journal-title":"Arch Orthop Trauma Surg"},{"issue":"13","key":"R24","first-page":"e74","volume":"93","author":"Meredith","year":"2011","journal-title":"JBJS Case Connect"},{"issue":"1","key":"R25","doi-asserted-by":"crossref","first-page":"91","DOI":"10.1097\/00004728-199401000-00019","volume":"18","author":"Yao","year":"1994","journal-title":"J Comput Assist Tomogr"},{"issue":"2","key":"R26","doi-asserted-by":"crossref","first-page":"742","DOI":"10.1007\/s11999-014-3926-x","volume":"473","author":"Muthusamy","year":"2015","journal-title":"Clin Orthop Relat Res"},{"issue":"8","key":"R27","doi-asserted-by":"crossref","first-page":"563","DOI":"10.1007\/BF00197136","volume":"22","author":"Shapeero","year":"1993","journal-title":"Skeletal Radiol"},{"issue":"1","key":"R28","doi-asserted-by":"crossref","first-page":"79","DOI":"10.1007\/s00428-013-1437-x","volume":"463","author":"Kashima","year":"2013","journal-title":"Virchows Arch"},{"issue":"11","key":"R29","doi-asserted-by":"crossref","first-page":"1234","DOI":"10.1016\/0046-8177(94)90041-8","volume":"25","author":"Dorfman","year":"1994","journal-title":"Human Pathol"},{"key":"R30","unstructured":"Hermann G, Garcia R. 2013. Exophytic fibrous dysplasia of the rib. Osteologiai K\u00f6zlem\u00e9nyek. Available from https:\/\/www.google.com\/search?q=hermann+exophytic+fibrous+dysplasia+of+the+rib&rlz=1C1CHBD_frFR838FR840&oq=hermann+exophytic+fibrous+dysplasia+of+the+rib++&aqs=chrome..69i57.91767j0j7&sourceid=chrome&ie=UTF-8."},{"issue":"3","key":"R31","doi-asserted-by":"crossref","first-page":"183","DOI":"10.1007\/BF00388097","volume":"111","author":"Latham","year":"1992","journal-title":"Arch Orthop Trauma Surg"},{"issue":"1","key":"R32","doi-asserted-by":"crossref","first-page":"7227","DOI":"10.4076\/1752-1947-3-7227","volume":"3","author":"Snieders","year":"2009","journal-title":"J Med Case Rep"},{"issue":"1","key":"R33","first-page":"82","volume":"23","author":"Sharifudin","year":"2016","journal-title":"Malays J Med Sci"},{"issue":"2","key":"R34","doi-asserted-by":"crossref","first-page":"139","DOI":"10.3340\/jkns.2011.50.2.139","volume":"50","author":"Lee","year":"2011","journal-title":"J Kor Neurosurg Soc"},{"issue":"3","key":"R35","doi-asserted-by":"crossref","first-page":"250","DOI":"10.1007\/s00586-007-0434-7","volume":"16","author":"Dang","year":"2007","journal-title":"Eur Spine J"},{"issue":"6","key":"R36","doi-asserted-by":"crossref","first-page":"712","DOI":"10.1016\/j.spinee.2006.10.023","volume":"7","author":"Medow","year":"2007","journal-title":"Spine J"},{"issue":"6","key":"R37","first-page":"1342","volume":"44","author":"Mezzadri","year":"1999","journal-title":"Neurosurgery"},{"issue":"6","key":"R38","doi-asserted-by":"crossref","first-page":"905","DOI":"10.1227\/00006123-198906000-00019","volume":"24","author":"Stompro","year":"1989","journal-title":"Neurosurgery"}],"container-title":["SICOT-J"],"original-title":[],"link":[{"URL":"https:\/\/www.sicot-j.org\/10.1051\/sicotj\/2019024\/pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2020,3,20]],"date-time":"2020-03-20T07:19:13Z","timestamp":1584688753000},"score":1,"resource":{"primary":{"URL":"https:\/\/www.sicot-j.org\/10.1051\/sicotj\/2019024"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019]]},"references-count":38,"alternative-id":["sicotj190060"],"URL":"https:\/\/doi.org\/10.1051\/sicotj\/2019024","relation":{},"ISSN":["2426-8887"],"issn-type":[{"value":"2426-8887","type":"electronic"}],"subject":[],"published":{"date-parts":[[2019]]}}}