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Congenital macroglossia stems from diverse conditions, such as muscular hypertrophy, hemangioma, lymphangioma, Down syndrome, and others. Acquired macroglossia can result from malignancies, endocrine and metabolic disorders, chronic infectious diseases, and head and neck infections, among other factors. Additionally, extended-prone surgery can lead to its development. The incidence of macroglossia is likely underreported. This presentation is rare with only six reported cases in the literature.<\/jats:p>","DOI":"10.1093\/jscr\/rjae313","type":"journal-article","created":{"date-parts":[[2024,5,19]],"date-time":"2024-05-19T19:22:00Z","timestamp":1716146520000},"source":"Crossref","is-referenced-by-count":1,"title":["An idiopathic severe macroglossia in a young adult patient: a rare case"],"prefix":"10.1093","volume":"2024","author":[{"given":"Bassem","family":"Al Hariri","sequence":"first","affiliation":[{"name":"Department of Medicine, Hamad Medical Corporation , Doha , Qatar"},{"name":"Weill Cornell Medicine-Qatar , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0009-0007-6128-1351","authenticated-orcid":false,"given":"Muad Abdi","family":"Hassan","sequence":"additional","affiliation":[{"name":"Medical Education Department, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Muhammad","family":"Sharif","sequence":"additional","affiliation":[{"name":"Department of Medicine, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Rawan S","family":"Mohamed","sequence":"additional","affiliation":[{"name":"Medical Education Department, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hadil Altaj Altrify","family":"Alsidig","sequence":"additional","affiliation":[{"name":"Medical Education Department, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hind Altag Alteraify","family":"Alsiddig","sequence":"additional","affiliation":[{"name":"Medical Education Department, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Memon Noor","family":"Illahi","sequence":"additional","affiliation":[{"name":"Department of Medicine, Hamad Medical Corporation , Doha , Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2024,5,18]]},"reference":[{"key":"2024051919215193300_ref1","first-page":"212","article-title":"\u201cMacroglosia cong\u00e9nita: caracter\u00edsticas cl\u00ednicas y estrategias de tratamiento en la edad pedi\u00e1trica\u201d [congenital macroglossia: clinical features and therapeutic strategies in paediatric patients]","volume":"73","author":"N\u00fa\u00f1ez-Mart\u00ednez","year":"2016","journal-title":"Boletin medico del Hospital Infantil de Mexico"},{"key":"2024051919215193300_ref2","doi-asserted-by":"crossref","first-page":"63","DOI":"10.1111\/j.1875-595X.2011.00015.x","article-title":"Macroglossia","volume":"61","author":"Topouzelis","year":"2011","journal-title":"Int Dent J"},{"key":"2024051919215193300_ref3","doi-asserted-by":"crossref","first-page":"534","DOI":"10.1213\/00000539-199908000-00064","article-title":"Macroglossia, deja vu","volume":"89","author":"Drummond","year":"1999","journal-title":"Anesth Analg"},{"key":"2024051919215193300_ref4","doi-asserted-by":"crossref","first-page":"382","DOI":"10.1111\/j.1365-2044.1988.tb09018.x","article-title":"Macroglossia and posterior fossa disease","volume":"43","author":"Moore","year":"1988","journal-title":"Anaesthesia"},{"key":"2024051919215193300_ref5","doi-asserted-by":"crossref","first-page":"078","DOI":"10.4103\/jnacc-jnacc-64.16","article-title":"Macroglossia in neurosurgery","volume":"04","author":"Brockerville","year":"2017","journal-title":"J Neuroanaesth Crit Care"},{"key":"2024051919215193300_ref6","doi-asserted-by":"crossref","first-page":"169","DOI":"10.1016\/S0377-1237(01)80147-7","article-title":"Macroglossia: a rare clinical entity","volume":"57","author":"Nambiar","year":"2001","journal-title":"Med J Armed Forces India"}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2024\/5\/rjae313\/57742484\/rjae313.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2024\/5\/rjae313\/57742484\/rjae313.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2024,5,19]],"date-time":"2024-05-19T19:22:06Z","timestamp":1716146526000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjae313\/7676256"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2024,5]]},"references-count":6,"journal-issue":{"issue":"5","published-print":{"date-parts":[[2024,5,2]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjae313","relation":{},"ISSN":["2042-8812"],"issn-type":[{"type":"electronic","value":"2042-8812"}],"subject":[],"published-other":{"date-parts":[[2024,5]]},"published":{"date-parts":[[2024,5]]},"article-number":"rjae313"}}