{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,6,13]],"date-time":"2026-06-13T15:45:20Z","timestamp":1781365520118,"version":"3.54.1"},"reference-count":78,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2026,1,11]],"date-time":"2026-01-11T00:00:00Z","timestamp":1768089600000},"content-version":"vor","delay-in-days":10,"URL":"http:\/\/creativecommons.org\/licenses\/by\/4.0\/"},{"start":{"date-parts":[[2026,1,1]],"date-time":"2026-01-01T00:00:00Z","timestamp":1767225600000},"content-version":"tdm","delay-in-days":0,"URL":"http:\/\/doi.wiley.com\/10.1002\/tdm_license_1.1"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Research Intellect Disabil"],"published-print":{"date-parts":[[2026,1]]},"abstract":"<jats:title>ABSTRACT<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Background<\/jats:title>\n                    <jats:p>Prader\u2010Willi syndrome is a complex neurogenetic condition. Recognised to affect the entire family, little is known of the sibling experience.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Objectives<\/jats:title>\n                    <jats:p>Review the experiences and support needs of siblings of people with Prader\u2010Willi syndrome.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Methods<\/jats:title>\n                    <jats:p>Eight databases, registers and grey literature were searched covering October 2000\u2013May 2024. Search terms were based on siblings and their experiences of a sibling who has Prader\u2010Willi syndrome. Quality appraisal deployed the Mixed Methods Appraisal Tool. Qualitative findings were assessed using thematic analysis. Quantitative results were summarised and integrated using narrative synthesis.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>Out of 7588 results, seven studies were selected. Quantitative reports primarily highlighted negative psychological effects, whilst qualitative reports concentrated on family relations. Narrative synthesis identified psychological impact, influence on family relationships, and the effect of familial characteristics.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions and Implications<\/jats:title>\n                    <jats:p>Sibling experiences are shaped by family context. The need for family\u2010centred approach in research and practise is advocated.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1111\/jar.70171","type":"journal-article","created":{"date-parts":[[2026,1,12]],"date-time":"2026-01-12T04:40:29Z","timestamp":1768192829000},"update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":1,"title":["Experiences and Support Needs of Siblings of Individuals With Prader\u2010Willi Syndrome: An Integrative Systematic Review"],"prefix":"10.1111","volume":"39","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-5799-4032","authenticated-orcid":false,"given":"Meghana Wadnerkar","family":"Kamble","sequence":"first","affiliation":[{"name":"School of Health Sciences, Faculty of Medicine and Health, University of East Anglia  Norwich UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jen","family":"Dawe","sequence":"additional","affiliation":[{"name":"School of Health Sciences, Faculty of Medicine and Health, University of East Anglia  Norwich UK"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-7396-9205","authenticated-orcid":false,"given":"Karen","family":"Bunning","sequence":"additional","affiliation":[{"name":"School of Health Sciences, Faculty of Medicine and Health, University of East Anglia  Norwich UK"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"311","published-online":{"date-parts":[[2026,1,11]]},"reference":[{"key":"e_1_2_12_2_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.socscimed.2010.11.032"},{"key":"e_1_2_12_3_1","doi-asserted-by":"publisher","DOI":"10.1007\/s40618\u2010015\u20100312\u20109"},{"key":"e_1_2_12_4_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.pedn.2007.08.013"},{"key":"e_1_2_12_5_1","doi-asserted-by":"publisher","DOI":"10.3109\/13668250.2022.2132630"},{"key":"e_1_2_12_6_1","volume-title":"Family Therapy in Clinical Practice","author":"Bowen M.","year":"1978"},{"key":"e_1_2_12_7_1","doi-asserted-by":"publisher","DOI":"10.1186\/s12905\u2010023\u201002798\u2010y"},{"key":"e_1_2_12_8_1","doi-asserted-by":"publisher","DOI":"10.4159\/9780674028845"},{"key":"e_1_2_12_9_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.cpr.2012.10.007"},{"key":"e_1_2_12_10_1","doi-asserted-by":"publisher","DOI":"10.3390\/medicina56100491"},{"key":"e_1_2_12_11_1","doi-asserted-by":"publisher","DOI":"10.1038\/gim.0b013e31822bead0"},{"key":"e_1_2_12_12_1","doi-asserted-by":"publisher","DOI":"10.1016\/j.ridd.2019.103496"},{"key":"e_1_2_12_13_1","doi-asserted-by":"publisher","DOI":"10.1111\/fare.13102"},{"key":"e_1_2_12_14_1","unstructured":"Child and Families Act.2014.\u201cChildren and Families Act 2014.\u201dAccessed January 5 2023.https:\/\/www.legislation.gov.uk\/ukpga\/2014\/6\/contents\/enacted."},{"key":"e_1_2_12_15_1","unstructured":"Cochrane Consumers and Communication.2022.\u201cConsumers and Communication Group Resources for Authors.\u201dAccessed November 3 2022.https:\/\/cccrg.cochrane.org\/author\u2010resources."},{"key":"e_1_2_12_16_1","doi-asserted-by":"publisher","DOI":"10.1111\/jppi.12094"},{"key":"e_1_2_12_17_1","doi-asserted-by":"publisher","DOI":"10.1177\/23333936241242929"},{"key":"e_1_2_12_18_1","doi-asserted-by":"publisher","DOI":"10.1352\/0895\u20108017(2003)108<>2.0.co;2"},{"key":"e_1_2_12_19_1","unstructured":"Down's Syndrome Association (DSA).2021.\u201cParents and Family Carers Well\u2010Being.\u201dAccessed June 17 2024.https:\/\/www.downs\u2010syndrome.org.uk\/about\u2010downs\u2010syndrome\/lifes\u2010journey\/parent\u2010and\u2010family\u2010carers\u2010well\u2010being\/."},{"key":"e_1_2_12_20_1","first-page":"1993","volume-title":"GeneReviews(R) [Internet] University of Washington","author":"Driscoll D. 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