{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,3,9]],"date-time":"2026-03-09T09:22:13Z","timestamp":1773048133266,"version":"3.50.1"},"reference-count":33,"publisher":"Wiley","issue":"3","license":[{"start":{"date-parts":[[2025,6,3]],"date-time":"2025-06-03T00:00:00Z","timestamp":1748908800000},"content-version":"vor","delay-in-days":33,"URL":"http:\/\/creativecommons.org\/licenses\/by-nc-nd\/4.0\/"},{"start":{"date-parts":[[2025,5,1]],"date-time":"2025-05-01T00:00:00Z","timestamp":1746057600000},"content-version":"tdm","delay-in-days":0,"URL":"http:\/\/doi.wiley.com\/10.1002\/tdm_license_1.1"}],"content-domain":{"domain":["onlinelibrary.wiley.com"],"crossmark-restriction":true},"short-container-title":["Special Care in Dentistry"],"published-print":{"date-parts":[[2025,5]]},"abstract":"<jats:title>ABSTRACT<\/jats:title>\n                  <jats:sec>\n                    <jats:title>Aim<\/jats:title>\n                    <jats:p>To identify the behavioral correlates of caregiver\u2010reported oral health of individuals with Joubert Syndrome (JS).<\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Methods<\/jats:title>\n                    <jats:p>\n                      This cross\u2010sectional study included 302 caregivers of individuals with JS from the JS registry who responded to a 56\u2010item REDCap survey, and a purposive subset of 30 participants with JS for which a dental screening was completed. The primary outcome was caregiver\u2010reported oral health of individuals with JS (good\/very good vs. fair\/poor). Logistic regression models were used to generate confounder\u2010adjusted odds ratios (OR) and evaluate associations between oral health behaviors and caregiver\u2010reported oral health of individuals with JS (\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0&lt;\u00a00.05).\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Results<\/jats:title>\n                    <jats:p>\n                      The mean age of individuals with JS was 14.6\u00a0years (SD: 10.3). Most caregivers were female (84.1%), White (87.4%), non\u2010Hispanic (91.1%), and reported annual household incomes above $100\u00a0000 (53.7%). Behaviors significantly associated with poorer oral health included not eating or drinking by mouth (OR\u00a0=\u00a04.52,\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0=\u00a00.005), not toothbrushing daily (OR\u00a0=\u00a05.29,\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0&lt;\u00a00.001), and infrequent toothpaste use (OR\u00a0=\u00a03.68,\n                      <jats:italic>p<\/jats:italic>\n                      \u00a0=\u00a00.003). Screenings showed 40.0% had poor hygiene, 23.3% had untreated caries, and 46.7% had gingivitis.\n                    <\/jats:p>\n                  <\/jats:sec>\n                  <jats:sec>\n                    <jats:title>Conclusions<\/jats:title>\n                    <jats:p>Future efforts should focus on improving oral health behaviors to prevent dental disease in individuals with JS.<\/jats:p>\n                  <\/jats:sec>","DOI":"10.1111\/scd.70050","type":"journal-article","created":{"date-parts":[[2025,6,4]],"date-time":"2025-06-04T00:14:15Z","timestamp":1748996055000},"update-policy":"https:\/\/doi.org\/10.1002\/crossmark_policy","source":"Crossref","is-referenced-by-count":1,"title":["Behavioral Correlates of Caregiver\u2010Reported Oral Health of Individuals With Joubert Syndrome: A Cross\u2010Sectional Observational Study"],"prefix":"10.1111","volume":"45","author":[{"given":"Sai Win Kyaw Htet","family":"Aung","sequence":"first","affiliation":[{"name":"Department of Oral Health Sciences University of Washington School of Dentistry  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Joshua","family":"Orack","sequence":"additional","affiliation":[{"name":"Department of Oral Health Sciences University of Washington School of Dentistry  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Dan","family":"Doherty","sequence":"additional","affiliation":[{"name":"Divisions of Genetics and Developmental Medicine Department of Pediatrics University of Washington School of Medicine  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Travis","family":"Nelson","sequence":"additional","affiliation":[{"name":"Department of Pediatric Dentistry University of Washington  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Jennifer C.","family":"Dempsey","sequence":"additional","affiliation":[{"name":"Department of Pediatrics Division of Genetic Medicine University of Washington  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Sophie R.","family":"Li","sequence":"additional","affiliation":[{"name":"Department of Oral Health Sciences University of Washington School of Dentistry  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-2289-7747","authenticated-orcid":false,"given":"Donald L.","family":"Chi","sequence":"additional","affiliation":[{"name":"Department of Oral Health Sciences University of Washington School of Dentistry  Seattle Washington USA"},{"name":"Department of Health Systems and Population Health University of Washington School of Public Health  Seattle Washington USA"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"311","published-online":{"date-parts":[[2025,6,3]]},"reference":[{"key":"e_1_2_10_2_1","doi-asserted-by":"publisher","DOI":"10.1177\/088307389901400902"},{"key":"e_1_2_10_3_1","doi-asserted-by":"publisher","DOI":"10.1055\/s\u20100028\u20101091505"},{"key":"e_1_2_10_4_1","doi-asserted-by":"publisher","DOI":"10.1038\/sj.ejhg.5201648"},{"key":"e_1_2_10_5_1","doi-asserted-by":"publisher","DOI":"10.1136\/jmedgenet\u20102015\u2010103087"},{"key":"e_1_2_10_6_1","doi-asserted-by":"publisher","DOI":"10.1212\/WNL.0000000000008996"},{"key":"e_1_2_10_7_1","doi-asserted-by":"publisher","DOI":"10.1186\/1750\u20101172\u20107\u20104"},{"key":"e_1_2_10_8_1","doi-asserted-by":"publisher","DOI":"10.22037\/ijcn.v16i2.28713"},{"key":"e_1_2_10_9_1","doi-asserted-by":"publisher","DOI":"10.5005\/jp\u2010journals\u201010005\u20101394"},{"key":"e_1_2_10_10_1","doi-asserted-by":"publisher","DOI":"10.1111\/scd.12572"},{"key":"e_1_2_10_11_1","doi-asserted-by":"publisher","DOI":"10.1055\/s\u20100042\u20101759516"},{"key":"e_1_2_10_12_1","doi-asserted-by":"publisher","DOI":"10.1186\/1750\u20101172\u20105\u201020"},{"key":"e_1_2_10_13_1","unstructured":"Oral Health in Children with Neurological Disorders accessed August 26 2024 https:\/\/www.jaypeedigital.com\/abstractArticleContentBrowse\/JPMER\/26853\/JPJ\/fullText."},{"key":"e_1_2_10_14_1","doi-asserted-by":"publisher","DOI":"10.1111\/j.1754\u20104505.2010.00136.x"},{"key":"e_1_2_10_15_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.a.37938"},{"key":"e_1_2_10_16_1","doi-asserted-by":"publisher","DOI":"10.1177\/088307389901400907"},{"key":"e_1_2_10_17_1","doi-asserted-by":"publisher","DOI":"10.1002\/ajmg.a.38272"},{"key":"e_1_2_10_18_1","unstructured":"H. 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