{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,7,28]],"date-time":"2026-07-28T19:29:54Z","timestamp":1785266994930,"version":"3.55.0"},"reference-count":66,"publisher":"Wiley","issue":"12","license":[{"start":{"date-parts":[[2025,10,13]],"date-time":"2025-10-13T00:00:00Z","timestamp":1760313600000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["J intellect Disabil Res"],"published-print":{"date-parts":[[2025,12]]},"abstract":"<jats:title>ABSTRACT<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Background<\/jats:title>\n                    <jats:p>The Bayley Scales of Infant Development is used in many studies and clinical trials in children with developmental disabilities, including children with Angelman syndrome (AS).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Method<\/jats:title>\n                    <jats:p>We assessed 142 children with AS in an international multicentre study with the Bayley Scales of Infant Development III, of which 52 children were tested more than once. We assessed criterion validity using proportion analysis, scalability using Mokken analyses and stability of scoring by counting pass\u2010to\u2010fail and fail\u2010to\u2010pass items.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>Results revealed good scalability in all scales but the expressive language scale, indicating that the items of these scales measured one underlying trait. In the expressive language scale, the AS\u2010related speech difficulties invalidated scoring. Scoring within children across assessments was unstable for all scales except the gross motor scale, as more than half of the children made one or more errors in previously correct items. Loss or regression of skills does not fully explain this finding. Alternative explanations including motivation, concentration, on\u2010task behaviour and anxiety should also be considered when scores decline.<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions<\/jats:title>\n                    <jats:p>This study shows that caution should be taken when interpreting single and successive scores of children with AS on the Bayley\u2010III and that other forms of assessment should complement assessment in children with AS.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1111\/jir.70026","type":"journal-article","created":{"date-parts":[[2025,10,14]],"date-time":"2025-10-14T04:12:21Z","timestamp":1760415141000},"page":"1382-1393","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":2,"title":["Criterion Validity, Scalability and Stability of Scoring on the Bayley\u2010III in Children With Angelman Syndrome"],"prefix":"10.1111","volume":"69","author":[{"ORCID":"https:\/\/orcid.org\/0009-0009-0420-7838","authenticated-orcid":false,"given":"Maartje","family":"ten Hooven\u2010Radstaake","sequence":"first","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Faculty of Social Sciences Radboud University  Nijmegen the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Sabine","family":"Herrman\u2010Mous","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0938-0591","authenticated-orcid":false,"given":"Anjali","family":"Sadhwani","sequence":"additional","affiliation":[{"name":"Boston Children's Hospital  Boston Massachusetts USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-2693-5616","authenticated-orcid":false,"given":"Anne","family":"Wheeler","sequence":"additional","affiliation":[{"name":"RTI International  Research Triangle Park North Carolina USA"},{"name":"Carolina Institute for Developmental Disabilities University of North Carolina, Chapel Hill  Chapel Hill North Carolina USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Margaret","family":"DeRamus","sequence":"additional","affiliation":[{"name":"Carolina Institute for Developmental Disabilities University of North Carolina, Chapel Hill  Chapel Hill North Carolina USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Gwen","family":"Dieleman","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Cindy","family":"Navis","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of ENT (Speech and Language Pathology) Erasmus Medical Center  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jeroen","family":"Legerstee","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0002-3122-7713","authenticated-orcid":false,"given":"Leontine","family":"ten Hoopen","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Jan","family":"van der Ende","sequence":"additional","affiliation":[{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the Netherlands"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Casey","family":"Okoniewski","sequence":"additional","affiliation":[{"name":"RTI International  Research Triangle Park North Carolina USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Laura","family":"Hiruma","sequence":"additional","affiliation":[{"name":"Carolina Institute for Developmental Disabilities University of North Carolina, Chapel Hill  Chapel Hill North Carolina USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"name":"ENCORE group","sequence":"additional","affiliation":[],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Andr\u00e9","family":"Rietman","sequence":"additional","affiliation":[{"name":"Erasmus MC Center of Expertise for Neurodevelopmental Disorders (ENCORE)  Rotterdam the Netherlands"},{"name":"Department of Child and Adolescent Psychiatry\/Psychology Erasmus Medical Center Sophia Children's Hospital  Rotterdam the 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