{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,9,15]],"date-time":"2026-09-15T12:34:13Z","timestamp":1789475653965,"version":"build-2803163510"},"reference-count":19,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2019,11,27]],"date-time":"2019-11-27T00:00:00Z","timestamp":1574812800000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Neuropathology"],"published-print":{"date-parts":[[2020,2]]},"abstract":"<jats:p>Linear scleroderma is a variant of localized scleroderma. We report a 43\u2010year\u2010old woman who had developed left arm weakness and linear scleroderma on her back during pregnancy at 25\u2009years of age, followed by left hemifacial atrophy and left leg weakness. She had multiple linear scleroderma lesions on her trunk and left limbs, left eyelid ptosis, impairment of vertical movement and abduction of the left eye, left hemifacial atrophy, and weakness and atrophy of the sternocleidomastoid, trapezius, and proximal limb muscles on the left side. On serology, antibodies to U1\u2010ribonucleoprotein and Jo\u20101 were positive; anti\u2010scleroderma\u201070 antibody was negative. Skin biopsy demonstrated increased hypertrophic collagen fibers without inflammatory infiltrates. Needle electromyography of left limb muscles revealed mild neurogenic patterns; left quadriceps muscle biopsy showed chronic neurogenic changes. Brain magnetic resonance imaging revealed mild left hemispheric atrophy. This is a rare case of linear scleroderma and Parry\u2013Romberg syndrome presenting with widespread ipsilateral neurogenic manifestations.<\/jats:p>","DOI":"10.1111\/neup.12614","type":"journal-article","created":{"date-parts":[[2019,11,28]],"date-time":"2019-11-28T00:25:27Z","timestamp":1574900727000},"page":"109-115","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":5,"title":["A case of overlapping adult\u2010onset linear scleroderma and Parry\u2010Romberg syndrome presenting with widespread ipsilateral neurogenic involvement"],"prefix":"10.1111","volume":"40","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-2071-7861","authenticated-orcid":false,"given":"Ryo","family":"Yamasaki","sequence":"first","affiliation":[{"name":"Department of Neurology, Neurological Institute, Graduate School of Medical Sciences Kyushu University  Higashi\u2010ku Fukuoka 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