{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,5]],"date-time":"2026-06-05T10:19:14Z","timestamp":1780654754889,"version":"3.54.1"},"reference-count":14,"publisher":"Oxford University Press (OUP)","issue":"6","license":[{"start":{"date-parts":[[2022,6,7]],"date-time":"2022-06-07T00:00:00Z","timestamp":1654560000000},"content-version":"vor","delay-in-days":6,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2022,6,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>The occurrence of a pathological fracture in children requires a rigorous diagnostic approach in order to establish the etiology and to develop a precise therapeutic strategy. Several causes are associated with these fractures, the most frequent being benign tumors in children in developed countries and chronic osteomyelitis in developing countries. More rarely, malignant tumors must however always be considered. The differential diagnosis on imaging may be difficult to establish between bone tumors and chronic infection. Surgical biopsy is therefore often performed to establish the precise origin of the fracture. We report the case of an adamantinoma (osteofibrous dysplasia-like) of the fibula in a 7-year-old child, discovered during the management of a pathologic fracture. The presumed diagnosis before biopsy was chronic osteomyelitis. A 14-cm-resection of the affected fibula was performed with good functional result. Differential diagnosis between adamantinoma, osteofibrous dysplasia and osteofibrous dysplasia-like adamantinoma remains very challenging.<\/jats:p>","DOI":"10.1093\/jscr\/rjac196","type":"journal-article","created":{"date-parts":[[2022,6,7]],"date-time":"2022-06-07T19:59:41Z","timestamp":1654631981000},"source":"Crossref","is-referenced-by-count":1,"title":["Osteofibrous dysplasia-like adamantinoma of isolated fibula in a child mimicking chronic osteomyelitis with pathological fracture"],"prefix":"10.1093","volume":"2022","author":[{"given":"Pierre-Emmanuel","family":"Goetz","sequence":"first","affiliation":[{"name":"Cliniques Universitaires Saint-Luc , Service de Chirurgie Orthop\u00e9dique et Traumatologique, Bruxelles, Belgium"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Dana","family":"Dumitriu","sequence":"additional","affiliation":[{"name":"Cliniques Universitaires Saint-Luc , Service d\u2019Imagerie M\u00e9dicale, Bruxelles, Belgium"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Christine","family":"Galant","sequence":"additional","affiliation":[{"name":"Cliniques Universitaires Saint-Luc , Service d\u2019Anatomie Pathologique, Bruxelles, Belgium"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0309-3970","authenticated-orcid":false,"given":"Pierre-Louis","family":"Docquier","sequence":"additional","affiliation":[{"name":"Cliniques Universitaires Saint-Luc , Service de Chirurgie Orthop\u00e9dique et Traumatologique, Bruxelles, Belgium"},{"name":"Secteur des Sciences de la Sant\u00e9 , Institut de Recherche Exp\u00e9rimentale et Clinique, Neuro Musculo Skeletal Lab (NMSK), Universit\u00e9 Catholique de Louvain, Bruxelles, Belgique"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"286","published-online":{"date-parts":[[2022,6,7]]},"reference":[{"key":"2022060719593388300_ref1","doi-asserted-by":"crossref","first-page":"358","DOI":"10.5435\/00124635-201006000-00008","article-title":"Osteofibrous dysplasia and adamantinoma","volume":"18","author":"Most","year":"2010","journal-title":"J Am Acad Orthop Surg"},{"key":"2022060719593388300_ref2","doi-asserted-by":"crossref","first-page":"200","DOI":"10.1016\/j.crad.2013.09.011","article-title":"Imaging in osteofibrous dysplasia, osteofibrous dysplasia-like adamantinoma, and classic adamantinoma","volume":"69","author":"Bethapudi","year":"2014","journal-title":"Clin Radiol"},{"key":"2022060719593388300_ref3","doi-asserted-by":"crossref","first-page":"S149","DOI":"10.1016\/j.otsr.2015.05.010","article-title":"Pathological fractures in children: diagnosis and treatment options","volume":"102","author":"Canavese","year":"2016","journal-title":"Orthop Traumatol Surg Res"},{"key":"2022060719593388300_ref4","first-page":"463","volume-title":"Adamantinoma of Long Bone in WHO Classification of Tumor Soft Tissue and Bone Tumor","author":"Nielsen","year":"2020","edition":"5th"},{"key":"2022060719593388300_ref5","doi-asserted-by":"publisher","DOI":"10.1007\/978-3-030-13290-3_42","volume-title":"Global Orthopedics","author":"Mkandawire","year":"2020"},{"key":"2022060719593388300_ref6","doi-asserted-by":"crossref","first-page":"363","DOI":"10.1097\/PAS.0b013e318150d53e","article-title":"Osteofibrous dysplasia and adamantinoma in children and adolescents: a clinicopathologic reappraisal","volume":"32","author":"Gleason","year":"2008","journal-title":"Am J Surg Pathol"},{"key":"2022060719593388300_ref7","doi-asserted-by":"crossref","first-page":"658","DOI":"10.1302\/0301-620X.88B5.17358","article-title":"Osteofibrous dysplasia of the tibia. Is there a need for a radical surgical approach?","volume":"88","author":"Lee","year":"2006","journal-title":"J Bone Joint Surg Br"},{"key":"2022060719593388300_ref8","doi-asserted-by":"crossref","first-page":"1482","DOI":"10.2106\/00004623-199410000-00008","article-title":"Adamantinoma of the long bones. A clinicopathological study of thirty-two patients with emphasis on histological subtype, precursor lesion, and biological behavior","volume":"76","author":"Hazelbag","year":"1994","journal-title":"J Bone Joint Surg Am"},{"key":"2022060719593388300_ref9","first-page":"E411","article-title":"Osteofibrous dysplasia-like adamantinoma of the tibia in a 15-year-old girl","volume":"44","author":"Ratra","year":"2015","journal-title":"Am J Orthop (Belle Mead NJ)"},{"key":"2022060719593388300_ref10","doi-asserted-by":"crossref","first-page":"809","DOI":"10.1016\/S0046-8177(98)90449-X","article-title":"Osteofibrous dysplasia-like adamantinoma of bone: a report of five cases with immunohistochemical and ultrastructural studies","volume":"29","author":"Kuruvilla","year":"1998","journal-title":"Hum Pathol"},{"key":"2022060719593388300_ref11","doi-asserted-by":"crossref","first-page":"1703","DOI":"10.2106\/JBJS.19.01056","article-title":"Surgical outcome and oncological survival of osteofibrous dysplasia-like and classic adamantinomas: an international multicenter study of 318 cases","volume":"102","author":"Schutgens","year":"2020","journal-title":"J Bone Joint Surg Am"},{"key":"2022060719593388300_ref12","doi-asserted-by":"crossref","first-page":"409","DOI":"10.1302\/0301-620X.99B3.38050","article-title":"Does osteofibrous dysplasia progress to adamantinoma and how should they be treated?","volume":"99-B","author":"Scholfield","year":"2017","journal-title":"Bone Joint J"},{"key":"2022060719593388300_ref13","doi-asserted-by":"crossref","DOI":"10.1016\/j.ijscr.2021.01.093","article-title":"Osteofibrous dysplasia-like adamantinoma versus osteofibrous dysplasia in children: a case report of challenging diagnosis","volume":"80","author":"Kamal","year":"2021","journal-title":"Int J Surg Case Rep"},{"key":"2022060719593388300_ref14","doi-asserted-by":"crossref","first-page":"351","DOI":"10.1016\/j.diii.2012.01.021","article-title":"Pitfalls in osteoarticular imaging: how to distinguish bone infection from tumour?","volume":"93","author":"Moser","year":"2012","journal-title":"Diagn Interv Imaging"}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2022\/6\/rjac196\/43969307\/rjac196.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2022\/6\/rjac196\/43969307\/rjac196.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2022,6,7]],"date-time":"2022-06-07T19:59:51Z","timestamp":1654631991000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjac196\/6603578"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2022,6,1]]},"references-count":14,"journal-issue":{"issue":"6","published-print":{"date-parts":[[2022,6,1]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjac196","relation":{},"ISSN":["2042-8812"],"issn-type":[{"value":"2042-8812","type":"electronic"}],"subject":[],"published-other":{"date-parts":[[2022,6]]},"published":{"date-parts":[[2022,6,1]]},"article-number":"rjac196"}}