{"status":"ok","message-type":"work","message-version":"1.0.0","message":{"indexed":{"date-parts":[[2026,8,18]],"date-time":"2026-08-18T15:56:17Z","timestamp":1787068577904,"version":"build-2736575974"},"reference-count":25,"publisher":"BMJ","issue":"5","content-domain":{"domain":["bmj.com"],"crossmark-restriction":true},"short-container-title":["BMJ Case Rep"],"accepted":{"date-parts":[[2020,5,4]]},"published-print":{"date-parts":[[2020,5]]},"abstract":"<jats:p>A newborn girl was referred to the otolaryngology service after prenatal imaging showed a right mandibular mass. Physical examination revealed a 1\u20132\u2009cm mass along the right mandible with the appearance of a vestigial oral cavity. Tissue resembling the vermillion and primitive tongue appeared innervated and moved in conjunction with oral movements. MRI and CT of the mandible after birth confirmed a partially ossified soft tissue mass of the right mandibular body, containing unerupted teeth. She was taken to the operating room at 6\u2009months of age for mass excision and reconstruction. Postoperatively, she healed well and was feeding without difficulty. Craniofacial duplication, including duplication of stomatodeal structures or diprosopus, is a rare condition with a variety of phenotypes. In the case of suspected craniofacial duplication, associated syndromes should be ruled out and appropriate imaging employed to determine the extent of involvement of adjacent structures, which will ultimately guide surgical planning.<\/jats:p>","DOI":"10.1136\/bcr-2019-233799","type":"journal-article","created":{"date-parts":[[2020,5,20]],"date-time":"2020-05-20T05:06:44Z","timestamp":1589951204000},"page":"e233799","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":7,"title":["Duplication of the oral cavity and mandible: a rare congenital craniofacial anomaly"],"prefix":"10.1136","volume":"13","author":[{"given":"Alexandra O","family":"Hamberis","sequence":"first","affiliation":[{"name":"College of Medicine, MUSC, Charleston, South Carolina, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"ORCID":"https:\/\/orcid.org\/0000-0003-0538-6259","authenticated-orcid":false,"given":"David","family":"Macias","sequence":"additional","affiliation":[{"name":"Otolaryngology - Head & Neck Surgery, MUSC, Charleston, South Carolina, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Clarice","family":"Clemmens","sequence":"additional","affiliation":[{"name":"Otolaryngology - Head & Neck Surgery, MUSC, Charleston, South Carolina, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]},{"given":"Krishna G","family":"Patel","sequence":"additional","affiliation":[{"name":"Otolaryngology - Head & Neck Surgery, MUSC, Charleston, South Carolina, USA"}],"role":[{"vocabulary":"crossref","role":"author"}]}],"member":"239","published-online":{"date-parts":[[2020,5,19]]},"reference":[{"key":"2025082703101013000_13.5.e233799.1","doi-asserted-by":"crossref","first-page":"290","DOI":"10.1016\/j.jcms.2013.05.016","article-title":"Partial craniofacial duplication: a review of the literature and case report","volume":"42","author":"Costa","year":"2014","journal-title":"J Craniomaxillofac Surg"},{"key":"2025082703101013000_13.5.e233799.2","first-page":"376","article-title":"[Partial facial duplication (a rare diprosopus): Case report and review of the literature]","volume":"116","author":"Es-Seddiki","year":"2015","journal-title":"Rev Stomatol Chir Maxillofac Chir Orale"},{"key":"2025082703101013000_13.5.e233799.3","doi-asserted-by":"crossref","first-page":"1924","DOI":"10.1016\/j.jcms.2014.07.013","article-title":"Accessory oral cavity associated with duplication of the tongue and the mandible in a newborn: a rare case of Diprosopus. 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