{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,1,16]],"date-time":"2026-01-16T07:36:02Z","timestamp":1768548962213,"version":"3.49.0"},"reference-count":27,"publisher":"Ovid Technologies (Wolters Kluwer Health)","issue":"9","license":[{"start":{"date-parts":[[2016,9,1]],"date-time":"2016-09-01T00:00:00Z","timestamp":1472688000000},"content-version":"unspecified","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":[],"published-print":{"date-parts":[[2016,9]]},"abstract":"<jats:p>Myxoid liposarcomas (MLSs) are genetically defined by the presence of <jats:italic toggle=\"yes\">DDIT3<\/jats:italic> gene fusions and most commonly arise in the extremities of young adults. Whether MLSs develop primarily in the retroperitoneum is controversial, and a recent retrospective study found no molecularly confirmed examples. Because MLSs tend to metastasize to deep soft tissues, purported examples of primary retroperitoneal lesions might represent distant metastasis, most commonly from extremities. In addition, well-differentiated or dedifferentiated liposarcomas, which are characterized by <jats:italic toggle=\"yes\">MDM2<\/jats:italic> amplifications, may exhibit prominent myxoid changes and mimic MLSs. Here, we document 5 cases of MLSs that originated in the retroperitoneum that were identified through critical clinicopathologic reevaluation. These cases accounted for 2.3% of 214 primary retroperitoneal liposarcomas and 3.2% of 156 MLSs in our database. They occurred in 3 men and 2 women with a median age of 32 years. All tumors were localized to the retroperitoneum at presentation, and no patient developed extra-abdominal recurrences during the clinical course (median, 50 mo). All 5 cases exhibited at least focal classic histologic findings. All harbored <jats:italic toggle=\"yes\">DDIT3<\/jats:italic> gene rearrangements, and none harbored <jats:italic toggle=\"yes\">MDM2<\/jats:italic> amplifications according to fluorescence in situ hybridization. This study demonstrates that primary MLSs can occur in the retroperitoneum, albeit rarely, and can be accurately diagnosed through combined clinicopathologic and molecular analysis.<\/jats:p>","DOI":"10.1097\/pas.0000000000000657","type":"journal-article","created":{"date-parts":[[2016,5,12]],"date-time":"2016-05-12T11:39:34Z","timestamp":1463053174000},"page":"1286-1290","source":"Crossref","is-referenced-by-count":51,"title":["Primary Retroperitoneal Myxoid Liposarcomas"],"prefix":"10.1097","volume":"40","author":[{"given":"Nokitaka","family":"Setsu","sequence":"first","affiliation":[{"name":"Pathology and Clinical Laboratories"},{"name":"Musculoskeletal Oncology"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mototaka","family":"Miyake","sequence":"additional","affiliation":[{"name":"Diagnostic Radiology"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Susumu","family":"Wakai","sequence":"additional","affiliation":[{"name":"Pathology and Clinical Laboratories"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Fumihiko","family":"Nakatani","sequence":"additional","affiliation":[{"name":"Musculoskeletal Oncology"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Eisuke","family":"Kobayashi","sequence":"additional","affiliation":[{"name":"Musculoskeletal Oncology"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Hirokazu","family":"Chuman","sequence":"additional","affiliation":[{"name":"Musculoskeletal Oncology"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Nobuyoshi","family":"Hiraoka","sequence":"additional","affiliation":[{"name":"Pathology and Clinical Laboratories"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Akira","family":"Kawai","sequence":"additional","affiliation":[{"name":"Musculoskeletal Oncology"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Akihiko","family":"Yoshida","sequence":"additional","affiliation":[{"name":"Pathology and Clinical Laboratories"},{"name":"Rare Cancer Center, National Cancer Center Hospital, Tokyo, Japan"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"276","reference":[{"key":"R2-20230922","doi-asserted-by":"crossref","first-page":"278","DOI":"10.1002\/gcc.2870050403","article-title":"Rearrangement of the transcription factor gene CHOP in myxoid liposarcomas with t(12;16)(q13;p11)","volume":"5","author":"Aman","year":"1992","journal-title":"Genes Chromosomes Cancer"},{"key":"R3-20230922","doi-asserted-by":"crossref","first-page":"175","DOI":"10.1038\/ng0693-175","article-title":"Fusion of the dominant negative transcription regulator CHOP with a novel gene FUS by translocation t(12;16) in malignant liposarcoma","volume":"4","author":"Rabbitts","year":"1993","journal-title":"Nat Genet"},{"key":"R4-20230922","first-page":"489","article-title":"Fusion of the EWS and CHOP genes in myxoid liposarcoma","volume":"12","author":"Panagopoulos","year":"1996","journal-title":"Oncogene"},{"key":"R5-20230922","doi-asserted-by":"crossref","first-page":"367","DOI":"10.1007\/BF00957030","article-title":"Liposarcoma. A study of 103 cases","volume":"335","author":"Enzinger","year":"1962","journal-title":"Virchows Arch Pathol Anat Physiol Klin Med"},{"key":"R6-20230922","doi-asserted-by":"crossref","first-page":"358","DOI":"10.1097\/01.sla.0000086542.11899.38","article-title":"Histologic subtype and margin of resection predict pattern of recurrence and survival for retroperitoneal liposarcoma","volume":"238","author":"Singer","year":"2003","journal-title":"Ann Surg"},{"key":"R8-20230922","doi-asserted-by":"crossref","first-page":"223","DOI":"10.1038\/modpathol.2008.164","article-title":"Primary retroperitoneal myxoid\/round cell liposarcoma is a nonexisting disease: an immunohistochemical and molecular biological analysis","volume":"22","author":"de Vreeze","year":"2009","journal-title":"Mod Pathol"},{"key":"R9-20230922","doi-asserted-by":"crossref","first-page":"1120","DOI":"10.1002\/1097-0142(19950301)75:5<1120::AID-CNCR2820750511>3.0.CO;2-7","article-title":"Frequent incidence of extrapulmonary sites of initial metastasis in patients with liposarcoma","volume":"75","author":"Cheng","year":"1995","journal-title":"Cancer"},{"key":"R10-20230922","doi-asserted-by":"crossref","first-page":"85","DOI":"10.1002\/(SICI)1097-0142(19990101)85:1<85::AID-CNCR12>3.0.CO;2-A","article-title":"Patterns of recurrence in extremity liposarcoma: implications for staging and follow-up","volume":"85","author":"Pearlstone","year":"1999","journal-title":"Cancer"},{"key":"R11-20230922","doi-asserted-by":"crossref","first-page":"1815","DOI":"10.1002\/cncr.22992","article-title":"Spinal metastases from myxoid liposarcoma warrant screening with magnetic resonance imaging","volume":"110","author":"Schwab","year":"2007","journal-title":"Cancer"},{"key":"R12-20230922","doi-asserted-by":"crossref","first-page":"251","DOI":"10.1007\/s00256-007-0424-1","article-title":"Metastatic myxoid liposarcomas: imaging and histopathologic findings","volume":"37","author":"Sheah","year":"2008","journal-title":"Skeletal Radiol"},{"key":"R13-20230922","doi-asserted-by":"crossref","first-page":"287","DOI":"10.1111\/j.1365-2559.2012.04348.x","article-title":"Well-differentiated and dedifferentiated liposarcomas with prominent myxoid stroma: analysis of 56 cases","volume":"62","author":"Sioletic","year":"2013","journal-title":"Histopathology"},{"key":"R14-20230922","doi-asserted-by":"crossref","first-page":"531","DOI":"10.1002\/(SICI)1096-9896(200004)190:5<531::AID-PATH579>3.0.CO;2-W","article-title":"Coordinated expression and amplification of the MDM2, CDK4, and HMGI-C genes in atypical lipomatous tumours","volume":"190","author":"Dei Tos","year":"2000","journal-title":"J Pathol"},{"key":"R15-20230922","doi-asserted-by":"crossref","first-page":"1476","DOI":"10.1097\/PAS.0b013e3180581fff","article-title":"Detection of MDM2-CDK4 amplification by fluorescence in situ hybridization in 200 paraffin-embedded tumor samples: utility in diagnosing adipocytic lesions and comparison with immunohistochemistry and real-time PCR","volume":"31","author":"Sirvent","year":"2007","journal-title":"Am J Surg Pathol"},{"key":"R16-20230922","first-page":"3977","article-title":"Prognostic impact of P53 status, TLS-CHOP fusion transcript structure, and histological grade in myxoid liposarcoma: a molecular and clinicopathologic study of 82 cases","volume":"7","author":"Antonescu","year":"2001","journal-title":"Clin Cancer Res"},{"key":"R17-20230922","doi-asserted-by":"crossref","first-page":"1450","DOI":"10.1002\/(SICI)1097-0142(19960415)77:8<1450::AID-CNCR5>3.0.CO;2-G","article-title":"The clinicopathologic spectrum of myxoid and round cell liposarcoma. A study of 95 cases","volume":"77","author":"Kilpatrick","year":"1996","journal-title":"Cancer"},{"key":"R18-20230922","doi-asserted-by":"crossref","first-page":"1868","DOI":"10.1002\/cncr.27847","article-title":"Localized and metastatic myxoid\/round cell liposarcoma: clinical and molecular observations","volume":"119","author":"Hoffman","year":"2013","journal-title":"Cancer"},{"key":"R19-20230922","doi-asserted-by":"crossref","first-page":"1081","DOI":"10.1245\/s10434-011-2127-z","article-title":"Myxoid\/round cell liposarcoma (MRCLS) revisited: an analysis of 418 primarily managed cases","volume":"19","author":"Moreau","year":"2012","journal-title":"Ann Surg Oncol"},{"key":"R20-20230922","doi-asserted-by":"crossref","first-page":"36785","DOI":"10.1155\/2007\/36785","article-title":"FDG-PET lacks sufficient sensitivity to detect myxoid liposarcoma spinal metastases detected by MRI","volume":"2007","author":"Schwab","year":"2007","journal-title":"Sarcoma"},{"key":"R21-20230922","doi-asserted-by":"crossref","first-page":"522","DOI":"10.1016\/j.ijrobp.2004.03.009","article-title":"Radiation response: an additional unique signature of myxoid liposarcoma","volume":"60","author":"Pitson","year":"2004","journal-title":"Int J Radiat Oncol Biol Phys"},{"key":"R22-20230922","doi-asserted-by":"crossref","first-page":"2853","DOI":"10.1016\/j.ejca.2005.07.023","article-title":"Differential sensitivity of liposarcoma subtypes to chemotherapy","volume":"41","author":"Jones","year":"2005","journal-title":"Eur J Cancer"},{"key":"R23-20230922","doi-asserted-by":"crossref","first-page":"5201","DOI":"10.1038\/onc.2013.462","article-title":"Mode of action of trabectedin in myxoid liposarcomas","volume":"33","author":"Di Giandomenico","year":"2014","journal-title":"Oncogene"},{"key":"R24-20230922","doi-asserted-by":"crossref","first-page":"595","DOI":"10.1016\/S1470-2045(07)70175-4","article-title":"Efficacy of trabectedin (ecteinascidin-743) in advanced pretreated myxoid liposarcomas: a retrospective study","volume":"8","author":"Grosso","year":"2007","journal-title":"Lancet Oncol"},{"key":"R25-20230922","doi-asserted-by":"crossref","first-page":"771","DOI":"10.1093\/annonc\/mdr265","article-title":"Phase II clinical trial of neoadjuvant trabectedin in patients with advanced localized myxoid liposarcoma","volume":"23","author":"Gronchi","year":"2012","journal-title":"Ann Oncol"},{"key":"R26-20230922","doi-asserted-by":"crossref","first-page":"876","DOI":"10.1016\/j.otsr.2010.05.010","article-title":"Liposarcoma of the extremities: MR imaging features and their correlation with pathologic data","volume":"96","author":"El Ouni","year":"2010","journal-title":"Orthop Traumatol Surg Res"},{"key":"R27-20230922","doi-asserted-by":"crossref","first-page":"1371","DOI":"10.1148\/rg.255055106","article-title":"From the archives of the AFIP: imaging of musculoskeletal liposarcoma with radiologic-pathologic correlation","volume":"25","author":"Murphey","year":"2005","journal-title":"Radiographics"},{"key":"R28-20230922","doi-asserted-by":"crossref","first-page":"1340","DOI":"10.1097\/01.pas.0000170343.09562.39","article-title":"MDM2 and CDK4 immunostainings are useful adjuncts in diagnosing well-differentiated and dedifferentiated liposarcoma subtypes: a comparative analysis of 559 soft tissue neoplasms with genetic data","volume":"29","author":"Binh","year":"2005","journal-title":"Am J Surg Pathol"},{"key":"R29-20230922","doi-asserted-by":"crossref","first-page":"645","DOI":"10.1097\/PAS.0b013e3181963c9c","article-title":"Liposarcomas in young patients: a study of 82 cases occurring in patients younger than 22 years of age","volume":"33","author":"Alaggio","year":"2009","journal-title":"Am J Surg Pathol"}],"container-title":["American Journal of Surgical Pathology"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/journals.lww.com\/00000478-201609000-00014","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2023,9,22]],"date-time":"2023-09-22T22:23:58Z","timestamp":1695421438000},"score":1,"resource":{"primary":{"URL":"https:\/\/journals.lww.com\/00000478-201609000-00014"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2016,9]]},"references-count":27,"journal-issue":{"issue":"9","published-print":{"date-parts":[[2016]]}},"URL":"https:\/\/doi.org\/10.1097\/pas.0000000000000657","relation":{},"ISSN":["0147-5185"],"issn-type":[{"value":"0147-5185","type":"print"}],"subject":[],"published":{"date-parts":[[2016,9]]}}}