{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,11,7]],"date-time":"2025-11-07T09:18:08Z","timestamp":1762507088929,"version":"3.37.3"},"reference-count":18,"publisher":"Wiley","issue":"9","license":[{"start":{"date-parts":[[2017,6,23]],"date-time":"2017-06-23T00:00:00Z","timestamp":1498176000000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["J Cutan Pathol"],"published-print":{"date-parts":[[2017,9]]},"abstract":"<jats:p>Idiopathic lymphoplasmacellular mucositis (<jats:styled-content style=\"fixed-case\">ILPM<\/jats:styled-content>) is a group of disorders histologically characterized by dense infiltrates of lymphocytes and plasma cells in submucosa. These lesions were initially observed on the glans penis and vulva, and later on buccal mucosa, lips, gingiva, tongue, epiglottis, larynx and other mucosal surfaces have also been reported. We have reviewed the previously reported cases of <jats:styled-content style=\"fixed-case\">ILPM<\/jats:styled-content> with lip involvement, outlining the clinical presentation, treatment and outcome of the entity to date. The etiology of <jats:styled-content style=\"fixed-case\">ILPM<\/jats:styled-content> is unknown, and the diagnosis is largely one of exclusion. To date, no consensus or consistently effective treatment for <jats:styled-content style=\"fixed-case\">ILPM<\/jats:styled-content> is available. Herein, we report an 18\u2010year\u2010old woman presented with markedly swollen lips with severe erosions, bleeding and yellow to black crusts who was diagnosed to have <jats:styled-content style=\"fixed-case\">ILPM<\/jats:styled-content> by histopathological study. The case occurred on rare lip site with an unusual appearance. Various treatment modalities were tried, but the responses were unsatisfactory and the lesion only responded to long\u2010term administration of oral steroids.<\/jats:p>","DOI":"10.1111\/cup.12967","type":"journal-article","created":{"date-parts":[[2017,5,24]],"date-time":"2017-05-24T00:39:37Z","timestamp":1495586377000},"page":"776-780","source":"Crossref","is-referenced-by-count":4,"title":["Idiopathic lymphoplasmacellular mucositis of the lips: A case report and review of the literature"],"prefix":"10.1111","volume":"44","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-4275-229X","authenticated-orcid":false,"given":"Ren\u2010Feng","family":"Liu","sequence":"first","affiliation":[{"name":"Department of Dermatology Drug Hypersensitivity Clinical and Research Center, Chang Gung Memorial Hospitals  Taipei, Linkou, and Keelung Taiwan"},{"name":"College of Medicine Chang Gung University  Taoyuan Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-7378-4235","authenticated-orcid":false,"given":"Chun\u2010Bing","family":"Chen","sequence":"additional","affiliation":[{"name":"Department of Dermatology Drug Hypersensitivity Clinical and Research Center, Chang Gung Memorial Hospitals  Taipei, Linkou, and Keelung Taiwan"},{"name":"College of Medicine Chang Gung University  Taoyuan Taiwan"},{"name":"Graduate Institute of Clinical Medical Sciences College of Medicine, Chang Gung University  Taoyuan Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Tseng\u2010tong","family":"Kuo","sequence":"additional","affiliation":[{"name":"Department of Pathology Chang Gung Memorial Hospital  Taipei Taiwan"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Wen\u2010Hung","family":"Chung","sequence":"additional","affiliation":[{"name":"Department of Dermatology Drug Hypersensitivity Clinical and Research Center, Chang Gung Memorial Hospitals  Taipei, Linkou, and Keelung Taiwan"},{"name":"College of Medicine Chang Gung University  Taoyuan 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