{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,5,6]],"date-time":"2026-05-06T08:08:07Z","timestamp":1778054887291,"version":"3.51.4"},"reference-count":31,"publisher":"Wiley","issue":"1","license":[{"start":{"date-parts":[[2021,8,3]],"date-time":"2021-08-03T00:00:00Z","timestamp":1627948800000},"content-version":"vor","delay-in-days":0,"URL":"http:\/\/onlinelibrary.wiley.com\/termsAndConditions#vor"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Special Care in Dentistry"],"published-print":{"date-parts":[[2022,1]]},"abstract":"<jats:title>Abstract<\/jats:title><jats:sec><jats:title>Objective<\/jats:title><jats:p>To identify factors associated with oral health care services for individuals with and without rare genetic diseases.<\/jats:p><\/jats:sec><jats:sec><jats:title>Materials and Method<\/jats:title><jats:p>A cross\u2010sectional study was undertaken, with 140 individuals paired by sex and age (70 with rare genetic diseases and 70 without), aged between 3 and 27 years, and their parents. The sample was selected from two reference hospitals for patients with rare genetic diseases in southeastern Brazil. The parents completed a questionnaire on individual aspects and their child's medical\/dental history. Participants who did and did not suffer from rare genetic diseases were examined for dental caries, malocclusion, dental anomalies, and oral hygiene. The theoretical model Directed Acyclic Graphs (DAG) was used to identify possible confounding variables in the association between rare diseases and access to dental care. Descriptive analyses and non\u2010matched and matched logistic regression models (<jats:italic>p<\/jats:italic>\u00a0&lt;\u00a00.05) were carried out.<\/jats:p><\/jats:sec><jats:sec><jats:title>Results<\/jats:title><jats:p>The chance of individuals without rare genetic disease having access to oral health care service was 5.32 times higher (95% CI 2.35\u201312.01) than those with such conditions. Individuals who had not suffered upper respiratory tract infections had a 3.16 times greater chance of being in the group with access to oral health care service (95% CI 1.45\u20136.90).<\/jats:p><\/jats:sec><jats:sec><jats:title>Conclusion<\/jats:title><jats:p>Individuals with no rare genetic diseases and no history of upper respiratory tract infections had a greater chance of belonging to the group of individuals with access to a dental service. Individuals with rare genetic diseases have less access to oral health care.<\/jats:p><\/jats:sec>","DOI":"10.1111\/scd.12639","type":"journal-article","created":{"date-parts":[[2021,8,3]],"date-time":"2021-08-03T17:30:57Z","timestamp":1628011857000},"page":"32-40","update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":20,"title":["Access to oral health care services for individuals with rare genetic diseases affecting skeletal development"],"prefix":"10.1111","volume":"42","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-1529-9311","authenticated-orcid":false,"given":"Su\u00e9len Alves Teixeira","family":"Debossan","sequence":"first","affiliation":[{"name":"Department of Dental Public Health, Faculty of Dentistry Federal University of Minas Gerais  Belo Horizonte Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Tahyn\u00e1 Duda","family":"Deps","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry, Faculty of Dentistry Federal University of Minas Gerais  Belo Horizonte Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Heloisa Vieira","family":"Prado","sequence":"additional","affiliation":[{"name":"Department of Dental Public Health, Faculty of Dentistry Federal University of Minas Gerais  Belo Horizonte Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mauro Henrique Nogueira Guimar\u00e3es","family":"de Abreu","sequence":"additional","affiliation":[{"name":"Department of Dental Public Health, Faculty of Dentistry Federal University of Minas Gerais  Belo Horizonte Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ana Cristina","family":"Borges\u2010Oliveira","sequence":"additional","affiliation":[{"name":"Department of Dental Public Health, Faculty of Dentistry Federal University of Minas Gerais  Belo Horizonte Brazil"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2021,8,3]]},"reference":[{"key":"e_1_2_10_2_1","doi-asserted-by":"publisher","DOI":"10.1177\/0022034514529150"},{"key":"e_1_2_10_3_1","first-page":"23","article-title":"Oral health and oromotor function in rare diseases \u2013 a database study","volume":"39","author":"Sj\u00f6green L","year":"2015","journal-title":"Swed Dent J"},{"issue":"5","key":"e_1_2_10_4_1","first-page":"e587","article-title":"Impact of rare diseases in oral health","volume":"21","author":"Molina\u2010Garcia A","year":"2016","journal-title":"Med Oral Patol Oral Cir Bucal"},{"key":"e_1_2_10_5_1","doi-asserted-by":"publisher","DOI":"10.1007\/s00198-018-4690-7"},{"key":"e_1_2_10_6_1","volume-title":"Basic Methods","author":"World Health Organization (WHO). 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