{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,3,6]],"date-time":"2026-03-06T20:47:52Z","timestamp":1772830072128,"version":"3.50.1"},"reference-count":11,"publisher":"BMJ","issue":"11","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2019,11,5]]},"published-print":{"date-parts":[[2019,11]]},"abstract":"<jats:p>We present a case of a 61-year-old woman who suffered a haemorrhagic complication of an aneurysmal left lingual artery, secondary to fibromuscular dysplasia, following transoral robotic surgery (TORS). She was admitted through the emergency department 3\u2009days after resection of a central base of tongue tumour. She suffered a massive haemorrhage requiring intensive care admission, blood transfusion, intubation, operative and endovascular intervention. The diagnosis of fibromuscular dysplasia was made at angiography. During attempts to embolise the culprit left lingual artery, the vessel dissected at its origin leading to arrest of bleeding. Repeat angiograms during her admission demonstrated unchanged appearances and ruled out recanalisation of the vessel. She was extubated and remained stable on the ward, discharged home some days later in good health. To our knowledge, this is the first ever reported case of fibromuscular dysplasia affecting the lingual artery leading to aneurysmal dilation and severe haemorrhage following TORS.<\/jats:p>","DOI":"10.1136\/bcr-2019-232022","type":"journal-article","created":{"date-parts":[[2019,11,25]],"date-time":"2019-11-25T04:25:17Z","timestamp":1574655917000},"page":"e232022","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":1,"title":["Large volume haemorrhage following transoral robotic surgery (TORS) as a result of fibromuscular dysplasia: first reported case"],"prefix":"10.1136","volume":"12","author":[{"ORCID":"https:\/\/orcid.org\/0000-0003-1876-3674","authenticated-orcid":false,"given":"Samuel Robert","family":"Leedman","sequence":"first","affiliation":[{"name":"Otolaryngology Head and Neck Surgery, Fiona Stanley Hospital, Murdoch, Western Australia, Australia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Aaron","family":"Esmaili","sequence":"additional","affiliation":[{"name":"Otolaryngology Head and Neck Surgery, Fiona Stanley Hospital, Murdoch, Western Australia, Australia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Tejinder","family":"Singh","sequence":"additional","affiliation":[{"name":"Interventional Radiology, Fiona Stanley Hospital, Murdoch, Western Australia, Australia"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Desmond","family":"Wee","sequence":"additional","affiliation":[{"name":"Otolaryngology Head and Neck Surgery, Fiona Stanley Hospital, Murdoch, Western Australia, Australia"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2019,11,24]]},"reference":[{"key":"2025082710514484000_12.11.e232022.1","doi-asserted-by":"crossref","first-page":"211","DOI":"10.1024\/0301-1526\/a000613","article-title":"Fibromuscular dysplasia - results of a multicentre study in Flanders","volume":"46","author":"De Groote","year":"2017","journal-title":"Vasa"},{"key":"2025082710514484000_12.11.e232022.2","doi-asserted-by":"publisher","DOI":"10.1111\/j.1747-4949.2010.00445.x"},{"key":"2025082710514484000_12.11.e232022.3","doi-asserted-by":"crossref","first-page":"616","DOI":"10.1016\/j.neurol.2015.02.011","article-title":"Fibromuscular dysplasia of cervicocephalic arteries: prevalence of multisite involvement and prognosis","volume":"171","author":"Pasquini","year":"2015","journal-title":"Rev Neurol"},{"key":"2025082710514484000_12.11.e232022.4","doi-asserted-by":"publisher","DOI":"10.1053\/j.tvir.2014.11.007"},{"key":"2025082710514484000_12.11.e232022.5","doi-asserted-by":"crossref","DOI":"10.1186\/1750-1172-2-28","article-title":"Fibromuscular dysplasia","volume":"2","author":"Plouin","year":"2007","journal-title":"Orphanet J Rare Dis"},{"key":"2025082710514484000_12.11.e232022.6","doi-asserted-by":"publisher","DOI":"10.2214\/ajr.162.5.8166011"},{"key":"2025082710514484000_12.11.e232022.7","doi-asserted-by":"publisher","DOI":"10.1136\/adc.84.3.263"},{"key":"2025082710514484000_12.11.e232022.8","first-page":"261","article-title":"Fibromuscular dysplasia of the extracranial carotid arteries. 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