{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2025,11,11]],"date-time":"2025-11-11T15:46:51Z","timestamp":1762876011548,"version":"3.44.0"},"reference-count":16,"publisher":"BMJ","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Reports"],"accepted":{"date-parts":[[2018,8,29]]},"abstract":"<jats:p>Status dystonicus, also known as the dystonic storm or dystonic crisis, is rare but may prove fatal due to respiratory and bulbar complications. In adults, the condition is rare and possibly under-reported. The lack of awareness of this condition among emergency and acute physicians may lead to an incorrect or delayed diagnosis, which should be avoided. We report a case of a 23-year-old man with athetoid cerebral palsy who presented to a district general hospital with uncontrolled dystonic movements, which were diagnosed as status dystonicus. This was successfully treated with intravenous clonidine, with full recovery returning to baseline functional state.<\/jats:p>","DOI":"10.1136\/bcr-2018-226531","type":"journal-article","created":{"date-parts":[[2018,9,12]],"date-time":"2018-09-12T10:55:21Z","timestamp":1536749721000},"page":"bcr-2018-226531","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":3,"title":["Status dystonicus: a diagnosis delayed"],"prefix":"10.1136","volume":"2018","author":[{"ORCID":"https:\/\/orcid.org\/0000-0001-9932-0941","authenticated-orcid":false,"given":"Muhammad Fahad","family":"Arshad","sequence":"first","affiliation":[{"name":"Diabetes and Endocrine Department, Doncaster Royal Infirmary, Doncaster, UK"},{"name":"Diabetes and Endocrine Department, Sheffield Teaching Hospitals NHS Foundation Trust, Sheffield, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ehtasham","family":"Ahmad","sequence":"additional","affiliation":[{"name":"Diabetes and Endocrine Department, Queen Elizabeth the Queen Mother Hospital, Margate, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Aiyappa Nanjappa","family":"Biddanda","sequence":"additional","affiliation":[{"name":"Diabetes and Endocrine Department, Sheffield Teaching Hospitals NHS Foundation Trust, Sheffield, UK"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Muhammad","family":"Sharif","sequence":"additional","affiliation":[{"name":"Acute Medicine Department, Doncaster Royal Infirmary, Doncaster, UK"},{"name":"Department of General Internal Medicine, Hamad General Hospital, Doha, Qatar"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2018,9,12]]},"reference":[{"key":"2025082801275861000_2018.sep11_2.bcr-2018-226531.1","doi-asserted-by":"publisher","DOI":"10.1111\/dmcn.12339"},{"key":"2025082801275861000_2018.sep11_2.bcr-2018-226531.2","doi-asserted-by":"publisher","DOI":"10.1002\/mds.24981"},{"key":"2025082801275861000_2018.sep11_2.bcr-2018-226531.3","doi-asserted-by":"publisher","DOI":"10.1590\/S0004-282X2005000100005"},{"key":"2025082801275861000_2018.sep11_2.bcr-2018-226531.4","doi-asserted-by":"crossref","first-page":"391","DOI":"10.1007\/s00702-013-1122-x","article-title":"Deep brain stimulation in critical care conditions","volume":"121","author":"Franzini","year":"2014","journal-title":"J Neural Transm"},{"key":"2025082801275861000_2018.sep11_2.bcr-2018-226531.5","doi-asserted-by":"crossref","first-page":"390","DOI":"10.1016\/j.ejpn.2011.12.007","article-title":"Management of status dystonicus in children. 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