{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,23]],"date-time":"2026-09-23T16:16:02Z","timestamp":1790180162419,"version":"4.1.0"},"reference-count":14,"publisher":"Wiley","issue":"5","license":[{"start":{"date-parts":[[2019,9,19]],"date-time":"2019-09-19T00:00:00Z","timestamp":1568851200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"funder":[{"name":"SMA Trust and MDUK for the SMA REACH UK project"},{"name":"MRC Translational Research Centre to UCL and Newcastle","award":["MR\/K501074\/1"],"award-info":[{"award-number":["MR\/K501074\/1"]}]}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Develop Med Child Neuro"],"published-print":{"date-parts":[[2020,5]]},"abstract":"<jats:sec>\n                    <jats:title>Aim<\/jats:title>\n                    <jats:p>\n                      To report the differences between Performance of Upper Limb (\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      ) versions 1.2 and 2.0, compare the measurement ability of the two versions, and compare their longitudinal performance in Duchenne muscular dystrophy.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Method<\/jats:title>\n                    <jats:p>Rasch analysis was performed on the dual data from three centres to confirm whether the two scales measure the same construct. Change scores in natural history for the different domains were compared for the two versions.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>\n                      Rasch analysis demonstrated that both versions measure\u00a0the same construct and that the\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      2.0 was a better fit to the construct of motor performance and better able to detect change at 12\u00a0months in all levels of ability than the\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      1.2. This was also true when change scores were reviewed over 2\u00a0years.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Interpretation<\/jats:title>\n                    <jats:p>\n                      Our results confirm that the\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      1.2 and 2.0 versions detect change in all domains over 2\u00a0years. They also demonstrate that simplifying the original scoring of the\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      1.2 for the revised\n                      <jats:styled-content style=\"fixed-case\">PUL<\/jats:styled-content>\n                      2.0 maintains the validity of the construct and enhances the scale measurement qualities.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>What this paper adds<\/jats:title>\n                    <jats:p>\n                      <jats:list list-type=\"bullet\">\n                        <jats:list-item>\n                          <jats:p>The original and revised Performance of Upper Limb (PUL) scales measure the same construct.<\/jats:p>\n                        <\/jats:list-item>\n                        <jats:list-item>\n                          <jats:p>Both scales detected change in all domains over 2\u00a0years.<\/jats:p>\n                        <\/jats:list-item>\n                        <jats:list-item>\n                          <jats:p>The PUL 2.0 enhances the measurement qualities of the scale.<\/jats:p>\n                        <\/jats:list-item>\n                      <\/jats:list>\n                    <\/jats:p>\n                  <\/jats:sec>","DOI":"10.1111\/dmcn.14361","type":"journal-article","created":{"date-parts":[[2019,9,20]],"date-time":"2019-09-20T01:49:59Z","timestamp":1568944199000},"page":"633-639","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":75,"title":["Performance of Upper Limb module for Duchenne muscular dystrophy"],"prefix":"10.1111","volume":"62","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-7085-9011","authenticated-orcid":false,"given":"Anna G","family":"Mayhew","sequence":"first","affiliation":[{"name":"The John Walton Muscular Dystrophy Research Centre Institute of Genetic Medicine Newcastle University and Newcastle Hospitals NHS Foundation Trust Newcastle upon Tyne UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Giorgia","family":"Coratti","sequence":"additional","affiliation":[{"name":"Child Neurology Unit e Centro Nemo IRCCS Fondazione Policlinico Gemelli Universit\u00e0 Cattolica del Sacro Cuore Rome Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Elena Stacy","family":"Mazzone","sequence":"additional","affiliation":[{"name":"Child Neurology Unit e Centro Nemo IRCCS Fondazione Policlinico Gemelli Universit\u00e0 Cattolica del Sacro Cuore Rome Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0001-5853-9680","authenticated-orcid":false,"given":"Katrijn","family":"Klingels","sequence":"additional","affiliation":[{"name":"Department of Rehabilitation Sciences KU Leuven \u2013 University of Leuven Heverlee Belgium"},{"name":"Faculty of Rehabilitation Sciences REVAL Hasselt University Hasselt Belgium"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Meredith","family":"James","sequence":"additional","affiliation":[{"name":"The John Walton Muscular Dystrophy Research Centre Institute of Genetic Medicine Newcastle University and Newcastle Hospitals NHS Foundation Trust Newcastle upon Tyne UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Marika","family":"Pane","sequence":"additional","affiliation":[{"name":"Child Neurology Unit e Centro Nemo IRCCS Fondazione Policlinico Gemelli Universit\u00e0 Cattolica del Sacro Cuore Rome Italy"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Volker","family":"Straub","sequence":"additional","affiliation":[{"name":"The John Walton Muscular Dystrophy Research Centre Institute of Genetic Medicine Newcastle University and Newcastle Hospitals NHS Foundation Trust Newcastle upon Tyne 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