{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,10,28]],"date-time":"2025-10-28T05:55:54Z","timestamp":1761630954675,"version":"3.41.2"},"reference-count":15,"publisher":"Oxford University Press (OUP)","issue":"5","license":[{"start":{"date-parts":[[2021,5,27]],"date-time":"2021-05-27T00:00:00Z","timestamp":1622073600000},"content-version":"vor","delay-in-days":26,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2021,5,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>Bronchogenic cyst (BC), cyst lined by respiratory epithelium, is uncommon congenital anomaly of bronchial tree. Intraoral BC is extremely rare lesions. Here, we report the unusual presentation of 2-year-old boy with symptomatic cystic lesion at floor of month combined with ankyloglossia. The operation was performed under general anesthesia. Frenotomy was performed. Complete cystic removal was successful with minimal leakage of cyst wall. Sclerosing agent was injected at surgical site to prevent the residual undetected cystic malformation. Pathological examination was demonstrated a unicystic lesion lined by ciliated pseudostratified columnar and cuboidal cells. The final diagnosis was bronchogenic cyst. No postoperative complication was found. The long-term course was uneventful with no signs of recurrence at 1\u00a0year. To our best knowledge, a rare example of BC at the floor of mouth combined with ankyloglossia has never been reported.<\/jats:p>","DOI":"10.1093\/jscr\/rjab211","type":"journal-article","created":{"date-parts":[[2021,5,5]],"date-time":"2021-05-05T13:30:26Z","timestamp":1620221426000},"source":"Crossref","is-referenced-by-count":1,"title":["Bronchogenic cyst of the floor of mouth combined with ankyloglossia: an extremely rare presentation of rare anomaly"],"prefix":"10.1093","volume":"2021","author":[{"given":"Nuttadon","family":"Wongprakob","sequence":"first","affiliation":[{"name":"Division of Plastic and Reconstructive Surgery, Department of Surgery, Phramongkutklao Hospital, Bangkok, Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Suthida","family":"Sae-Guay","sequence":"additional","affiliation":[{"name":"Division of Pediatric Surgery, Department of Surgery, Phramongkutklao Hospital and Phramongkutklao College of Medicine, Bangkok, Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Chairat","family":"Burusapat","sequence":"additional","affiliation":[{"name":"Division of Plastic and Reconstructive Surgery, Department of Surgery, Phramongkutklao Hospital and Phramongkutklao College of Medicine, Bangkok, Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kittisak","family":"Wongchansom","sequence":"additional","affiliation":[{"name":"Department of Pathology and Laboratory Medicine, Phramongkutklao Hospital, Bangkok, Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Nutthapong","family":"Wanichjaroen","sequence":"additional","affiliation":[{"name":"Division of Plastic and Reconstructive Surgery, Department of Surgery, Phramongkutklao Hospital and Phramongkutklao College of Medicine, Bangkok, Thailand"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2021,5,27]]},"reference":[{"key":"2021070811442391400_ref1","doi-asserted-by":"crossref","first-page":"476","DOI":"10.1097\/00000658-194803000-00010","article-title":"Bronchogenic cysts of the mediastinum","volume":"127","author":"Maier","year":"1948","journal-title":"Ann Surg"},{"key":"2021070811442391400_ref2","doi-asserted-by":"crossref","first-page":"817","DOI":"10.1016\/0002-9149(75)90466-X","article-title":"Intrapericardial bronchogenic cysts","volume":"36","author":"Gomes","year":"1975","journal-title":"Am J Cardiol"},{"key":"2021070811442391400_ref3","doi-asserted-by":"crossref","first-page":"1165","DOI":"10.2214\/ajr.138.6.1165","article-title":"Transdiaphragmatic bronchopulmonary foregut anomaly: \"Dumbell\" bronchogenic cyst","volume":"138","author":"Amendola","year":"1982","journal-title":"AJR Am J Roentgenol"},{"key":"2021070811442391400_ref4","doi-asserted-by":"crossref","first-page":"93","DOI":"10.1007\/BF00739965","article-title":"Bronchogenic cyst in the abdomen","volume":"408","author":"Sumiyoshi","year":"1985","journal-title":"Virchows Arch A Pathol Anat Histopathol"},{"key":"2021070811442391400_ref5","doi-asserted-by":"crossref","first-page":"993","DOI":"10.1016\/S0022-3468(88)80002-2","article-title":"Subcutaneous bronchogenic cysts","volume":"23","author":"Bagwell","year":"1988","journal-title":"J Pediatr Surg"},{"key":"2021070811442391400_ref6","doi-asserted-by":"crossref","first-page":"724","DOI":"10.1016\/j.amjoto.2016.11.008","article-title":"Oral foregut duplication cysts: a rare and fascinating congenital lesion. 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