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Transvaginal ultrasound and MRI suggested the presence of an hypoplasic uterus in left rotation. Laparoscopically, two asymmetric rudimentary horns were found, united by a fibrous central band, with an enlarged and congestive left horn. The three structures were removed as a whole. Histopathological examination reported the presence of multiple adenomyotic foci along the full thickness of the left rudimentary horn. The patient had an uneventful postoperative recovery and full remission of her symptoms.<\/jats:p>","DOI":"10.1136\/bcr-2021-244127","type":"journal-article","created":{"date-parts":[[2022,2,7]],"date-time":"2022-02-07T11:32:05Z","timestamp":1644233525000},"page":"e244127","update-policy":"https:\/\/doi.org\/10.1136\/crossmarkpolicy","source":"Crossref","is-referenced-by-count":2,"title":["Adenomyosis in a uterine horn of a patient with Mayer-Rokitansky-Kuster-Hauser syndrome"],"prefix":"10.1136","volume":"15","author":[{"ORCID":"https:\/\/orcid.org\/0000-0002-9788-4249","authenticated-orcid":false,"given":"Ana Marta","family":"Pinto","sequence":"first","affiliation":[{"name":"Obstetrics and Gynaecology, Centro Hospitalar do Baixo Vouga, EPE, Aveiro, Portugal"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Ana Cl\u00e1udia","family":"Santos","sequence":"additional","affiliation":[{"name":"Obstetrics and Gynaecology, Centro Hospitalar do Baixo Vouga, EPE, Aveiro, Portugal"},{"name":"Obstetrics and Gynaecology, Centro Hospitalar e Universit\u00e1rio de Coimbra, EPE, Coimbra, Portugal"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"Nuno","family":"Oliveira","sequence":"additional","affiliation":[{"name":"Obstetrics and Gynaecology, Centro Hospitalar do Baixo Vouga, EPE, Aveiro, Portugal"}],"role":[{"role":"author","vocabulary":"crossref"}]},{"given":"M\u00e1rio","family":"Oliveira","sequence":"additional","affiliation":[{"name":"Obstetrics and Gynaecology, Centro Hospitalar do Baixo Vouga, EPE, Aveiro, Portugal"}],"role":[{"role":"author","vocabulary":"crossref"}]}],"member":"239","published-online":{"date-parts":[[2022,2,7]]},"reference":[{"doi-asserted-by":"publisher","key":"2025082700465613000_15.2.e244127.1","DOI":"10.1093\/humrep\/dew220"},{"key":"2025082700465613000_15.2.e244127.2","doi-asserted-by":"crossref","first-page":"e35","DOI":"10.1097\/AOG.0000000000002458","article-title":"ACOG Committee opinion no. 728: M\u00fcllerian agenesis: diagnosis, management, and treatment","volume":"131","year":"2018","journal-title":"Obstet Gynecol"},{"key":"2025082700465613000_15.2.e244127.3","doi-asserted-by":"crossref","first-page":"1","DOI":"10.1155\/2016\/3725043","article-title":"Rare case of leiomyoma and adenomyosis in Mayer-Rokitansky-Kuster-Hauser syndrome","volume":"2016","author":"Hoo","year":"2016","journal-title":"Case Rep Obstet Gynecol"},{"key":"2025082700465613000_15.2.e244127.4","doi-asserted-by":"crossref","first-page":"294","DOI":"10.5468\/ogs.2019.62.4.294","article-title":"Leiomyoma development in Mayer-Rokitansky-K\u00fcster-Hauser syndrome: a case report and a narrative review of the literature","volume":"62","author":"Blontzos","year":"2019","journal-title":"Obstet Gynecol Sci"},{"key":"2025082700465613000_15.2.e244127.5","doi-asserted-by":"crossref","first-page":"4147","DOI":"10.18203\/2320-1770.ijrcog20174080","article-title":"Fibroid originated from rudimentary horn in Mullerian agenesis","volume":"6","author":"Gupta","year":"2017","journal-title":"Int J Reprod Contracept Obstet Gynecol"},{"key":"2025082700465613000_15.2.e244127.6","doi-asserted-by":"crossref","first-page":"207","DOI":"10.3109\/01443619409004080","article-title":"Adenomyosis limited to a rudimentary uterine horn","volume":"14","author":"Tsuda","year":"1994","journal-title":"J Obstet Gynaecol"},{"key":"2025082700465613000_15.2.e244127.7","first-page":"235","article-title":"Acute abdomen in a case with noncommunicating rudimentary horn and unicornuate uterus","volume":"9","author":"Atmaca","year":"2005","journal-title":"JSLS"},{"key":"2025082700465613000_15.2.e244127.8","first-page":"e134","article-title":"Pregnancy in the rudimentary uterine horn: case report of an unusual presentation","volume":"14","author":"Ambusaidi","year":"2014","journal-title":"Sultan Qaboos Univ Med J"},{"key":"2025082700465613000_15.2.e244127.9","doi-asserted-by":"crossref","DOI":"10.5812\/ircmj.19351","article-title":"Functional rudimentary horn as a rare cause of pelvic pain: a case report","volume":"16","author":"Arab","year":"2014","journal-title":"Iran Red Crescent Med J"},{"doi-asserted-by":"publisher","key":"2025082700465613000_15.2.e244127.10","DOI":"10.1016\/j.jpag.2014.09.001"},{"key":"2025082700465613000_15.2.e244127.11","doi-asserted-by":"crossref","first-page":"901","DOI":"10.1016\/j.jmig.2017.04.020","article-title":"Obstructive reproductive tract anomalies: a review of surgical management","volume":"24","author":"Skinner","year":"2017","journal-title":"J Minim Invasive Gynecol"},{"doi-asserted-by":"publisher","key":"2025082700465613000_15.2.e244127.12","DOI":"10.1016\/j.jpag.2013.03.004"},{"key":"2025082700465613000_15.2.e244127.13","first-page":"203","article-title":"Laparoscopy for pelvic pain in the Mayer-Rokitansky-Kuster-Hauser syndrome. 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