{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,10,31]],"date-time":"2026-10-31T17:22:35Z","timestamp":1793467355101,"version":"4.5.0"},"reference-count":10,"publisher":"Oxford University Press (OUP)","issue":"7","license":[{"start":{"date-parts":[[2020,7,8]],"date-time":"2020-07-08T00:00:00Z","timestamp":1594166400000},"content-version":"vor","delay-in-days":7,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2020,7,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:p>This case describes a 9-year-old male who presented to general surgical clinic with a 3-year history of persistent natal cleft swelling, previously unsuccessfully treated as a pilonidal abscess in the community with multiple courses of antibiotics. In clinic, a 50\u00a0\u00d7\u00a030-mm soft tissue swelling was found in the natal cleft and a clinical diagnosis of a pilonidal cyst was made. A cream-coloured solid mass measuring 50\u00a0\u00d7\u00a035\u00a0\u00d7\u00a030\u00a0mm was subsequently excised under general anaesthetic, with specialist histology and immunostaining confirming an unexpected diagnosis of a subcutaneous extraspinal myxopapillary ependymoma, a tumour usually found in the neuraxis. Given the atypical anatomical site of the tumour, the case presented a unique management challenge. Ultimately, the patient underwent a re-operation after specialist multi-disciplinary discussion and is currently disease free at 18 months post-surgery. The authors wish to contribute their experiences of managing this rare extraspinal ependymoma to the few existing reports in the literature.<\/jats:p>","DOI":"10.1093\/jscr\/rjaa177","type":"journal-article","created":{"date-parts":[[2020,5,12]],"date-time":"2020-05-12T15:08:47Z","timestamp":1589296127000},"source":"Crossref","is-referenced-by-count":8,"title":["An unexpected diagnosis of paediatric subcutaneous sacrococcygeal extraspinal ependymoma: lessons learnt and review of the literature"],"prefix":"10.1093","volume":"2020","author":[{"given":"Tanya","family":"Gupta","sequence":"first","affiliation":[{"name":"Department of General Surgery, Lister Hospital, Stevenage, UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-8298-9232","authenticated-orcid":false,"given":"Vikesh","family":"Patel","sequence":"first","affiliation":[{"name":"Department of General Surgery, Lister Hospital, Stevenage, UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Faisal","family":"El-Medani","sequence":"first","affiliation":[{"name":"Department of General Surgery, Lister Hospital, Stevenage, UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sanjay","family":"Gupta","sequence":"first","affiliation":[{"name":"Department of General Surgery, Lister Hospital, Stevenage, UK"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"286","published-online":{"date-parts":[[2020,7,8]]},"reference":[{"key":"2020070811041313900_ref1","doi-asserted-by":"crossref","first-page":"1405","DOI":"10.1016\/S0022-3468(99)90020-9","article-title":"Sacrococcygeal ependymoma: case report and review of the literature","volume":"34","author":"Johnson","year":"1999","journal-title":"J Pediatr Surg"},{"key":"2020070811041313900_ref2","volume-title":"The Human Nervous System: An Anatomical Viewpoint","author":"Barr","year":"1983","edition":"4th"},{"key":"2020070811041313900_ref3","doi-asserted-by":"crossref","first-page":"104","DOI":"10.1055\/s-0038-1636503","article-title":"Ependymoma","volume":"38","author":"Pajtler","year":"2018","journal-title":"Semin Neurol"},{"key":"2020070811041313900_ref4","doi-asserted-by":"crossref","first-page":"216","DOI":"10.21037\/jss.2016.08.06","article-title":"Spinal myxopapillary ependymoma with interval drop metastasis presenting as cauda equine syndrome: a case report and review of literature","volume":"2","author":"Rege","year":"2016","journal-title":"J Spine Surg"},{"key":"2020070811041313900_ref5","doi-asserted-by":"crossref","first-page":"97","DOI":"10.1007\/s00401-007-0243-4","article-title":"The 2007 WHO classification of tumours of the central nervous system","volume":"114","author":"Louis","year":"2007","journal-title":"Acta Neuropathol"},{"key":"2020070811041313900_ref6","doi-asserted-by":"crossref","first-page":"7","DOI":"10.1186\/1477-5751-10-7","article-title":"Histopathological grading of pediatric ependymoma: reproducibility and clinical relevance in European trial cohorts","volume":"10","author":"Ellison","year":"2011","journal-title":"J Negat Results Biomed"},{"key":"2020070811041313900_ref7","first-page":"1","article-title":"Extradural sacrococcygeal subcutaneous ependymoma misdiagnosed as pilonidal disease: case report and review of the literature","volume":"7","author":"McEachron","year":"2016","journal-title":"J Surg Case Rep"},{"key":"2020070811041313900_ref8","doi-asserted-by":"crossref","first-page":"1291","DOI":"10.1007\/s00381-018-3805-y","article-title":"Pediatric extraspinal sacrococcygeal ependymoma (ESE): an Italian AIEOP experience of six cases and literature review","volume":"34","author":"Schiavello","year":"2018","journal-title":"Childs Nerv Syst"},{"key":"2020070811041313900_ref9","doi-asserted-by":"crossref","first-page":"144","DOI":"10.1016\/j.jocn.2018.01.048","article-title":"Unusual paediatric spinal myxopapillary ependymomas: unique molecular entities or pathological variations on a theme?","volume":"50","author":"Rogers","year":"2018","journal-title":"J Clin Neurosci"},{"key":"2020070811041313900_ref10","doi-asserted-by":"crossref","first-page":"445","DOI":"10.1038\/nature13108","article-title":"Epigenomic alterations define lethal CIMP-positive ependymomas of infancy","volume":"506","author":"Mack","year":"2014","journal-title":"Nature"}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/academic.oup.com\/jscr\/article-pdf\/2020\/7\/rjaa177\/33473125\/rjaa177.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"http:\/\/academic.oup.com\/jscr\/article-pdf\/2020\/7\/rjaa177\/33473125\/rjaa177.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2020,7,8]],"date-time":"2020-07-08T11:04:21Z","timestamp":1594206261000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjaa177\/5866331"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2020,7,1]]},"references-count":10,"journal-issue":{"issue":"7","published-print":{"date-parts":[[2020,7,1]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjaa177","relation":{},"ISSN":["2042-8812"],"issn-type":[{"value":"2042-8812","type":"electronic"}],"subject":[],"published-other":{"date-parts":[[2020,7]]},"published":{"date-parts":[[2020,7,1]]},"article-number":"rjaa177"}}