{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,1,8]],"date-time":"2026-01-08T16:56:02Z","timestamp":1767891362557,"version":"3.49.0"},"reference-count":13,"publisher":"Oxford University Press (OUP)","issue":"5","license":[{"start":{"date-parts":[[2022,5,24]],"date-time":"2022-05-24T00:00:00Z","timestamp":1653350400000},"content-version":"vor","delay-in-days":23,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2022,5,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>A Japanese boy, presented with epibulbar dermoid and ipsilateral preauricular appendages, had a pit on his cheek of the same side. An atrial septal defect and vertebral fusions were also identified. He was diagnosed with a mild type of oculo-auriculo-vertebral spectrum (OAVS). At the age of 18\u00a0months, his cheek was swollen with a slight fever. An infected cyst and cutaneous fistula enveloped by the risorius muscle were extracted. It was assumed to be a remnant of the fissure between the maxillary and mandibular prominences. This was the first case of cutaneous fistula confirmed histologically with OAVS, although there seem to be more cases. The possibility of the mechanism of smiling cheek dimple is also discussed.<\/jats:p>","DOI":"10.1093\/jscr\/rjac187","type":"journal-article","created":{"date-parts":[[2022,4,15]],"date-time":"2022-04-15T11:09:57Z","timestamp":1650020997000},"source":"Crossref","is-referenced-by-count":2,"title":["Cutaneous fistula on the cheek associated with oculo-auriculo-vertebral spectrum"],"prefix":"10.1093","volume":"2022","author":[{"given":"Soh","family":"Nishimoto","sequence":"first","affiliation":[{"name":"Department of Plastic Surgery, Hyogo College of Medicine, Nishinomiya, Hyogo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Kenichiro","family":"Kawai","sequence":"additional","affiliation":[{"name":"Department of Plastic Surgery, Hyogo College of Medicine, Nishinomiya, Hyogo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Toshihiro","family":"Fujiwara","sequence":"additional","affiliation":[{"name":"Department of Plastic Surgery, Hyogo College of Medicine, Nishinomiya, Hyogo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hisako","family":"Ishise","sequence":"additional","affiliation":[{"name":"Department of Plastic Surgery, Hyogo College of Medicine, Nishinomiya, Hyogo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Masao","family":"Kakibuchi","sequence":"additional","affiliation":[{"name":"Department of Plastic Surgery, Hyogo College of Medicine, Nishinomiya, Hyogo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2022,5,24]]},"reference":[{"key":"2022052419364536000_ref1","doi-asserted-by":"crossref","first-page":"361","DOI":"10.1002\/ajmg.1320260215","article-title":"Oculoauriculovertebral dysplasia and variants: phenotypic characteristics of 294 patients","volume":"26","author":"Rollnick","year":"1987","journal-title":"Am J Med Genet"},{"key":"2022052419364536000_ref2","doi-asserted-by":"crossref","first-page":"443","DOI":"10.1017\/S0370164600039778","article-title":"A description of congenital malformation of the auricle and external meatus of both sides in three persons, with experiments on the state of hearing in them, and remarks on the mode of hearing by conduction through the hard parts of the head in general","volume":"1","author":"Allen","year":"1845","journal-title":"N Proc R Soc Edinburgh"},{"key":"2022052419364536000_ref3","doi-asserted-by":"crossref","first-page":"485","DOI":"10.1097\/00006534-196511000-00001","article-title":"The first and second branchial arch syndrome","volume":"36","author":"Grabb","year":"1965","journal-title":"Plast Reconstr Surg"},{"key":"2022052419364536000_ref4","doi-asserted-by":"crossref","first-page":"136","DOI":"10.1288\/00005537-198702000-00003","article-title":"First branchial cleft cysts: clinical update","volume":"97","author":"Finn","year":"1987","journal-title":"Laryngoscope"},{"key":"2022052419364536000_ref5","doi-asserted-by":"crossref","first-page":"361","DOI":"10.1136\/jmg.2008.062158","article-title":"Genetics of microtia and associated syndromes","volume":"46","author":"Alasti","year":"2009","journal-title":"J Med Genet"},{"key":"2022052419364536000_ref6","doi-asserted-by":"crossref","first-page":"69","DOI":"10.1016\/S0301-0503(76)80013-6","article-title":"Anatomical classification facial, cranio-facial and latero-facial clefts","volume":"4","author":"Tessier","year":"1976","journal-title":"J Maxillofac Surg"},{"key":"2022052419364536000_ref7","first-page":"243","article-title":"Associations malformatives de l\u2019oeil et de l\u2019oreille, en particulier le syndrome dermo\u00efde epibulbaire-appendices auriculaires-fistula auris congenita et ses relations avec la dysostose mandibulo-faciale","volume":"1","author":"Goldenhar","year":"1952","journal-title":"J Genet Hum"},{"key":"2022052419364536000_ref8","doi-asserted-by":"crossref","first-page":"991","DOI":"10.1016\/S0022-3476(63)80233-4","article-title":"Oculoauriculovertebral dysplasia","volume":"63","author":"Gorlin","year":"1963","journal-title":"J Pediatr"},{"key":"2022052419364536000_ref9","volume-title":"The Developing Human\u00a0: Clinically Oriented Embryology","author":"Moore","year":"2018","edition":"11th"},{"key":"2022052419364536000_ref10","doi-asserted-by":"crossref","first-page":"360","DOI":"10.1002\/lary.24859","article-title":"Cheek fistula from the ectopic salivary gland: a variant of the oculo-auriculo-vertebral spectrum","volume":"125","author":"Sun","year":"2015","journal-title":"Laryngoscope"},{"key":"2022052419364536000_ref11","doi-asserted-by":"crossref","first-page":"1351","DOI":"10.1002\/lary.26343","article-title":"The ectopic accessory parotid system with congenital cheek fistula: an overview and current update","volume":"127","author":"Dutta","year":"2017","journal-title":"Laryngoscope"},{"key":"2022052419364536000_ref12","doi-asserted-by":"crossref","first-page":"63","DOI":"10.1002\/ar.1091670107","article-title":"The early development of the parotid gland around the facial nerve and its branches in man","volume":"167","author":"Gasser","year":"1970","journal-title":"Anat Rec"},{"key":"2022052419364536000_ref13","doi-asserted-by":"crossref","first-page":"310","DOI":"10.1002\/(SICI)1098-2353(1998)11:5<310::AID-CA3>3.0.CO;2-T","article-title":"Double or bifid zygomaticus major muscle: anatomy, incidence, and clinical correlation","volume":"11","author":"Pessa","year":"1998","journal-title":"Clin Anat"}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2022\/5\/rjac187\/43800701\/rjac187.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2022\/5\/rjac187\/43800701\/rjac187.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2022,5,24]],"date-time":"2022-05-24T19:37:28Z","timestamp":1653421048000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjac187\/6590881"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2022,5,1]]},"references-count":13,"journal-issue":{"issue":"5","published-print":{"date-parts":[[2022,5,1]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjac187","relation":{},"ISSN":["2042-8812"],"issn-type":[{"value":"2042-8812","type":"electronic"}],"subject":[],"published-other":{"date-parts":[[2022,5]]},"published":{"date-parts":[[2022,5,1]]},"article-number":"rjac187"}}