{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,31]],"date-time":"2026-07-31T10:32:40Z","timestamp":1785493960561,"version":"3.56.0"},"reference-count":29,"publisher":"Georg Thieme Verlag KG","issue":"06","content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Eur J Pediatr Surg"],"published-print":{"date-parts":[[2022,12]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>\n          Introduction\u2003To investigate the current experience of the ARM-Net Consortium in the management of epididymo-orchitis (EO) in patients with anorectal malformations (ARMs), and to identify specific risk factors and the need for urological care involvement.<\/jats:p><jats:p>\n          Materials and Methods\u2003We retrospectively collected data of EO in patients with ARM between 2015 and 2019. Data on urological aspects, ARM type, surgical approach, associated anomalies, diagnosis, and treatment of EO were collected and analyzed.<\/jats:p><jats:p>\n          Results\u2003Twenty-nine patients were reported by 12 centers. Twenty-six patients with EO (90%) had ARM with a rectourinary fistula. Median age at first EO was 2 years (range: 15 days\u201327 years). Twenty patients (69%) experienced multiple EO, and 60% of recurrences were ipsilateral. Associated urological anomalies included vesicoureteral reflux (48%), urethral anomalies (41%), neurogenic bladder (41%), and ectopic vas (10%). A positive urine culture during EO was present in 69%. EO was treated with antibiotics (90%), limiting surgical exploration to 14%. Prevention of recurrences included surgery (bulking agents 15%, vasectomy 15%, and orchiectomy 5%) and antibiotic prophylaxis (20%).<\/jats:p><jats:p>\n          Conclusion\u2003Urologists may encounter patients with EO in ARM patients, frequently with positive urine culture. An appropriate urologic work-up for most ARM patients is necessary to identify and treat underlying risk factors. A practical scheme for the work-up is suggested for a close collaboration between pediatric surgeons and urologists.<\/jats:p>","DOI":"10.1055\/s-0042-1742300","type":"journal-article","created":{"date-parts":[[2022,1,24]],"date-time":"2022-01-24T23:46:45Z","timestamp":1643068005000},"page":"504-511","source":"Crossref","is-referenced-by-count":4,"title":["Urological Impact of Epididymo-orchitis in Patients with Anorectal Malformation: An ARM-Net Consortium Study"],"prefix":"10.1055","volume":"32","author":[{"given":"Anna","family":"Morandi","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milano, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Maria","family":"Fanjul","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery, Hospital Gregorio Mara\u00f1\u00f3n, Madrid, Spain"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Barbara Daniela","family":"Iacobelli","sequence":"additional","affiliation":[{"name":"Newborn Surgery Unit, Department of Medical and Surgical Neonatology, Research Institute, Bambino Ges\u00f9 Children's Hospital, Rome, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Inbal","family":"Samuk","sequence":"additional","affiliation":[{"name":"Department of Pediatric and Adolescent Surgery, Schneider Children's Medical Center, Sackler Faculty of Medicine, Tel Aviv University, Tel Aviv, Israel"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Dalia","family":"Aminoff","sequence":"additional","affiliation":[{"name":"AIMAR-Italian Patients' and Parents' Organization for Anorectal Malformation, Rome, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Paola","family":"Midrio","sequence":"additional","affiliation":[{"name":"Pediatric Surgery Unit, C\u00e0 Foncello Hospital, Treviso, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3995-7286","authenticated-orcid":false,"given":"Ivo","family":"de Blaauw","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery, Radboudumc Amalia Children's Hospital, Nijmegen, the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-7950-2104","authenticated-orcid":false,"given":"Eberhard","family":"Schmiedeke","sequence":"additional","affiliation":[{"name":"Clinic for Paediatric Surgery and Paediatric Urology, Klinikum Bremen-Mitte, Bremen, Germany"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-3080-7481","authenticated-orcid":false,"given":"Alessio","family":"Pini Prato","sequence":"additional","affiliation":[{"name":"Pediatric Surgery Unit, The Children Hospital, Azienda Ospedaliera SS Antonio e Biagio e Cesare Arrigo, Alessandria, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Wout","family":"Feitz","sequence":"additional","affiliation":[{"name":"Division of Paediatric Urology, Department of Urology, Radboudumc Amalia Children's Hospital, Nijmegen, the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Hendrik J. J.","family":"van der Steeg","sequence":"additional","affiliation":[{"name":"Department of Pediatric Surgery, Radboudumc Amalia Children's Hospital, Nijmegen, the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-8399-3751","authenticated-orcid":false,"given":"Dario Guido","family":"Minoli","sequence":"additional","affiliation":[{"name":"Pediatric Urology Unit, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, Milano, Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Cornelius E. 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A 20-year retrospective study","volume":"141","author":"S Likitnukul","year":"1987","journal-title":"Am J Dis Child"},{"key":"ref14","doi-asserted-by":"crossref","first-page":"1100","DOI":"10.1016\/S0022-5347(17)43514-2","article-title":"Epididymitis in infants and boys: underlying urogenital anomalies and efficacy of imaging modalities","volume":"138","author":"A Siegel","year":"1987","journal-title":"J Urol"},{"issue":"04","key":"ref15","doi-asserted-by":"crossref","first-page":"273","DOI":"10.1080\/003655998750015449","article-title":"Acute epididymitis and urinary tract anomalies in children","volume":"32","author":"E Merlini","year":"1998","journal-title":"Scand J Urol Nephrol"},{"issue":"01","key":"ref16","doi-asserted-by":"crossref","first-page":"131","DOI":"10.1016\/S0022-5347(17)47024-8","article-title":"Ectopic ureter presenting with epididymitis in childhood: report of 5 cases","volume":"134","author":"T Umeyama","year":"1985","journal-title":"J Urol"},{"key":"ref17","doi-asserted-by":"crossref","first-page":"2657","DOI":"10.1016\/j.juro.2006.08.027","article-title":"Endoscopic treatment of vesicovasal and vesicoureteral reflux in infants with persisting mesonephric duct","volume":"176","author":"A M Kajbafzadeh","year":"2006","journal-title":"J Urol"},{"issue":"06","key":"ref18","doi-asserted-by":"crossref","first-page":"1414","DOI":"10.1016\/j.urology.2011.04.012","article-title":"Unusual presentation of a Mullerian remnant in an infant with recurrent epididymo-orchitis","volume":"78","author":"A D Gupta","year":"2011","journal-title":"Urology"},{"issue":"05","key":"ref19","doi-asserted-by":"crossref","first-page":"492.e1","DOI":"10.1016\/j.jpurol.2017.01.019","article-title":"The prostatic utricle: an under-recognized condition resulting in significant morbidity in boys with both hypospadias and normal external genitalia","volume":"13","author":"A G Hester","year":"2017","journal-title":"J Pediatr Urol"},{"issue":"06","key":"ref20","doi-asserted-by":"crossref","first-page":"997","DOI":"10.1046\/j.1464-410X.1997.00271.x","article-title":"Recurrent epididymo-orchitis in a child secondary to a stone in the seminal vesicle","volume":"79","author":"R Carachi","year":"1997","journal-title":"Br J Urol"},{"issue":"03","key":"ref21","doi-asserted-by":"crossref","first-page":"181","DOI":"10.1308\/003588414X13814021679311","article-title":"The aetiology and current management of prepubertal epididymitis","volume":"96","author":"A Gkentzis","year":"2014","journal-title":"Ann R Coll Surg Engl"},{"issue":"03","key":"ref22","doi-asserted-by":"crossref","first-page":"339","DOI":"10.1053\/jpsu.2002.30810","article-title":"Urologic injuries associated with repair of anorectal malformations in male patients","volume":"37","author":"A R Hong","year":"2002","journal-title":"J Pediatr Surg"},{"issue":"05","key":"ref23","doi-asserted-by":"crossref","first-page":"958","DOI":"10.1016\/S0022-5347(17)51595-5","article-title":"The persisting mesonephric duct syndrome: the description of a new syndrome","volume":"130","author":"J S Vordermark II","year":"1983","journal-title":"J Urol"},{"issue":"02","key":"ref24","doi-asserted-by":"crossref","first-page":"323","DOI":"10.1016\/S0022-5347(17)39947-0","article-title":"Is micturition disorder a pathogenic factor in acute epididymitis? An evaluation of simultaneous bladder pressure and urine flow in men with previous acute epididymitis","volume":"143","author":"P Thind","year":"1990","journal-title":"J Urol"},{"issue":"04","key":"ref25","doi-asserted-by":"crossref","first-page":"783","DOI":"10.1016\/j.pcl.2012.05.007","article-title":"Functional bladder problems in children: pathophysiology, diagnosis, and treatment","volume":"59","author":"I Franco","year":"2012","journal-title":"Pediatr Clin North Am"},{"key":"ref26","doi-asserted-by":"crossref","first-page":"S64","DOI":"10.5489\/cuaj.4411","article-title":"Bladder and bowel dysfunction in children: an update on the diagnosis and treatment of a common, but underdiagnosed pediatric problem","volume":"11","author":"J D Santos","year":"2017","journal-title":"Can Urol Assoc J"},{"issue":"05","key":"ref27","doi-asserted-by":"crossref","first-page":"476","DOI":"10.1016\/j.jpurol.2018.06.014","article-title":"Endoscopic injection of bulking agent around the ejaculatory ducts at the verumontanum for recurrent paediatric epididymitis","volume":"14","author":"A Faure","year":"2018","journal-title":"J Pediatr Urol"},{"issue":"05","key":"ref28","doi-asserted-by":"crossref","first-page":"552","DOI":"10.1016\/j.jpurol.2010.06.002","article-title":"Management of recurrent epididymitis in children: application of neurovascular sparing vas clipping in refractory cases","volume":"7","author":"A M Kajbafzadeh","year":"2011","journal-title":"J Pediatr Urol"},{"issue":"11","key":"ref29","doi-asserted-by":"crossref","first-page":"2935","DOI":"10.1093\/humrep\/17.11.2935","article-title":"Aspermia and chronic testicular pain after imperforate anus correction. 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