{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,4,28]],"date-time":"2025-04-28T04:02:20Z","timestamp":1745812940747,"version":"3.40.4"},"reference-count":11,"publisher":"BMJ","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Reports"],"accepted":{"date-parts":[[2014,11,2]]},"abstract":"<jats:p>Macrodystrophia lipomatosa (MDL), a rare non-hereditary congenital disorder of localised gigantism, is characterised by progressive proliferation of all mesenchymal elements, with a disproportionate increase in fibroadipose tissue. We report a case of a 19-year-old man who presented with a history of painless enlargement of the left upper limb since childhood, which was gradually increasing in size and predominantly involving the radial aspect of the upper limb with relative sparing of the ulnar aspect. The patient was imaged with X-ray and MRI. Imaging and clinical features were classical of MDL. The patient underwent stage 1 reduction plasty of the left forearm; preoperative and histopathological findings confirmed the preoperative diagnosis.<\/jats:p>","DOI":"10.1136\/bcr-2014-204899","type":"journal-article","created":{"date-parts":[[2014,11,18]],"date-time":"2014-11-18T13:59:04Z","timestamp":1416319144000},"page":"bcr2014204899","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":2,"title":["Imaging features of macrodystrophia lipomatosa: an unusual cause of a brawny arm"],"prefix":"10.1136","volume":"2014","author":[{"given":"Jagadeesan","family":"Dhanasekaran","sequence":"first","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ajit Kumar","family":"Reddy","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Radha","family":"Sarawagi","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Prakash Manikka","family":"Lakshmanan","sequence":"additional","affiliation":[],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2014,11,18]]},"reference":[{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.1","doi-asserted-by":"publisher","DOI":"10.14260\/jemds\/973"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.2","first-page":"2744","article-title":"Limb salvage surgery in a patient with macrodystrophia lipomatosa involving an entire upper extremity","volume":"123","author":"Gao","year":"2010","journal-title":"Chin Med J (Engl)"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.3","first-page":"47","article-title":"MR imaging of macrodystrophia lipomatosa","volume":"74","author":"Turkington","year":"2005","journal-title":"Ulster Med J"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.4","doi-asserted-by":"publisher","DOI":"10.1259\/0007-1285-65-777-769"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.5","doi-asserted-by":"publisher","DOI":"10.1080\/j.1600-0455.2003.00056.x"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.6","doi-asserted-by":"publisher","DOI":"10.1186\/1824-7288-36-69"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.7","doi-asserted-by":"publisher","DOI":"10.2214\/ajr.128.1.101"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.8","doi-asserted-by":"publisher","DOI":"10.1016\/S0363-5023(82)80104-4"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.9","first-page":"41","article-title":"Macrodystrophia lipomatosa a letter to the editor","volume":"13","author":"Hafeez","year":"2006","journal-title":"JK Pract"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.10","doi-asserted-by":"publisher","DOI":"10.1080\/00207450601050071"},{"key":"2025042706571567000_2014.nov18_2.bcr2014204899.11","doi-asserted-by":"publisher","DOI":"10.1007\/s003830050728"}],"container-title":["BMJ Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/syndication.highwire.org\/content\/doi\/10.1136\/bcr-2014-204899","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2025,4,27]],"date-time":"2025-04-27T13:57:22Z","timestamp":1745762242000},"score":1,"resource":{"primary":{"URL":"https:\/\/casereports.bmj.com\/lookup\/doi\/10.1136\/bcr-2014-204899"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2014,11,18]]},"references-count":11,"alternative-id":["10.1136\/bcr-2014-204899"],"URL":"https:\/\/doi.org\/10.1136\/bcr-2014-204899","relation":{},"ISSN":["1757-790X"],"issn-type":[{"type":"electronic","value":"1757-790X"}],"subject":[],"published":{"date-parts":[[2014,11,18]]}}}