{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,2]],"date-time":"2026-05-02T22:48:59Z","timestamp":1777762139325,"version":"3.51.4"},"reference-count":15,"publisher":"Oxford University Press (OUP)","issue":"4","license":[{"start":{"date-parts":[[2026,4,29]],"date-time":"2026-04-29T00:00:00Z","timestamp":1777420800000},"content-version":"vor","delay-in-days":28,"URL":"https:\/\/creativecommons.org\/licenses\/by-nc\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2026,4,1]]},"abstract":"<jats:title>Abstract<\/jats:title>\n                  <jats:p>Osteogenesis imperfecta (OI) is a rare genetic disorder marked by bone fragility and progressive deformity. Type III OI represents a severe form characterized by recurrent fractures, bowing, and significant functional impairment. We report a 17-year-old with type III OI and an extreme 111.4\u00b0 tibial procurvatum deformity alongside recurrent femoral fractures. His history included multiple intramedullary nailing procedures and revision surgeries. The most recent treatment involved a two-level tibial osteotomy with subsequent cast immobilization, resulting in marked improvement. The Lower Extremity Functional Scale increased from 38\/80 preoperatively to 70\/80 at follow-up, surpassing the minimal clinically important difference. Severe long bone deformities exceeding 60\u201390\u00b0 in OI are uncommon and require individualized, multidisciplinary care. Multilevel osteotomies with intramedullary fixation remain central to correction, though complications persist. This case highlights the complexity of managing extreme tibial deformities in OI and supports multistage reconstruction to restore alignment and function.<\/jats:p>","DOI":"10.1093\/jscr\/rjag213","type":"journal-article","created":{"date-parts":[[2026,3,14]],"date-time":"2026-03-14T12:38:58Z","timestamp":1773491938000},"source":"Crossref","is-referenced-by-count":0,"title":["Corrective osteotomy for 111.4-degree tibial procurvatum in osteogenesis imperfecta type III patient: a rare case report with multistage interventions"],"prefix":"10.1093","volume":"2026","author":[{"given":"Badr","family":"Alshehri","sequence":"first","affiliation":[{"name":"Orthopedic Department, King Saud University Medical City , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0009-0008-4861-733X","authenticated-orcid":false,"given":"Abdulaziz S","family":"AlNahari","sequence":"additional","affiliation":[{"name":"College of Medicine, King Saud University , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Bandar I","family":"Aljammaz","sequence":"additional","affiliation":[{"name":"Orthopedic Department, King Saud University Medical City , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Abdulrahman M","family":"Alrajhi","sequence":"additional","affiliation":[{"name":"Orthopedic Department, King Saud University Medical City , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Abdullah A","family":"Alqarni","sequence":"additional","affiliation":[{"name":"College of Medicine, King Saud University , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Fahad S","family":"Alhuzaimi","sequence":"additional","affiliation":[{"name":"King Saud University Medical City , Riyadh ,","place":["Saudi Arabia"]}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2026,4,29]]},"reference":[{"key":"2026042910254878400_ref1","doi-asserted-by":"publisher","first-page":"69","DOI":"10.3892\/wasj.2024.284","article-title":"Beyond brittle bones: genetic mechanisms underlying osteogenesis imperfecta (review)","volume":"6","author":"Khan","year":"2024","journal-title":"World Acad Sci J"},{"key":"2026042910254878400_ref2","first-page":"64","article-title":"The orthopaedic assessment of children with osteogenesis imperfecta","volume":"74","author":"Laliotis","year":"2023","journal-title":"Acta Orthop Trauma Hell"},{"key":"2026042910254878400_ref3","doi-asserted-by":"publisher","first-page":"316","DOI":"10.1016\/j.jor.2020.05.017","article-title":"Combined technique of titanium telescopic rods and external fixation in osteogenesis imperfecta patients: first 12 consecutive cases","volume":"22","author":"Popkov","year":"2020","journal-title":"J Orthop"},{"key":"2026042910254878400_ref4","doi-asserted-by":"publisher","first-page":"480","DOI":"10.1590\/s1679-45082010rc1863","article-title":"Severe osteogenesis imperfecta: case report","volume":"8","author":"Bastos","year":"2010","journal-title":"Einstein (S\u00e3o Paulo)"},{"key":"2026042910254878400_ref5","doi-asserted-by":"publisher","first-page":"e70609","DOI":"10.7759\/cureus.70609","article-title":"Management of multiple fractures in a preadolescent with osteogenesis imperfecta types III-IV","volume":"16","author":"Somankar","year":"2024","journal-title":"Cureus"},{"key":"2026042910254878400_ref6","doi-asserted-by":"publisher","DOI":"10.26502\/acmcr.96550673","article-title":"Management of a severe case of osteogenesis imperfecta in Ghana: evaluation of outcome","volume":"8","author":"","year":"2024","journal-title":"Arch Clin Med Case Rep"},{"key":"2026042910254878400_ref7","doi-asserted-by":"publisher","first-page":"165","DOI":"10.1016\/j.reumae.2018.05.001","article-title":"Osteogenesis imperfecta. Report of 15 cases","volume":"16","author":"L\u00f3pez","year":"2019","journal-title":"Reumatolog\u00eda Cl\u00ednica (English Edition)"},{"key":"2026042910254878400_ref8","doi-asserted-by":"publisher","first-page":"114","DOI":"10.1016\/j.recote.2014.01.009","article-title":"Osteogenesis imperfecta: treatment and results of a case series","volume":"58","author":"Rey","year":"2014","journal-title":"Revista Espa\u00f1ola De Cirug\u00eda Ortop\u00e9dica Y Traumatolog\u00eda"},{"key":"2026042910254878400_ref9","article-title":"Osteogenesis imperfecta type III \u2013 a short review and an example of personalized surgery approach","author":"Primorac","year":"2021"},{"key":"2026042910254878400_ref10","doi-asserted-by":"publisher","DOI":"10.2106\/jbjs.cc.21.00480","article-title":"An unusual presentation of osteogenesis imperfecta","volume":"11","author":"Lindsay","year":"2021","journal-title":"JBJS Case Connector"},{"key":"2026042910254878400_ref11","doi-asserted-by":"publisher","first-page":"608","DOI":"10.1080\/17453674.2021.1941628","article-title":"A roadmap to surgery in osteogenesis imperfecta: results of an international collaboration of patient organizations and interdisciplinary care teams","volume":"92","author":"Sakkers","year":"2021","journal-title":"Acta Orthop"},{"key":"2026042910254878400_ref12","doi-asserted-by":"publisher","first-page":"56","DOI":"10.20473\/joints.v14i1.2025.56-63","article-title":"Type III osteogenesis imperfecta with severe limb deformities: A report with review of the literature","volume":"14","author":"Zacharia","year":"2025","journal-title":"J Orthop Traumatol Surabaya"},{"key":"2026042910254878400_ref13","doi-asserted-by":"publisher","first-page":"1540","DOI":"10.12659\/ajcr.918560","article-title":"Surgical treatment of bilateral tibia deformity in a 9-year-old child suffering from osteogenesis imperfecta type III: A case report","volume":"20","author":"Delniotis","year":"2019","journal-title":"Am J Case Rep"},{"key":"2026042910254878400_ref14","doi-asserted-by":"publisher","first-page":"543","DOI":"10.25122\/jml-2020-0161","article-title":"Revision rates for osteogenesis imperfecta patients treated with telescopic nails. A follow-up study after a 7-year experience","volume":"13","author":"Sterian","year":"2020","journal-title":"J Med Life"},{"key":"2026042910254878400_ref15","doi-asserted-by":"publisher","first-page":"199","DOI":"10.1177\/18632521251332498","article-title":"Plates for the treatment of long bone metaphyseal and diaphyseal fracture and deformity in osteogenesis imperfecta: A scoping review","volume":"19","author":"Louni","year":"2025","journal-title":"J Child Orthop"}],"container-title":["Journal of Surgical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2026\/4\/rjag213\/68186147\/rjag213.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/jscr\/article-pdf\/2026\/4\/rjag213\/68186147\/rjag213.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2026,4,29]],"date-time":"2026-04-29T14:25:56Z","timestamp":1777472756000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/jscr\/article\/doi\/10.1093\/jscr\/rjag213\/8664821"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2026,4,1]]},"references-count":15,"journal-issue":{"issue":"4","published-print":{"date-parts":[[2026,4,1]]}},"URL":"https:\/\/doi.org\/10.1093\/jscr\/rjag213","relation":{},"ISSN":["2042-8812"],"issn-type":[{"value":"2042-8812","type":"electronic"}],"subject":[],"published-other":{"date-parts":[[2026,4]]},"published":{"date-parts":[[2026,4,1]]},"article-number":"rjag213"}}