{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,8,25]],"date-time":"2025-08-25T06:40:01Z","timestamp":1756104001979,"version":"3.44.0"},"reference-count":10,"publisher":"Oxford University Press (OUP)","issue":"8","license":[{"start":{"date-parts":[[2025,8,25]],"date-time":"2025-08-25T00:00:00Z","timestamp":1756080000000},"content-version":"vor","delay-in-days":24,"URL":"https:\/\/creativecommons.org\/licenses\/by\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2025,8,11]]},"abstract":"<jats:title>Abstract<\/jats:title>\n               <jats:p>Introduction: Syringomyelia is a rare pathology which is rarely revealed by urinary urgency. We report the case of a 20-year-old man with persistent urinary urgency and pollakiuria for two years, with no identifiable organic cause despite a thorough urological work-up. A transient episode of lower limb atony prompted spinal MRI, which revealed an isolated syrinx at the T6\u2013T7 level, without associated Chiari malformation or conus medullaris involvement. The final diagnosis was vesico-sphincter dyssynergia with overactive bladder syndrome secondary to idiopathic thoracic syringomyelia. Conservative management, including anticholinergic therapy and psychological support, led to significant clinical improvement. Conclusion: As illustrated by our case, syringomyelia may present exclusively with urinary symptoms. However, such presentation is uncommon. This case highlights the importance of considering spinal cord pathology in the differential diagnosis of unexplained urinary symptoms, even in the absence of overt neurological deficits.<\/jats:p>","DOI":"10.1093\/omcr\/omaf149","type":"journal-article","created":{"date-parts":[[2025,8,25]],"date-time":"2025-08-25T06:15:25Z","timestamp":1756102525000},"source":"Crossref","is-referenced-by-count":0,"title":["Pollakiuria: a rare and unique mode of revelation of silent dorsal syringomyelia in a young man\u2014a case report"],"prefix":"10.1093","volume":"2025","author":[{"ORCID":"https:\/\/orcid.org\/0009-0002-9353-1662","authenticated-orcid":false,"given":"Richard","family":"Houeze","sequence":"first","affiliation":[{"name":"University Neurology Clinic, National University Hospital Center Hubert , Koutoukou MAGA Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mendinatou","family":"Agbetou Houessou","sequence":"additional","affiliation":[{"name":"Department of Neurology, Faculty of Health Sciences , University of Parakou, Zongo II District, Parakou, Borgou Department, P.O. Box 123, Parakou, Republic of","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Alexandre D","family":"Faton","sequence":"additional","affiliation":[{"name":"University Clinic for Physical Medicine and Rehabilitation , National University Hospital Center Hubert, Koutoukou MAGA, Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0009-0008-3761-6577","authenticated-orcid":false,"given":"Salim","family":"Djaouga","sequence":"additional","affiliation":[{"name":"University Neurology Clinic, National University Hospital Center Hubert , Koutoukou MAGA Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Richmine","family":"Covi Zinsou","sequence":"additional","affiliation":[{"name":"University Neurology Clinic, National University Hospital Center Hubert , Koutoukou MAGA Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Eug\u00e9nie","family":"Dansou","sequence":"additional","affiliation":[{"name":"University Internal Medicine Clinic, National University Hospital Center Hubert , Koutoukou MAGA, Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Martial","family":"Avoce","sequence":"additional","affiliation":[{"name":"University Neurology Clinic, National University Hospital Center Hubert , Koutoukou MAGA Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Constant K","family":"Adjien","sequence":"additional","affiliation":[{"name":"University Neurology Clinic, National University Hospital Center Hubert , Koutoukou MAGA Littoral Department, Cotonou Cadjehoun District, Avenue Jean-Paul II, P.O. Box 01BP386,","place":["Benin"]}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"286","published-online":{"date-parts":[[2025,8,25]]},"reference":[{"key":"2025082502151981400_ref1","doi-asserted-by":"crossref","first-page":"179","DOI":"10.1007\/978-2-287-99160-8_16","volume-title":"Les incontinences urinaires de l'homme: Diagnostics et traitements","author":"Denys","year":"2011"},{"key":"2025082502151981400_ref2","doi-asserted-by":"publisher","first-page":"407","DOI":"10.1136\/jnnp.61.4.407","article-title":"Reversible urinary retention as the main symptom in the first manifestation of a syringomyelia","volume":"61","author":"Amoiridis","year":"1996","journal-title":"J Neurol Neurosurg Psychiatry"},{"key":"2025082502151981400_ref3","doi-asserted-by":"publisher","first-page":"100","DOI":"10.1016\/S0022-510X(96)00178-5","article-title":"Micturitional disturbance in syringomyelia","volume":"143","author":"Sakakibara","year":"1996","journal-title":"J Neurol Sci"},{"key":"2025082502151981400_ref4","volume-title":"Neuroscience","author":"Purves","year":"2001","edition":"2nd edition"},{"key":"2025082502151981400_ref5","first-page":"260","article-title":"Retension aigue d'urines: un mode de revelation rare d'une syringomyelie cervicodorsale a l'occasion de la prise de cyproheptadine","volume":"1","author":"Houang","year":"1994","journal-title":"Arch Pediatr"},{"key":"2025082502151981400_ref6","doi-asserted-by":"publisher","first-page":"738","DOI":"10.1136\/jnnp.54.8.738","article-title":"Neurophysiological findings and MRI in anterior spinal artery syndrome of the lower cervical cord: the value of F-waves","volume":"54","author":"Amoiridis","year":"1991","journal-title":"J Neurol Neurosurg Psychiatry"},{"key":"2025082502151981400_ref7","doi-asserted-by":"publisher","first-page":"479","DOI":"10.1016\/0168-5597(95)00096-B","article-title":"Recovery after surgery of the spinal N24 SEP in dural arteriovenous malformation of the dorsal cord","volume":"96","author":"Valeriani","year":"1995","journal-title":"Electroencephalogr Clin Neurophysiol"},{"key":"2025082502151981400_ref8","doi-asserted-by":"publisher","first-page":"146","DOI":"10.1016\/j.annrmp.2004.09.007","article-title":"Association de maladie de Charcot-Marie-tooth et de syringomy\u00e9lie r\u00e9v\u00e9l\u00e9e par la survenue de troubles urinaires","volume":"48","author":"Lassalle","year":"2005","journal-title":"Ann Readapt Med Phys"},{"key":"2025082502151981400_ref9","doi-asserted-by":"publisher","first-page":"451","DOI":"10.1177\/088307389501000605","article-title":"Neurophysiologic assessment of urinary dysfunction in children with thoracic syringomyelia","volume":"10","author":"Kothari","year":"1995","journal-title":"J Child Neurol"},{"key":"2025082502151981400_ref10","doi-asserted-by":"publisher","first-page":"13","DOI":"10.3109\/02688699209002896","article-title":"Syringomyelia in children : six case reports and review of the literature","volume":"6","author":"Iqbal","year":"1992","journal-title":"Br J Neurosurg"}],"container-title":["Oxford Medical Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/academic.oup.com\/omcr\/article-pdf\/2025\/8\/omaf149\/64116229\/omaf149.pdf","content-type":"application\/pdf","content-version":"vor","intended-application":"syndication"},{"URL":"https:\/\/academic.oup.com\/omcr\/article-pdf\/2025\/8\/omaf149\/64116229\/omaf149.pdf","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2025,8,25]],"date-time":"2025-08-25T06:15:26Z","timestamp":1756102526000},"score":1,"resource":{"primary":{"URL":"https:\/\/academic.oup.com\/omcr\/article\/doi\/10.1093\/omcr\/omaf149\/8240496"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2025,8]]},"references-count":10,"journal-issue":{"issue":"8","published-print":{"date-parts":[[2025,8,11]]}},"URL":"https:\/\/doi.org\/10.1093\/omcr\/omaf149","relation":{},"ISSN":["2053-8855"],"issn-type":[{"type":"electronic","value":"2053-8855"}],"subject":[],"published-other":{"date-parts":[[2025,8]]},"published":{"date-parts":[[2025,8]]},"article-number":"omaf149"}}