{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,3,17]],"date-time":"2026-03-17T21:49:50Z","timestamp":1773784190756,"version":"3.50.1"},"reference-count":15,"publisher":"Oxford University Press (OUP)","issue":"3","license":[{"start":{"date-parts":[[2026,3,17]],"date-time":"2026-03-17T00:00:00Z","timestamp":1773705600000},"content-version":"vor","delay-in-days":16,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2026,3,6]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:p>Melorheostosis is a progressive sclerosing bone dysplasia that rarely involves the spine. When spinal involvement occurs, it can lead to significant neurological compromise due to spinal cord compression. We report the case of a previously healthy 22-year-old woman who presented with progressive gait instability and upper motor neuron symptoms secondary to a hyperostotic lesion extending from C2 to C5. Imaging demonstrated severe left-sided spinal canal stenosis, prompting urgent surgical decompression with posterior cervical fusion. Intraoperative neuromonitoring showed complete loss of all sensory and motor potentials from the left side following decompression. Accordingly, she woke up with complete hemiplegia; however, rapid improvement was noted over the following days. Through analysis of 25 documented cases, we highlight the variability in anatomical involvement, clinical presentation, and management strategies. This report underscores the importance of an individually tailored surgical intervention and contributes to the scarce literature on cervical spinal melorheostosis.<\/jats:p>","DOI":"10.1093\/jscr\/rjag125","type":"journal-article","created":{"date-parts":[[2026,3,17]],"date-time":"2026-03-17T18:06:51Z","timestamp":1773770811000},"source":"Crossref","is-referenced-by-count":0,"title":["Cervical spinal melorheostosis causing myelopathy: a rare case and review of the literature"],"prefix":"10.1093","volume":"2026","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-5931-5822","authenticated-orcid":false,"given":"Naama","family":"Turner","sequence":"first","affiliation":[{"name":"Department of Neurosurgery, Rambam Health Care Campus , Ha Aliya Ha Shniya St 8, Haifa 3109601 ,","place":["Israel"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ravit Gabay","family":"Yehezkely","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Rambam Health Care Campus , Ha Aliya Ha Shniya St 8, Haifa 3109601 ,","place":["Israel"]},{"name":"Technion - Israel Institute of Technology , Efron 1, Haifa ,","place":["Israel"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Shady","family":"Hayek","sequence":"additional","affiliation":[{"name":"Department of Neurosurgery, Rambam Health Care Campus , Ha Aliya Ha Shniya St 8, Haifa 3109601 ,","place":["Israel"]}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2026,3,17]]},"reference":[{"key":"2026031714064793100_ref1","first-page":"1141","article-title":"Une affection non d\u00e9crite des os: hyperostose \u201cen coul\u00e9e\u201d Sur toute la longueur d\u2019un membre ou \u201cmelorheostose.\u201d","volume":"46","author":"Leri","year":"1922","journal-title":"Bull Mem Soc Med Hop 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presentation.","author":"Serttas","journal-title":"JBJS Case Connect"},{"key":"2026031714064793100_ref9","doi-asserted-by":"publisher","first-page":"2050313X20940564","DOI":"10.1177\/2050313X20940564","article-title":"The dripping candle wax sign of melorheostosis","volume":"8","author":"Hoang","year":"2020","journal-title":"SAGE Open Med Case Rep"},{"key":"2026031714064793100_ref10","doi-asserted-by":"publisher","first-page":"2415","DOI":"10.1016\/j.radcr.2020.09.028","article-title":"Axial melorheostosis: a rare presentation","volume":"15","author":"Bayya","year":"2020","journal-title":"Radiol Case Rep"},{"key":"2026031714064793100_ref11","first-page":"1198","article-title":"Melorheostosis involving the cervical and upper thoracic spine: radiographic, CT, and MR imaging findings","volume":"27","author":"Motimaya","year":"2006","journal-title":"AJNR Am J 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