{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,7,30]],"date-time":"2025-07-30T12:04:56Z","timestamp":1753877096443,"version":"3.41.2"},"reference-count":10,"publisher":"Oxford University Press (OUP)","issue":"10","license":[{"start":{"date-parts":[[2020,10,31]],"date-time":"2020-10-31T00:00:00Z","timestamp":1604102400000},"content-version":"vor","delay-in-days":30,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2020,10,1]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>This is a rare case of a 42-year-old Hispanic male with macrodactyly who presented with recurrent carpal tunnel syndrome (CTS) due to Lipofibromatous Hamartoma (LFH). A slowly growing mass in his right palm with pain and numbness, along with motor and sensory deficits in the median nerve distribution, was reported since the past year prior to visit. Previous open carpal tunnel release was performed at 16\u00a0years of age due to CTS without complications. The diagnosis of LFH was made based on ultrasound, electromyography test and physical examination. An extended open carpal tunnel release with transection of transverse ligament was performed. The 24-month postoperative evaluation showed complete resolution of symptoms. This report illustrates the management of a recurrent CTS due to LFH in a Hispanic adult patient with macrodactyly that was successfully treated with a carpal tunnel decompression.<\/jats:p>","DOI":"10.1093\/jscr\/rjaa418","type":"journal-article","created":{"date-parts":[[2020,9,11]],"date-time":"2020-09-11T11:10:39Z","timestamp":1599822639000},"source":"Crossref","is-referenced-by-count":3,"title":["Lipofibromatous Hamartoma in a Hispanic Patient with macrodactyly: a rare peripheral nerve tumor causing recurrent carpal tunnel syndrome"],"prefix":"10.1093","volume":"2020","author":[{"given":"Marcantonio V","family":"Pinci","sequence":"first","affiliation":[{"name":"Orthopaedic Surgery Department University of Puerto Rico, Medical Sciences Campus San Juan, San Juan 00936-5067, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-4792-4625","authenticated-orcid":false,"given":"Gerardo","family":"Olivella","sequence":"additional","affiliation":[{"name":"Orthopaedic Surgery Department University of Puerto Rico, Medical Sciences Campus San Juan, San Juan 00936-5067, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Manuel","family":"Rodr\u00edguez","sequence":"additional","affiliation":[{"name":"Orthopaedic Surgery Department University of Puerto Rico, Medical Sciences Campus San Juan, San Juan 00936-5067, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hans W","family":"Hess-Arcelay","sequence":"additional","affiliation":[{"name":"Orthopaedic Surgery Department University of Puerto Rico, Medical Sciences Campus San Juan, San Juan 00936-5067, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Norman","family":"Ram\u00edrez","sequence":"additional","affiliation":[{"name":"Pediatric Orthopaedic Surgery Department, Mayag\u00fcez Medical Center, Mayag\u00fcez 00681, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Christian","family":"Foy-Parilla","sequence":"additional","affiliation":[{"name":"Orthopaedic Surgery Department University of Puerto Rico, Medical Sciences Campus San Juan, San Juan 00936-5067, Puerto Rico"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2020,10,31]]},"reference":[{"key":"2020103108205238100_ref1","doi-asserted-by":"crossref","first-page":"109","DOI":"10.1055\/s-0038-1626682","article-title":"Lipofibromatous Hamartoma of the palmar cutaneous branch of the median nerve","volume":"10","author":"Hoellwarth","year":"2018","journal-title":"J Hand Microsurg."},{"key":"2020103108205238100_ref2","doi-asserted-by":"crossref","first-page":"2055","DOI":"10.1016\/j.jhsa.2013.03.022","article-title":"Lipofibromatous hamartoma of the median nerve: a comprehensive review and systematic approach to evaluation, diagnosis, and treatment","volume":"38","author":"Tahiri","year":"2013","journal-title":"J Hand Surg Am."},{"key":"2020103108205238100_ref3","doi-asserted-by":"crossref","first-page":"403","DOI":"10.1016\/S0363-5023(85)80044-7","article-title":"Lipofibromas of the median nerve: long-term follow-up of four cases","volume":"10","author":"Louis","year":"1985","journal-title":"J Hand Surg Am."},{"key":"2020103108205238100_ref4","doi-asserted-by":"crossref","first-page":"1394","DOI":"10.1016\/j.bjps.2006.01.016","article-title":"Recurrent carpal tunnel syndrome in a child due to fibrolipomatous hamartoma of the median nerve successfully treated by limited excision and decompression","volume":"59","author":"Bains","year":"2006","journal-title":"J Plast Reconstr Aesthet Surg."},{"key":"2020103108205238100_ref5","doi-asserted-by":"crossref","first-page":"7","DOI":"10.1097\/00000478-198501000-00004","article-title":"Fibrolipomatous hamartoma of nerve. A clinicopathologic analysis of 26 cases","volume":"9","author":"Silverman","year":"1985","journal-title":"Am J Surg Pathol."},{"key":"2020103108205238100_ref6","doi-asserted-by":"crossref","first-page":"1","DOI":"10.3941\/jrcr.v10i11.2787","article-title":"Lipofibromatous Hamartoma of the median nerve: a case report","volume":"10","author":"Shekhani","year":"2016","journal-title":"J Radiol Case Rep"},{"key":"2020103108205238100_ref7","doi-asserted-by":"crossref","first-page":"664","DOI":"10.3340\/jkns.2020.0082","article-title":"Carpal tunnel syndrome caused by Lipofibromatous Hamartoma of the median nerve","volume":"63","author":"Roh","year":"2020","journal-title":"J Korean Neurosurg Soc."},{"key":"2020103108205238100_ref8","doi-asserted-by":"crossref","first-page":"71","DOI":"10.1186\/1749-799X-5-71","article-title":"Lipofibromatous hamartoma of the median nerve","volume":"5","author":"Al-Jabri","year":"2010","journal-title":"J Orthop Surg Res"},{"key":"2020103108205238100_ref9","article-title":"Use of ultra-high-frequency ultrasound on diagnosis and management of Lipofibromatous Hamartoma: a technical report","volume":"11","author":"Boczar","year":"2019","journal-title":"Cureus"},{"key":"2020103108205238100_ref10","doi-asserted-by":"crossref","first-page":"68","DOI":"10.1016\/J.JHSB.2005.09.022","article-title":"Revision surgery after carpal tunnel release--analysis of the pathology in 200 cases during a 2-year period","volume":"31","author":"St\u00fctz","year":"2006","journal-title":"J Hand Surg Br."}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"http:\/\/academic.oup.com\/jscr\/article-pdf\/2020\/10\/rjaa418\/34069094\/rjaa418.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"http:\/\/academic.oup.com\/jscr\/article-pdf\/2020\/10\/rjaa418\/34069094\/rjaa418.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,10,7]],"date-time":"2023-10-07T06:30:38Z","timestamp":1696660238000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjaa418\/5944223"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2020,10,1]]},"references-count":10,"journal-issue":{"issue":"10","published-print":{"date-parts":[[2020,10,1]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjaa418","relation":{},"ISSN":["2042-8812"],"issn-type":[{"type":"electronic","value":"2042-8812"}],"subject":[],"published-other":{"date-parts":[[2020,10]]},"published":{"date-parts":[[2020,10,1]]},"article-number":"rjaa418"}}