{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,12,8]],"date-time":"2025-12-08T22:15:56Z","timestamp":1765232156454},"reference-count":37,"publisher":"Wiley","issue":"2","license":[{"start":{"date-parts":[[2014,3,24]],"date-time":"2014-03-24T00:00:00Z","timestamp":1395619200000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Pediatric Dermatology"],"published-print":{"date-parts":[[2015,3]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>Rhabdomyomatous mesenchymal hamartoma (<jats:styled-content style=\"fixed-case\">RMH<\/jats:styled-content>) is a rare, benign, congenital tumor of the dermis and subcutaneous tissue comprised of skeletal muscle and adipose and adnexal elements. Although the majority of cases are an incidental finding in otherwise healthy patients, some have been reported in association with other anomalies. We present a full\u2010term boy evaluated on day 2 of life for two lesions located on the midline of the lower back and right buttock that each appeared clinically as an atrophic, pink plaque. Ultrasound of the midline lesion revealed an underlying lipomyelomeningocele with a tethered cord in the spinal canal. Histopathology of the right buttock cutaneous lesion was consistent with a diagnosis of <jats:styled-content style=\"fixed-case\">RMH<\/jats:styled-content>. Surgical excision was performed on the midline intradural lipoma and the lesion on the buttock was monitored clinically. Repeat biopsy of this site at 1\u00a0year of age revealed complete spontaneous regression. This case highlights three interesting features: the association with an occult spinal dysraphism lipomyelomeningocele and tethered cord, the clinical presentation of an atrophic plaque as opposed to the more commonly reported raised lesions, and the phenomenon of spontaneous regression of the lesion. Most importantly, this final feature of regression in our patient suggests that, in the absence of symptoms, clinical observation of <jats:styled-content style=\"fixed-case\">RMH<\/jats:styled-content> lesions is warranted for spontaneous regression for 1 to 2\u00a0years provided that no functional deficit is noted and that the cutaneous or deeper lesions are not causing a medical problem.<\/jats:p>","DOI":"10.1111\/pde.12331","type":"journal-article","created":{"date-parts":[[2014,3,24]],"date-time":"2014-03-24T11:29:15Z","timestamp":1395660555000},"page":"256-262","source":"Crossref","is-referenced-by-count":25,"title":["Biopsy\u2010Proven Spontaneous Regression of a Rhabdomyomatous Mesenchymal Hamartoma"],"prefix":"10.1111","volume":"32","author":[{"given":"Joni M.","family":"Mazza","sequence":"first","affiliation":[{"name":"Department of Dermatology St. Luke's\u2010Roosevelt Center of the Icahn School of Medicine at Mount Sinai New York New York"},{"name":"Department of Dermatology 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