{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,1,22]],"date-time":"2026-01-22T18:38:13Z","timestamp":1769107093546,"version":"3.49.0"},"reference-count":15,"publisher":"Wiley","issue":"12","license":[{"start":{"date-parts":[[2022,9,10]],"date-time":"2022-09-10T00:00:00Z","timestamp":1662768000000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"}],"content-domain":{"domain":["obgyn.onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["J of Obstet and Gynaecol"],"published-print":{"date-parts":[[2022,12]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>Kagami\u2010Ogata syndrome (KOS14) is a rare disease characterized by omphalocele, polyhydramnios and a bell\u2010shaped thorax. Although the coat\u2010hanger appearance of the ribs on postnatal X\u2010rays is a key diagnostic finding of KOS14, its prenatal diagnosis remains challenging. We encountered a case of KOS14 diagnosed prenatally that showed omphalocele, polyhydramnios, and a bell\u2010shaped narrow thorax. The coat\u2010hanger angle (CHA) measured at the sixth thoracic vertebrae and the ribs using three\u2010dimensional (3D) ultrasonography was 39\u00b0, reflecting the coat\u2010hanger appearance of the ribs. Segmental uniparental disomy chromosome 14 (UPD(14)pat) was confirmed by a methylation analysis and microsatellite analysis after birth. The median CHA (minimum, maximum) in 25 normal fetuses was 19 (9, 26) degrees, and a sonographic CHA of 30\u00b0 may be a border value for diagnosing KOS14. When the combination of omphalocele and polyhydramnios is found prenatally, 3D ultrasonography for CHA might aid in the differential diagnosis of KOS14.<\/jats:p>","DOI":"10.1111\/jog.15425","type":"journal-article","created":{"date-parts":[[2022,9,10]],"date-time":"2022-09-10T12:09:05Z","timestamp":1662811745000},"page":"3314-3318","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":2,"title":["Quantitative assessment of coat\u2010hanger ribs detected on three\u2010dimensional ultrasound for prenatal diagnosis of <scp>Kagami\u2010Ogata<\/scp> syndrome"],"prefix":"10.1111","volume":"48","author":[{"given":"Akane","family":"Kuriki","sequence":"first","affiliation":[{"name":"Division of Fetal Medicine, Center for Maternal\u2010Fetal, Neonatal and Reproductive Medicine National Center for Child Health and Development  Tokyo Japan"},{"name":"Department of Obstetrics and Gynecology Showa University School of Medicine  Tokyo 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