{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2024,5,18]],"date-time":"2024-05-18T05:10:04Z","timestamp":1716009004085},"reference-count":29,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2015,1,21]],"date-time":"2015-01-21T00:00:00Z","timestamp":1421798400000},"content-version":"vor","delay-in-days":20,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":[],"crossmark-restriction":false},"short-container-title":["Pediatric Dermatology"],"published-print":{"date-parts":[[2015,1]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:p>Capillary malformation (<jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content>) can be a \u201cred flag\u201d for several syndromic vascular anomalies. We identified a subset of patients with diffuse <jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> and fetal pleural effusion and documented the type of <jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content>, the etiology of the pleural effusion, the potential syndromic diagnosis, and outcome. Patients with a history of <jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> and fetal pleural effusion were identified by searching the database of patients evaluated at the Vascular Anomalies Center at Boston Children's Hospital. Standardized patient interviews and a retrospective review of records, photographs, and imaging studies were conducted. Five patients had diffuse <jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> and fetal pleural effusion. Two patients had macrocephaly\u2010<jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> (M\u2010<jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content>), one had features of M\u2010<jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> and <jats:styled-content style=\"fixed-case\">CLOVES<\/jats:styled-content> (congenital lipomatous overgrowth, vascular malformations, epidermal nevi, and spinal\/skeletal anomalies and\/or scoliosis), and one had diffuse <jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content> with overgrowth. The pleural fluid was chylous in four patients. One patient had thoracic lymphatic malformation. Recurrent effusion occurred in one patient coincident with pneumonia at age 11\u00a0years. Four patients had a history of reactive airway disease and episodic pulmonary infections. The diagnosis of vascular anomaly\u2013overgrowth syndromes, particularly M\u2010<jats:styled-content style=\"fixed-case\">CM<\/jats:styled-content>, should be considered in neonates with fetal pleural effusion.<\/jats:p>","DOI":"10.1111\/pde.12401","type":"journal-article","created":{"date-parts":[[2015,1,21]],"date-time":"2015-01-21T10:18:44Z","timestamp":1421835524000},"page":"70-75","source":"Crossref","is-referenced-by-count":7,"title":["Diffuse Capillary Malformation in Association with Fetal Pleural Effusion: Report of Five Patients"],"prefix":"10.1111","volume":"32","author":[{"given":"Jillian F.","family":"Rork","sequence":"first","affiliation":[{"name":"Division of Dermatology University of Massachusetts Medical School Worcester Massachusetts"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ahmad I.","family":"Alomari","sequence":"additional","affiliation":[{"name":"Division of Vascular and Interventional Radiology Boston Children's Hospital Boston 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