{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,8,28]],"date-time":"2025-08-28T12:16:54Z","timestamp":1756383414202,"version":"3.44.0"},"reference-count":15,"publisher":"BMJ","issue":"2","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2018,10,28]]},"published-print":{"date-parts":[[2019,2]]},"abstract":"<jats:p>A 30-year-old ex-smoker with a background history of childhood asthma presented with worsening shortness of breath despite receiving high doses of oral corticosteroid for pemphigus vulgaris which was diagnosed 5\u2009years earlier. A high-resolution CT examination of the thorax reported non-specific bronchiectatic changes and revealed an incidental suprarenal mass. A subsequent CT scan confirmed a large adrenal mass with areas of necrosis and calcification. Serum renin and aldosterone, urinary catecholamine and 5-hydroxyindoleacetic acid were within normal limits. Surgical intervention was delayed due to difficulty in optimising preoperative respiratory functions. He finally underwent a midline laparotomy for removal of the tumour. Histopathological examinations revealed extrapulmonary inflammatory myofibroblastic tumour arising from the periadrenal soft-tissue, with presence of normal adrenal gland. He showed immediate improvements of his asthmatic symptoms and pemphigus vulgaris following the surgery. His oral steroid was rapidly reduced and he achieved complete remission 2\u2009months later.<\/jats:p>","DOI":"10.1136\/bcr-2018-225687","type":"journal-article","created":{"date-parts":[[2019,2,1]],"date-time":"2019-02-01T13:56:41Z","timestamp":1549029401000},"page":"e225687","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":0,"title":["Periadrenal inflammatory myofibroblastic tumour: half a decade before cure"],"prefix":"10.1136","volume":"12","author":[{"given":"Rohana","family":"Abdul Ghani","sequence":"first","affiliation":[{"name":"Endocrine Unit, Department of Medicine, Universiti Teknologi MARA Sungai Buloh Campus, Selangor, Malaysia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Fatimah Zaherah","family":"Mohamed Shah","sequence":"additional","affiliation":[{"name":"Endocrine Unit, Department of Medicine, Universiti Teknologi MARA Sungai Buloh Campus, Selangor, Malaysia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mohammad","family":"Hanafiah","sequence":"additional","affiliation":[{"name":"Medical Imaging Unit, Faculty of Medicine, Universiti Teknologi MARA, Sungai Buloh, Malaysia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Mardiana","family":"Abdul Aziz","sequence":"additional","affiliation":[{"name":"Anatomic Pathology Unit, Department of Pathology, Faculty of Medicine, Universiti Teknologi MARA, Sungai Buloh, Malaysia"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2019,2,1]]},"reference":[{"key":"2025082804305187000_12.2.e225687.1","first-page":"1524","article-title":"Rare case of inflammatory myofibroblastic tumor of the adrenal mimicking adrenocortical carcinoma","volume":"2","author":"Johri","year":"2017","journal-title":"Clin Surg"},{"key":"2025082804305187000_12.2.e225687.2","doi-asserted-by":"publisher","DOI":"10.1097\/00000478-199508000-00001"},{"key":"2025082804305187000_12.2.e225687.3","doi-asserted-by":"crossref","first-page":"55","DOI":"10.1016\/S0096-5588(20)30758-3","article-title":"Postinflammatory tumors of the lung; report of four cases simulating xanthoma, fibroma, or plasma cell tumor","volume":"28","author":"Umiker","year":"1954","journal-title":"J Thorac Surg"},{"key":"2025082804305187000_12.2.e225687.4","doi-asserted-by":"publisher","DOI":"10.1136\/bcr-2013-010122"},{"key":"2025082804305187000_12.2.e225687.5","doi-asserted-by":"crossref","first-page":"33","DOI":"10.1016\/j.anndiagpath.2016.04.011","article-title":"An isolated inflammatory myofibroblastic tumor of adrenal gland","volume":"25","author":"Al Sannaa","year":"2016","journal-title":"Ann Diagn Pathol"},{"key":"2025082804305187000_12.2.e225687.6","doi-asserted-by":"crossref","first-page":"1535","DOI":"10.3892\/ol.2016.4767","article-title":"Recurrent retroperitoneal inflammatory myofibroblastic tumor: a case report","volume":"12","author":"Wang","year":"2016","journal-title":"Oncol Lett"},{"key":"2025082804305187000_12.2.e225687.7","doi-asserted-by":"publisher","DOI":"10.1136\/jcp.2007.049387"},{"key":"2025082804305187000_12.2.e225687.8","doi-asserted-by":"crossref","first-page":"410","DOI":"10.1016\/j.diii.2012.02.002","article-title":"Abdominal inflammatory myofibroblastic tumour","volume":"93","author":"Aptel","year":"2012","journal-title":"Diagn Interv Imaging"},{"key":"2025082804305187000_12.2.e225687.9","doi-asserted-by":"crossref","first-page":"274","DOI":"10.4103\/0976-237X.91787","article-title":"Inflammatory myofibroblastic tumor","volume":"2","author":"Palaskar","year":"2011","journal-title":"Contemp Clin Dent"},{"key":"2025082804305187000_12.2.e225687.10","doi-asserted-by":"crossref","first-page":"1552","DOI":"10.1097\/SCS.0b013e318188a2e9","article-title":"Inflammatory pseudotumor in the mandible","volume":"19","author":"Oh","year":"2008","journal-title":"J Craniofac Surg"},{"key":"2025082804305187000_12.2.e225687.11","doi-asserted-by":"crossref","first-page":"1672","DOI":"10.3892\/ol.2013.1260","article-title":"Complete remission of ALK-negative plasma cell granuloma (inflammatory myofibroblastic tumor) of the lung induced by celecoxib: a case report and review of the literature","volume":"5","author":"Chavez","year":"2013","journal-title":"Oncol Lett"},{"key":"2025082804305187000_12.2.e225687.12","doi-asserted-by":"publisher","DOI":"10.1002\/jso.20516"},{"key":"2025082804305187000_12.2.e225687.13","doi-asserted-by":"publisher","DOI":"10.1007\/s00408-011-9314-3"},{"key":"2025082804305187000_12.2.e225687.14","doi-asserted-by":"crossref","first-page":"77","DOI":"10.1016\/j.clineuro.2011.07.026","article-title":"The successful long-term management of an intracranial inflammatory myofibroblastic tumor with corticosteroids","volume":"114","author":"Carswell","year":"2012","journal-title":"Clin Neurol Neurosurg"},{"key":"2025082804305187000_12.2.e225687.15","first-page":"1121","article-title":"Improvement of inflammatory pseudotumor of the liver after nonsteroidal anti-inflammatory agent therapy","volume":"88","author":"Hakozaki","year":"1993","journal-title":"Am J Gastroenterol"}],"container-title":["BMJ Case Reports"],"original-title":[],"language":"en","link":[{"URL":"https:\/\/syndication.highwire.org\/content\/doi\/10.1136\/bcr-2018-225687","content-type":"unspecified","content-version":"vor","intended-application":"similarity-checking"}],"deposited":{"date-parts":[[2025,8,28]],"date-time":"2025-08-28T11:30:58Z","timestamp":1756380658000},"score":1,"resource":{"primary":{"URL":"https:\/\/casereports.bmj.com\/lookup\/doi\/10.1136\/bcr-2018-225687"}},"subtitle":[],"short-title":[],"issued":{"date-parts":[[2019,2]]},"references-count":15,"journal-issue":{"issue":"2","published-online":{"date-parts":[[2019,2,1]]},"published-print":{"date-parts":[[2019,2]]}},"alternative-id":["10.1136\/bcr-2018-225687"],"URL":"https:\/\/doi.org\/10.1136\/bcr-2018-225687","relation":{},"ISSN":["1757-790X"],"issn-type":[{"type":"electronic","value":"1757-790X"}],"subject":[],"published":{"date-parts":[[2019,2]]}}}