{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2022,3,31]],"date-time":"2022-03-31T16:22:28Z","timestamp":1648743748630},"reference-count":7,"publisher":"Georg Thieme Verlag KG","issue":"04","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Int J Angiol"],"published-print":{"date-parts":[[2020,12]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>A 43-year-old male presented with shortness of breath and palpitations. Physical examination was significant for skin lichenification, an erythematous maculopapular rash with annular plaques, a fissured tongue, and digital clubbing. Electrocardiogram captured a supraventricular tachycardia and right bundle branch block. Left heart catheterization found several proximal left coronary artery branch aneurysms, a right coronary\u2013pulmonary artery fistula, venous\u2013luminal vessels between the right heart chambers and cardiac veins, and thebesian venous lakes. Functional cardiac capacity was reduced, with left ventricular ejection fraction of 35 to 40%, on ventriculogram. A diagnosis of discoid lupus erythematosus was established after skin biopsies revealed systemic lupus erythematosus-like features but negative anti-nuclear, anti-Smith, anti-ds-deoxyribonucleic acid, anti-Ro, and anti-La antibodies. The case reported is unique, in that while our patient had pathologic electrophysiologic changes typically seen with autoimmune disease, the patient had many anatomical cardiac anomalies without atherosclerotic coronary disease. It is uncertain whether these findings are purely incidental or are related to an underlying genetic disorder.<\/jats:p>","DOI":"10.1055\/s-0039-1696978","type":"journal-article","created":{"date-parts":[[2019,9,12]],"date-time":"2019-09-12T22:43:02Z","timestamp":1568328182000},"page":"260-262","source":"Crossref","is-referenced-by-count":1,"title":["Uncommon Coronary Abnormalities in a Patient with Discoid Lupus Erythematosus"],"prefix":"10.1055","volume":"29","author":[{"given":"Damian","family":"Valencia","sequence":"additional","affiliation":[{"name":"Department of Internal Medicine, Kettering Medical Center, Kettering, Ohio"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Juan","family":"Linares","sequence":"additional","affiliation":[{"name":"Department of Internal Medicine, Kettering Medical Center, Kettering, Ohio"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Sulagna","family":"Das","sequence":"additional","affiliation":[{"name":"Department of Internal Medicine, Kettering Medical Center, Kettering, Ohio"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Victor","family":"Valencia","sequence":"additional","affiliation":[{"name":"Feinberg School of Medicine, Northwestern University, Chicago, Illinois"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Yan","family":"Yatsynovich","sequence":"additional","affiliation":[{"name":"Department of Internal Medicine, Kettering Medical Center, Kettering, Ohio"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"194","published-online":{"date-parts":[[2019,9,12]]},"reference":[{"issue":"03","key":"ref1","doi-asserted-by":"crossref","first-page":"275","DOI":"10.4065\/74.3.275","article-title":"Cardiac involvement in systemic lupus erythematosus","volume":"74","author":"K G Moder","year":"1999","journal-title":"Mayo Clin Proc"},{"issue":"S 04","key":"ref2","doi-asserted-by":"crossref","first-page":"iv8","DOI":"10.1093\/rheumatology\/kel308","article-title":"Heart involvement in systemic lupus erythematosus, anti-phospholipid syndrome and neonatal lupus","volume":"45","author":"A Tincani","year":"2006","journal-title":"Rheumatology (Oxford)"},{"issue":"10","key":"ref3","doi-asserted-by":"crossref","first-page":"813","DOI":"10.1053\/euhj.2000.2186","article-title":"Immunological basis of the cardiac conduction and rhythm disorders","volume":"22","author":"B Maisch","year":"2001","journal-title":"Eur Heart J"},{"issue":"08","key":"ref4","doi-asserted-by":"crossref","first-page":"379","DOI":"10.1007\/s11748-004-0015-1","article-title":"Coronary artery aneurysm with systemic lupus erythematosus","volume":"52","author":"M Yoshikai","year":"2004","journal-title":"Jpn J Thorac Cardiovasc Surg"},{"issue":"10","key":"ref5","doi-asserted-by":"crossref","first-page":"933","DOI":"10.1016\/j.amjmed.2014.06.005","article-title":"Tiny bubbles: coronary aneurysms and lupus","volume":"127","author":"G Famularo","year":"2014","journal-title":"Am J Med"},{"issue":"06","key":"ref6","doi-asserted-by":"crossref","first-page":"527","DOI":"10.1177\/000331979504600611","article-title":"Myocardial infarction secondary to coronary aneurysm in systemic lupus erythematosus. An autopsy case","volume":"46","author":"H Sumino","year":"1995","journal-title":"Angiology"},{"issue":"04","key":"ref7","first-page":"333","article-title":"Coronary steal due to ruptured right coronary aneurysm causing myocardial infarction in a patient with systemic lupus erythematosus","volume":"4","author":"K Hirata","year":"2014","journal-title":"Cardiovasc Diagn Ther"}],"container-title":["International Journal of Angiology"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/www.thieme-connect.de\/products\/ejournals\/pdf\/10.1055\/s-0039-1696978.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2020,11,26]],"date-time":"2020-11-26T23:35:10Z","timestamp":1606433710000},"score":1,"resource":{"primary":{"URL":"http:\/\/www.thieme-connect.de\/DOI\/DOI?10.1055\/s-0039-1696978"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019,9,12]]},"references-count":7,"journal-issue":{"issue":"04","published-online":{"date-parts":[[2020,11,26]]},"published-print":{"date-parts":[[2020,12]]}},"URL":"https:\/\/doi.org\/10.1055\/s-0039-1696978","relation":{},"ISSN":["1061-1711","1615-5939"],"issn-type":[{"value":"1061-1711","type":"print"},{"value":"1615-5939","type":"electronic"}],"subject":[],"published":{"date-parts":[[2019,9,12]]}}}